Jasmin A. Keller1, Sigurdur Sigurdsson 2, Mark A. van Buchem1, Lenore J. Launer3, Matthias J.P. van Osch1, Vilmundur Gudnason2,4, and Jeroen H.J.M. de Bresser1
1Department of Radiology, Leiden University Medical Center, Leiden, Netherlands, 2Icelandic Heart Association, Kopavogur, Iceland, 3Laboratory of Epidemiology and Population Science, National Institute on Aging, Bethesda, MD, United States, 4Faculty of Medicine, University of Iceland, Reykjavik, Iceland
Synopsis
Keywords: Dementia, Aging, Cerebral small vessel disease
White matter hyperintensity (WMH) shape was recently introduced as a
novel small vessel disease (SVD) marker that may provide a more detailed
characterization of WMH than volume alone. We aimed to investigate
the association between baseline WMH shape and cerebrovascular disease progression
over 5 years. A more irregular shape of periventricular/confluent and deep WMH
at baseline is associated with increased progression of WMH volume. Moreover, a
more irregular shape of periventricular/confluent WMH was associated with occurrence
of new microbleeds and new subcortical infarcts at follow-up. Our findings
indicate that a more irregular WMH shape is associated with SVD progression.
Introduction
Cerebral small vessel disease (SVD) is a strong
vascular contributor of cognitive decline and dementia1. Common SVD
markers on brain MRI are white matter hyperintensity (WMH) volume, lacunes and
microbleeds. Recently, WMH shape was introduced as a novel marker that may provide
a more detailed characterization of WMH compared to the most commonly used WMH volume.
WMH shape markers have been associated with the occurrence of future stroke and
increased mortality in patients with an increased vascular burden2. Moreover,
a more irregular shape of periventricular/confluent WMH was associated with an
increased long-term risk for dementia3. Since it is unknown whether
WMH shape is a predictor of SVD progression, we aimed to investigate the association
between baseline WMH shape and progression of SVD markers over 5 years. Methods
Participants
& study design
Data from the AGES Reykjavik
study was used in the current study4. FLAIR and T1-weighted brain
MRI scans were acquired at baseline from 2002 to 2006 on a 1.5 Tesla Signa
Twinspeed system (General Electric Medical Systems, Waukesha, Wisconsin). Five
years later, follow-up MRI scans were acquired from 2007 to 2011 with the same
protocol. A total of 2297 participants were included in the current study.
WMH shape
WMH
were segmented automatically on registered FLAIR images using the LST toolbox
in SPM125. Lateral ventricles were segmented from T1 scans and the ventricle
masks were inflated with 3 and 10 mm. The inflated ventricle masks aided WMH classification
into periventricular, confluent, and deep WMH (figure 1). WMH shape markers were
calculated based on the WMH segmentations. Convexity, solidity, concavity
index, and fractal dimensions were determined for periventricular/confluent
WMHs6. A lower convexity and solidity, and higher concavity index
and fractal dimension indicate more irregularly shaped periventricular or
confluent WMH. Fractal dimensions and eccentricity were calculated for deep WMH6.
Higher eccentricity and fractal dimensions indicate a more complex shape of
deep WMH.
Other SVD markers
Gray matter, white
matter, cerebrospinal fluid and WMH volume were segmented automatically with a
modified algorithm based on the Montreal Neurological Institute pipeline7.
Intracranial volume resulted from the addition of the volumes of gray matter,
white matter, cerebrospinal fluid and WMH8. Occurrence of new brain subcortical
infarcts and microbleeds was rated by comparing the baseline and follow-up MRI
scans9.
Statistical analysis
Solidity and convexity were
inverted for the logistic regression analyses to aid comparability of the
results. Solidity was multiplied by 100 and natural log transformed due to
non-normal distribution. Z-scores of WMH shape markers were calculated to aid
comparability. To study the association between WMH shape markers and ΔWMH
volume linear regression analyses controlled for age, sex, and ICV were
performed. To study the association between WMH shape markers and occurrence of
new infarcts and new microbleeds logistic regression analyses were performed,
controlled for age and sex.
Results
Characteristics
of the study sample are shown in table 1. The relation of WMH shape markers and
ΔWMH volume at the 5-year follow-up is shown in figure 2. A more irregular
shape of periventricular/confluent (solidity, convexity, concavity index,
fractal dimension) and deep WMH (eccentricity, fractal dimension) at baseline were associated with increased progression of
WMH volume over 5 years (table 2). A more irregular shape of periventricular/confluent
WMH (solidity, convexity, concavity
index, fractal dimension) was associated with new subcortical infarcts
and new microbleeds at the 5 year follow-up (table 3).Discussion
We
found that a more irregular shape of periventricular/confluent and deep WMH is
associated with increased progression of WMH volume over 5 years. Moreover, a
more irregular shape of periventricular/confluent WMH was associated with
occurrence of new subcortical infarcts and new microbleeds at the 5 year
follow-up. The etiology of WMH in SVD is heterogenous and the pathophysiology
remains poorly understood. A more irregular shape of WMH may reflect a more
severe underlying etiology of SVD, and as such is subsequently followed by increased
progression of SVD related brain changes. This hypothesis is in line with
previous post-mortem histopathological studies that showed that a more
irregular shape of confluent WMH was associated with more severe brain parenchymal
changes compared to the mild and smooth periventricular WMH10,11. In
conclusion, our findings indicate that a more irregular
WMH shape is associated with long-term SVD progression. Acknowledgements
This research was
supported by an Alzheimer Nederland grant (WE.03-2019-08).References
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