Caleb J. Han1, Spencer Waddle1, Maria Garza1, L. Taylor Davis2, Jarrod Eisma1, Rohan Chitale3, Matthew Fusco3, Colin D. McKnight2, Sky Jones1, Lori C. Jordan1,4, and Manus J. Donahue1,2,5
1Neurology, Vanderbilt University Medical Center, Nashville, TN, United States, 2Radiology, Vanderbilt University Medical Center, Nashville, TN, United States, 3Neurosurgery, Vanderbilt University Medical Center, Nashville, TN, United States, 4Pediatrics, Vanderbilt University Medical Center, Nashville, TN, United States, 5Psychiatry, Vanderbilt University Medical Center, Nashville, TN, United States
Synopsis
Keywords: Neurofluids, Stroke, Moyamoya, glymphatic, choroid plexus, cerebrovascular reactivity, CSF
This work applies hypercapnic reactivity and deep-learning techniques to evaluate choroid plexus (ChP) vascular compliance dependence on large arterial patency in intracranial vasculopathy. ChP reactivity was found to be preserved regardless of macrovascular vasculopathy, despite dependencies of resting ChP perfusion on cortical ischemia. Findings support the possibility that changes in resting ChP function in other studies in the presence of arterial vasculopathy and cerebral ischemia may be a response to circulating biochemical markers of ischemic stress, prompting the ChP to attenuate CSF production levels through feedback, rather than vascular mechanisms, to support glial health in ischemia.
Introduction
The overall goal of this work is to apply hypercapnic reactivity and deep-learning techniques to evaluate choroid plexus (ChP) vascular compliance dependencies on arterial patency in patients with intracranial vasculopathy. It has recently been shown that the ChP, the primary site of cerebrospinal fluid (CSF) production, can exhibit local hyperemia in patients with cerebral ischemia secondary to bilateral intracranial vasculopathy, which can reduce following successful surgical revascularization1. This suggests, but does not confirm, that ChP perfusion may provide a central marker of ischemic stress. One explanation underlying this observation is that compliance of microvasculature may be reduced during ischemia, prompting the ChP to increase CSF production to clear solutes along less compliant perivascular pathways. However, the ChP activity may also simply depend on changes in macrovascular arterial patency and the reserve capacity of the ChP itself. We investigate ChP and cortical vascular compliance by evaluating cerebrovascular reserve capacity in patients with intracranial vasculopathy with and without prior surgical revascularization. We hypothesize that, unlike in cortical blood flow territories, ChP vascular reserve is unaffected by intracranial stenosis; thus, changes in ChP activity following revascularization are likely to arise from circulating markers of ischemic stress.Materials and Methods
Demographics. Participants (n=58) were recruited from the neurosurgical services at our institute and had a clinical diagnosis of moyamoya (i.e., non-atherosclerotic) vasculopathy based on catheter angiography and neurological assessment. Prior surgical revascularization was not an exclusion criterion and was considered in the analysis.
Experiment. All participants underwent clinically-indicated catheter angiography (bilateral internal carotid artery and vertebral artery injections)2 in sequence with non-contrasted anatomical MRI (T1-weighted, T2-weighted, T2-weighted FLAIR, and DWI), blood oxygenation level-dependent (BOLD; TE=35 ms; spatial resolution=3.5x3.5x3.5 mm, TR=2000 ms) at 3.0 Tesla (Philips)3. A paradigm of two blocks of 180s hypercapnia gas (5% CO2) interleaved with 180s normocapnia gas (~21% O2/~79% N2) was performed.
Analysis. A board-certified neuroradiologist graded stenotic or occluded vessels in each hemisphere from catheter angiography according to NASCET criteria4. Arterial stenosis was ranked ordinally: 0: no-to-69% stenosis present, 1: 70%-99% stenosis, 2: occlusion. Time regression analysis was performed for quantification of timing-uncorrected cerebrovascular reactivity (CVRRAW), maximum cerebrovascular reactivity (CVRMAX), and reactivity delay time (CVRDELAY)5. ChP structures in the atria of the lateral ventricles and third ventricles were localized by a convolution neural network algorithm applied to the T1-weighted scan6, 7. Cortical masks derived for the middle-cerebral-artery (MCA) flow territory map were used to determine CVR parameters in the proximity of the revascularization site, separately for the left and right hemispheres.
Statistics. This analysis aimed to understand whether published post-surgical ChP perfusion reductions1 were attributable to changes in the ChP parenchymal vascular reactivity. Each participant was categorized based on prior revascularization status, then further organized based on the vasculopathy ranking of their worst vessel. A one-way ANOVA test was applied, separately in ChP and MCA territories, for the reactivity parameters. Significance criterion: Bonferroni-corrected two-sided p<0.05.Results
Table 1 summarizes participant demographics, including the cohort with (n=32; age=43.1±14.9 years) and without (n=26; age=49.8±14.0 years) prior revascularization surgeries. All surgeries were indirect (e.g., encephalo-duro-arterio-synangiosis, EDAS). Similar to a previously mentioned perfusion study1, all participants had stenosis or occlusion of at least one intracranial internal-carotid-artery or first segment of MCA but lacked posterior circulation stenosis. Fig. 1 shows examples of a representative participant's MCA and ChP regions. In patients without prior revascularization surgeries, the degree of arterial vasculopathy reduced CVRRAW and CVRMAX, and lengthened CVRDELAY in the MCA territories, as expected (p≤0.029) (Fig. 2). No significant change was observed in the MCA territory of post-surgical participants (Fig. 2), highlighting that, as expected, MCA territory reserve capacity is affected by arterial vasculopathy and improves following surgical revascularization. However, regardless of surgical history, the ChP reactivity statistics were not significantly related to the degree of stenosis (Fig. 3). Fig. 4 shows a representative example of ChP vs. cortical hemodynamics, demonstrating lateralizing effects in cortical regions and symmetric vascular compliance in ChP in a manner that is independent of arterial patency.Discussion
While cortical hemodynamics relate to proximal arterial patency and prior surgical history in non-atherosclerotic moyamoya vasculopathy, ChP reactivity was observed to be preserved regardless of large vessel vasculopathy and revascularization status. This supports the interpretation that previously reported changes in ChP hemodynamics1 following surgical revascularization are less likely related to the vascular supply of the ChP itself and more likely attributable to the ChP response to circulating markers of ischemic or glial stress. This is also consistent with the arterial supply of the ChP: anterior and posterior choroidal arteries, which branch from the posterior circulation, and are known to be less affected than anterior circulation vessels in moyamoya. Improved arterial supply to damaged or at-risk glial tissue could reduce biochemical signs of cellular stress secretion, prompting ChP to attenuate high CSF production levels which were previously necessary to clear neurofluid along less compliant perivascular pathways in times of vascular stress.Conclusion
Findings support that ChP reactivity is frequently preserved in moyamoya vasculopathy; as such, changes in ChP function in response to revascularization or circulating markers of cerebral ischemia are more likely to reflect central feedback phenomena rather than ChP vascular reserve changes.Acknowledgements
References
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