Hiroyuki Kameda1,2, Taisuke Harada1,3, Hiroyuki Sugimori4, Xiawei Bai3, Kazuyuki Minowa2, and Kohsuke Kudo3,5
1Department of Diagnostic and Interventional Radiology, Hokkaido University Hospital, Sapporo, Japan, 2Department of Raiology, Faculty of Dental Medicine, Hokkaido University, Sapporo, Japan, 3Department of Diagnostic Imaging, Facaulty of Medicine and Graduate School of Medicine, Hokkaido University, Sapporo, Japan, 4Faculty of Health Sciences, Hokkaido University, Sapporo, Japan, 5Global Center for Biomedical Science and Engineering, Hokkaido University, Sapporo, Japan
Synopsis
Keywords: Neurofluids, Neurofluids
Imaging of neurofluids dynamics is a
promising aspect in clinical imaging. Only few methods of long-term water tracking
in the brain have been described for diagnostic purposes. Herein, we examined water
circulation between the CSF and ISF
using an intrathecal injection of
17O-labeled water and 3T-MRI in two
patients with dementia. Signal changes were detected in the brain
parenchyma after the intrathecal administration. This
visualization technique can detect the distribution of water tracers to the CSF and brain parenchyma and could become a clinical tool for evaluating neurofluids dynamics in humans.
INTRODUCTION
The neurofluids acts as the clearance
system of the brain through circulation of the cerebral spinal fluid (CSF) and
cerebral interstitial fluid (ISF). Evidence of its
existence has been reported in many animal and human studies1,2. Visualization
of this aspect of brain physiology is expected to have a significant impact on
clinical imaging. Former MRI tracer studies have used gadolinium contrast media
as a soluble tracer for intrathecal injection3. However, it is
associated with side effects and may not accurately reflect the dynamics of neurofluids since solutes and water molecules behave differently. 17O-labeled water, which is water labeled with a stable
oxygen isotope, is a T2-shortening contrast agent in proton MRI, allowing
direct imaging of water4-7. We previously reported the feasibility
of water clearance assessment in the CSF using this tracer8.
However, the study did not successfully evaluate the distribution of 17O
in the brain parenchyma because the long echo time (TE) to target the CSF
reduced the signal-to-noise ratio (SNR) of the brain parenchyma. In this study,
we evaluated the visualization of water circulation between CSF and ISF in
humans using an intrathecal injection of 17O-labeled water and MRI
in a small number of patients.MATERIALS AND METHODS
The institutional review board approved the study, and
the written informed consent was obtained from the patient. Because of the procedure’s
invasiveness, only patients already scheduled for lumbar puncture were included.
Two patients with suspected dementia (patient 1, an 84-year-old woman; patient 2, a 63-year-old man) were examined using MRI. After lumbar puncture examination, 10 ml
of 17O-labeled physiological saline (enriched to 10 mol%, PSO17,
Taiyo Nippon Sanso, Tokyo, Japan) was slowly administered intrathecally. MRI
scans were performed using a 3.0 Tesla MRI scanner (Hitachi, Ltd., Tokyo, Japan).
Whole-brain 3D-T2-weighted images were acquired using a fast spin echo (FSE)
sequence (TR = 3500 ms; effective TE = 100 ms; FA = 90o; NSA = 1;
echo train length = 35; acceleration factor = 2; matrix size = 192×192; field of view (FOV) = 320 mm; slice thickness = 1.7 mm)
at four time points (baseline and post-1, 8, and 24 h; Fig. 1). Patient-specific
fixation pillows were used to align the patient positions for each MRI scan.
The receiver amplifier gain for each session was fixed. Statistical Parametric
Mapping software (SPM12) and
MATLAB R2022a was used for image alignment, segmentation, and calculation of
17O concentration maps. Changes in the 17O
concentration were calculated considering the baseline signal using a previously
reported formula4-6.RESULTS
The patients did not experience any adverse
events after receiving 17O labeled water. In both patients, the 17O
concentrations peaked in the CSF space, mainly in the basilar cistern and bilateral
sylvian valley, 1 h after administration, and then declined (Fig. 2). A similar
trend was observed in the brain parenchyma, but the heterogeneity of 17O
was noticeable across regions. Lumbar puncture was performed in the lateral position,
and the signal change was particularly pronounced in the area that was in the
direction of gravity in the lateral position
(Fig. 2).DISCUSSION
In this study, we detected signal changes in the brain parenchyma using clinical MRI after intrathecal
administration of 17O-labelled water. We speculate that these signal
changes indicate the circulation of the water tracer from the CSF space to
the brain parenchyma via the perivascular space, i.e., the glymphatic pathway. Although previous studies in rats have used high
17O concentration water (90 mol%) and ultra-high field 7T MRI7,
our preliminary data indicate that even a 10% concentration of 17O-labeled
water and a 3T-MRI can be valuable tools for visualizing neurofluids dynamics in humans. However, our study has some limitations.
First, we used weighted MR images to measure 17O signal changes;
these may be influenced by session-to-session differences in the patient’s geometric
position relative to the MR coil that affect the B1 profiles,
and other related factors. Our next plan consists of using high-resolution
3D-T2 mapping for improving the accuracy and reliability of 17O measurements. Second, since part
of the observed 17O distribution to the brain parenchyma seemed to
be related to the body position at the time of injection, adjusting the body
position during or after injection may be necessary to avoid uneven distribution
of tracer. Third, the effects from blood circulation are unknown because 17O
pharmacokinetics were not assessed by blood or spinal fluid sampling. Finally, the
small number of patients presents a limitation.CONCLUSION
Direct imaging of water tracers using MRI
with intrathecal administration of 17O-labeled water can detect their
distribution to the CSF and brain parenchyma. This technique can become a
successful clinical tool for the evaluation of neurofluids
dynamics in humans.Acknowledgements
No acknowledgement found.References
- Benjamin A Plog and Maiken Nedergaard.
2018. “The Glymphatic System in Central Nervous System Health and Disease:
Past, Present, and Future.” Annual Review of Pathology 13: 379–94.
-
Martin Kaag Rasmussen, Humberto Mestre, and
Maiken Nedergaard. 2018. “The glymphatic pathway in neurological disorders.” Lancet
Neurology 17 (11): 1016–24.
-
Geir Ringstad, Lars M Valnes, Anders M
Dale, Are H Pripp, Svein-Are S Vatnehol, Kyrre E Emblem, Kent-Andre Mardal, and
Per K Eide. 2018. “Brain-wide glymphatic enhancement and clearance in humans assessed
with MRI.” JCI Insight 3 (13): e121537.
-
Kohsuke Kudo, Taisuke Harada, Hiroyuki
Kameda, Ikuko Uwano, Fumio Yamashita, Satomi Higuchi, Kunihiro Yoshioka, and
Makoto Sasaki. 2018. “Indirect MRI of 17O-labeled water using steady-state
sequences: Signal simulation and preclinical experiment.” Journal of
Magnetic Resonance Imaging: JMRI 47 (5): 1373–79.
-
Kohsuke Kudo, Taisuke Harada, Hiroyuki
Kameda, Ikuko Uwano, Fumio Yamashita, Satomi Higuchi, Kunihiro Yoshioka, and
Makoto Sasaki. 2018. “Indirect Proton MR Imaging and Kinetic Analysis of 17O-Labeled
Water Tracer in the Brain.” Magnetic Resonance in Medical Sciences: MRMS: an
official journal of Japan Society of Magnetic Resonance in Medicine 17 (3):
223–30.
-
Taisuke Harada, Kohsuke Kudo, Hiroyuki Kameda, Ryota Sato, Toru Shirai, Yoshitaka Bito, Noriyuki Fujima, et al. 2022. “Phase
I Randomized Trial of 17O-Labeled Water: Safety and Feasibility
Study of Indirect Proton MRI for the Evaluation of Cerebral Water Dynamics.” Journal of Magnetic Resonance Imaging: JMRI.
-
Mohammed S Alshuhri, Lindsay Gallagher,
Lorraine M Work, and William M Holmes. 2021. “Direct imaging of glymphatic transport
using H217O MRI.” JCI Insight 6 (10): e141159.
-
Hiroyuki Sugimori, Hiroyuki Kameda, Taisuke
Harada, Kinya Ishizaka, Masayoshi Kajiyama, Tasuku Kimura, Niki Udo, et al.
2022. “Quantitative magnetic resonance imaging for evaluating of the cerebrospinal
fluid kinetics with 17O-labeled water tracer: A preliminary report.” Magnetic
Resonance Imaging 87: 77–85.