Irene Margaret Vavasour1,2, Kyle Vavasour3, Adam Dvorak4, Tigris Joseph2,4, Robert Carruthers5, Shannon Kolind1,2,4,5, Alice Schabas5, Ana-Luiza Sayao5, Virginia Devonshire5, Roger Tam1,6, GR Wayne Moore2,5,7, Anthony Traboulsee5, David Li1,5, and Cornelia Laule1,2,4,7
1Radiology, University of British Columbia, Vancouver, BC, Canada, 2International Collaboration on Repair Discoveries, University of British Columbia, Vancouver, BC, Canada, 3University of British Columbia, Vancouver, BC, Canada, 4Physics and Astronomy, University of British Columbia, Vancouver, BC, Canada, 5Medicine, University of British Columbia, Vancouver, BC, Canada, 6School of Biomedical Engineering, University of British Columbia, Vancouver, BC, Canada, 7Pathology & Laboratory Medicine, University of British Columbia, Vancouver, BC, Canada
Synopsis
Keywords: Multiple Sclerosis, Multiple Sclerosis, diffusely abnormal white matter, T2 relaxation
Diffusely abnormal white matter (DAWM)
is seen on 25-50% of conventional brain MRI scans from all stages of multiple
sclerosis (MS). From
8 advanced MRI metrics, geometric mean T
2 of the intra/extracellular
water (IET
2) best separated MS participants with and without DAWM.
Comparing IET
2 to controls using z-scores, regions with an
intermediate increase in IET
2 (z-scores between 1-2) may identify
DAWM voxels.
Introduction
Diffusely abnormal white matter (DAWM)
is a common, yet understudied, feature found on brain MRI in 25-50% of people
with multiple sclerosis (MS). DAWM is defined as diffuse areas of white matter
with mildly increased proton-density (PD) and T2-weighted signal, similar
to grey matter and less hyperintense than focal lesions, with post-mortem
histology showing myelin changes, axonal loss and blood-brain barrier breakdown1-5.
DAWM contributes to MS disease4,6,7 and accurate identification is
important for understanding MS pathogenesis.
DAWM is most commonly identified based on PD/T2-weighted scan
intensity, however, this is a very subjective definition. Advanced MRI measures
may help in better defining areas of DAWM due to their quantitative nature and greater
specificity to underlying pathology. Myelin
water fraction (MWF8)
has been histologically validated as a marker for myelin9. T1
relaxation is closely related to water content10 and intra/extracellular
water geometric mean T2 relaxation (IET2) is
related to water mobility and tissue microstructure. Diffusion basis
spectrum imaging (DBSI) models myelinated and demyelinated axons as anisotropic
diffusion tensors, and cells/extracellular space as isotropic diffusion tensors11
providing axial diffusivity (related to axonal integrity), fibre
fraction (axon density12), radial diffusivity (modulated
by myelin13), restricted fraction (cellularity11)
and non-restricted fraction (edema12). Objective
To determine the advanced MR metrics best able to separate MS
participants with DAWM (DAWM+) from those without DAWM (DAWM–) and to develop
an automated, quantitative approach for detection of DAWM using those MR
metrics.Methods
Subjects
and MR Experiments: 103 MS participants (Fig.1) were scanned at 3T (Philips
Achieva). Scanning sequences included 48-echo GRASE T2 relaxation (TR/TE=1073/8ms, 1x1x2.5mm3, slices=40)14,
inversion recovery T1
(TIs=150,400,750,1200,2100ms, TR=3000ms, 1x1x2.5mm3, slices=40), DBSI (99 directions, b-values=0-1500,
TR/TE=4798/79ms, 2x2x2mm3, slices=40)10, PD/T2-weighted
(TR/TE1/TE2=2900/8.42/80ms, 1x1x3mm3), 3DT1-MPRAGE (TR/TE/TI=3000/3.5/926ms, 1x1x1mm3).
Data
Analysis/Statistics: Voxel-wise T2
distributions were calculated using non-negative least squares (MWF: fractional
signal T2<40ms; IET2: mean 40<T2<200ms).15,16
T1 was fit to a single exponential. DBSI data was analysed to
calculate DBSI metric maps12. Metric maps were registered to 3DT1
(FLIRT, FSL toolbox)17. White matter (WM) masks were created on the
3DT1 (FAST18). Lesions were automatically segmented using
seed points19. DAWM+ and DAWM– participants were identified by
consensus by three experienced MRI researchers. DAWM and similarly located normal-appearing
white matter (NAWM) areas in the DAWM– subjects were delineated (Fig.2a). Masks were overlaid onto
registered MRI metric maps to obtain mean measurements in WM, lesions and
DAWM/NAWM-matched areas.
MR metrics means of each tissue mask were
entered into a classification tree to identify which of the MR metrics were best
able to separate DAWM+ from DAWM– participants (RStudio 2022.02.2). Z-score
maps of the best DAWM+/DAWM– separator were then calculated using a premade
healthy control atlas from 100 participants20 (z-score=(individual MS
data – mean controls)/(standard deviation of controls)). A region
surrounding the posterior end of the ventricles where DAWM is most often
located was delineated and used as a mask for the z-score maps (Fig.2b).
The number of voxels with a z-scores >4, 1-2 and 2-3 within all NAWM and
within the posterior WM-defined region was determined and compared between
DAWM+ and DAWM– participants using a t-test.Results
Fifty participants were identified as DAWM+ (
Fig.1). From the classification tree, only IET
2
in DAWM/matched-NAWM and lesions were used to best separate DAWM+ and DAWM–
participants (
Fig.3a). 5
participants were misclassified as DAWM+ and 9 as DAWM– (
Fig.3b).
Fig.4 shows example images from DAWM+ and DAWM– participants.
Comparing DAWM+ and DAWM–:
- the
difference in the number of voxels with elevated z-score values was more
significant within the posterior WM-defined region than all NAWM.
- a
difference was found in the number of voxels with z-score>4 in all NAWM
(p=0.04) but not in the posterior defined WM region (p=0.2) (Fig.5).
- the
number of voxels with z-scores between 1-2 (all NAWM p=0.0002; posterior WM p<0.0001)
and 2-3 (all NAWM p=0.012; posterior WM p=0.0003) was different between DAWM+
and DAWM– (Fig.5).
- The
number of voxels with z-scores between 1-2 had the lowest p-value in both all
NAWM and posterior WM regions.
Discussion
The classification tree, which
maximises the separation of DAWM+ and DAWM– participants while also keeping the
number of measures included low, showed that a mean IET2 < 80ms
within the DAWM/NAWM-matched regions indicated no DAWM. Areas of DAWM have
previously shown elevated IET221, likely representing
areas of tissue edema and/or inflammation. If the DAWM/NAWM-matched areas had a
mean IET2 >80ms, then if the mean IET2 of lesions was
>103ms, the participant was classified as DAWM–. Lesions with large IET2
may be more extensive which makes the identification of subtle intensity
changes from DAWM difficult to detect leading to a DAWM– labeling. Voxels with
a z-score >4 likely represent lesional areas whereas DAWM is less abnormal
and therefore more likely in the z-score range from 1-3. By limiting our region
of interest to areas where DAWM predominates and using a z-score range of 1-2,
we get better separation of DAWM+ and DAWM– participants.Conclusion
DAWM is most commonly identified based on PD/T2-weighted
scan intensity, however, a more objective method of identification is needed. Using
intermediately increased z-scores (1-2) in IET2 may identify DAWM+
voxels with less subjectivity. Incorporation of advanced imaging metrics into tissue
classification may lead to more objective DAWM identification in the future.Acknowledgements
We would like to thank the MS volunteers and the
staff at the UBC MRI Research Centre and UBC MS Clinic. This study was funded
by the Multiple Sclerosis Society of Canada and by the VGH and UBC Hospital
Foundation. This
work was conducted on the traditional, ancestral, and unceded territories of
Coast Salish Peoples, including the territories of the xwməθkwəy̓əm (Musqueam),
Skwxwú7mesh (Squamish), Stó:lō and Səl̓ílwətaʔ/Selilwitulh (Tsleil- Waututh)
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