Naoya Kinota1,2, Hiroyuki Kameda3,4, Kazuyuki Minowa3, and Kohsuke Kudo1,5
1Department of Diagnostic Imaging, Faculty of Medicine and Graduate School of Medicine, Hokkaido University, Sapporo, Japan, 2Department of Dental Radiology, Hokkaido University Hospital, Sapporo, Japan, 3Department of Radiology, Faculty of Dental Medicine, Hokkaido University, Sapporo, Japan, 4Department of Diagnostic and Interventional Radiology, Hokkaido University Hospital, Sapporo, Japan, 5Global Center for Biomedical Science and Engineering, Faculty of Medicine, Hokkaido University, Sapporo, Japan
Synopsis
Keywords: Neurofluids, Neurofluids, Glymphatic System
Previous reports showed that deep
cervical lymph nodes (DCLNs) receive cerebrospinal fluid (CSF) outflow. DCLN
ligation resulted in intracranial accumulation of waste proteins due to
impaired CSF outflow; however, changes in extracranial outflow after DCLN
ligation have not been directly observed. We examined extracranial CSF outflow
in rats after DCLN ligation by using intrathecal gadolinium (Gd)-based
dynamic contrast-enhanced MRI. DCLN ligation blocked CSF- tracer outflow into
the nasal cavity. A weak trend towards CSF-tracer retention in the ventral
cistern was also observed. These results suggest that DCLN ligation affects CSF
outflow in rodents.
Introduction
The
transnasal pathway is a major cerebrospinal fluid (CSF) outflow route in rodents.1-3 Recent
studies have also reported the existence of an efflux pathway via meningeal
lymphatic vessels.4 Connections between deep cervical lymph nodes
(DCLNs) and these efflux pathways may serve as relay points for CSF and solute
outflow.2–8 Surgical
ligation of DCLNs accelerates the intracranial accumulation of amyloid-β or
α-synuclein by blocking the outflow of CSF, and exacerbates the symptoms of Alzheimer’s
and Parkinson’s diseases in mouse models.7,8 Although such
pathological effects have been reported, changes in extracranial CSF outflow after ligation
of DCLNs have not been directly observed. In this study, we examined whether
DCLN ligation changes the extracranial outflow of CSF tracers using a rat model
of Gd-based dynamic contrast-enhanced (DCE) MRI.
Material and Methods
The Animal Study Committee of our institute approved all study
experiments. Male Wistar 7-10-week-old rats were used in the study. Twelve rats
were divided into two groups: a bilateral DCLN-ligation group (n = 6) and a sham
operation group (n = 6). After placing an intrathecal injection tube in the
cisterna magna, DCE MRI was conducted using a 3.0-T clinical scanner (Magnetom
Prisma, Siemens, Germany) with a custom-made 8-channel phased array receiver
coil (Takashima Seisakusho, Japan). Scans were acquired using 3D T1 weighted volumetric
interpolated breath-hold examination sequences (VIBE) with the following
parameters: TR, 8.72 ms; TR, 3.6 ms; flip angle, 14 deg; acquisition resolution,
0.4 × 0.4 × 0.2 mm; reconstruction resolution, 0.2 × 0.2 × 0.2 mm; number of excitations,
1; scan time per phase, 147 s; number of repetitions, 43; and total scan time,
105 min 21 s. After acquiring three phases of pre-contrast images, the rats received
an intrathecal injection of 10 mmol/L of gadolinium (Gd)-BTDO3A (Gadovist,
Bayer HealthCare Japan, Japan) diluted in normal saline at 1.7 μL/min for 20
min using an MR-compatible microinjector, resulting in a total amount of 34 μL.
After initiating intrathecal injection, 40 phases of 3D-T1 VIBE images were
acquired. Details of the procedures are shown in Figure 1. Rectangle
ROIs were manually placed on CSF space at the pituitary recess, between
olfactory bulbs and the pineal recess. Polygonal ROIs were placed on upper
nasal turbinates and soft tissue outside the bilateral jugular foramen. For
each ROI, the signal ratio of each phase from the average of 3 pre-contrast phases
was calculated, and average time-intensity curves (TICs) were generated for
both groups and compared using 2-way repeated measures ANOVA. The peak signal
ratios and peak timing of signal ratios were also compared using U-tests. A
p-value of < 0.05 was considered significant.Results
Gd-BTDO3A injected from the cisterna magna spread through
the CSF space rostrally
over time and flowed out through the cribriform plate into the nasal cavity (Figure
2 and 3). The DCLN-ligation group demonstrated a
lower signal ratio with statistical significance in the upper nasal turbinates
in the early phases from 17.2 to 31.9
minutes after injection initiation (Figure 4). In the ligation group, we
observed a trend towards a higher signal
ratio in the CSF space at the pituitary recess in the delayed phase,
but this was not statistically significant. No apparent
signal change was observed in the soft tissue around the jugular
foramen. The
peak signal-ratio timing in the CSF was delayed at the level of the olfactory bulb in
the DCLN-ligation group (p = 0.02), and we also observed a higher peak signal
ratio in the upper nasal turbinates in the DCLN-ligation group (p = 0.002) (Figure
5). Discussion
Our results
suggest that ligation of DCLNs blocks the nasal lymphatic pathway in rodents. This
observation is consistent with previous studies proposing that intrathecally administered
tracers mainly drain into the nasal cavity and travel through the peripheral lymphatic
vessels of the nasopharynx to the DCLNs.1–3
Previous
reports showed the contribution of meningeal lymphatics to CSF clearance, and several
studies demonstrated an accumulation of Gd tracers in the lymphatic vessels
around the jugular foramen using sequences sensitive to small amounts of Gd.3,4
In the present study, we did not detect this accumulation using the T1-VIBE
sequence, in
contrast to the clear observation of tracer outflow into the nasal cavity.
This result indicated that in rats, the amount of CSF tracer flowing out from the jugular region was
significantly smaller than that from the nasal
pathway.
In this study, a weak trend towards tracer
retention in the basal CSF space during the late phases was observed. This might be explained by the blocked CSF outflow of the
nasal lymphatic pathway.
However, other compensatory mechanisms might exist, such as distribution into
the brain or spinal subarachnoid space, because the observed difference
was small. We were interested to elucidate the possible compensatory mechanisms;
however, the tracer was not sufficiently distributed into the brain parenchyma
under our injection conditions containing low Gd
concentrations, (data not shown), and the spinal cord was
outside the field of view. Conclusion
DCLN ligation blocks the nasal
lymphatic pathway in rats. DCLN ligation may also cause solute retention in the basal CSF space.Acknowledgements
No acknowledgement found.References
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