Mariem Hamzaoui1, Jeanne Garcia1,2, Giacomo Boffa1,3, Andrea Lazzarotto1,2,4, Vito A G Ricigliano2, Arya Yazdan Panah1, Théodore Soulier1, Celine Louapre1, Benedetta Bodini1,2, and Bruno Stankoff1,2
1Sorbonne Université, Paris Brain Institute, ICM, CNRS, Inserm, Paris, France, paris, France, 2Department of Neurology, Saint- Antoine Hospital, APHP, Paris, France, paris, France, 3Department of Neurology, Rehabilitation, Ophthalmology, Genetics, Maternal and Child Health, University of Genoa, Genoa, Italy, genoa, Italy, 4Padova Neuroscience Center, University of Padua, Padua, Italy, padua, Italy
Synopsis
Keywords: Multiple Sclerosis, Neuroinflammation, [¹⁸F]-DPA-714, TSPO, Lesion individualization and phenotyping, disease progression
Positron emission tomography
with18kDa-translocator (TSPO) tracers opens the perspective to image
innate immune cells underlying the smoldering component of multiple
sclerosis (MS), that currently mostly escape from MRI evaluation.
Using [
18F]-DPA-714-PET,
we developed a novel lesion TSPO based classification of MS lesions
and showed that an unexpectedly high proportion have a persistent
neuroinflammatory content. A longitudinal follow up of subjects
unraveled that this lesional smoldering component predicted atrophy
and clinical progression. Following the acute phase, most lesions may
therefore develop a chronic inflammatory component which can persist
for several years, subsequently promoting neurodegeneration and
clinical progression in MS.
Introduction
Several
post-mortem investigations described a large heterogeneity in white
matter (WM) lesions when it comes to their inflammatory composition
in people with multiple sclerosis (PwMS).¹ ²
A subtype of lesion with a persistent inflammatory component as
reflected by activated innate immune cells that are localized on the
border or widespread within the lesion have been linked to the
severity of the disease.¹ ³
As current MRI sequences do not specifically quantify innate immune
cells, little is known about
their contribution to disease evolution in vivo. In this study with
the aim to
unravel the prognostic value of persisting neuroinflammation in MS
lesions, we developed a 18kDa-translocator-protein-PET based
classification of each lesion according to innate
immune cell content and localization
and assessed the respective predictive value of lesion phenotype on
atrophy and disability progression over 2 years.Methods
We analyzed
36 PwMS (12 relapsing-remitting MS RRMS; 13 secondary progressive MS,
SPMS; 11 primary progressive MS) and 19 healthy controls (HC), who
underwent a dynamic [18F]-DPA-714 PET at baseline. At baseline
and 2 years of follow-up, PwMS underwent MRI and were clinically
evaluated with the Expanded-Disability-Status-Scale (EDSS). We
calculated the EDSS-stepwise-change and classified patients with
clinical worsening (EDSS-stepwise-change>0)
or clinically stable at 2 years of follow up.
The MRI
protocol included the following sequences: 3-dimensional T1-weighted
magnetization-prepared rapid gradient-echo (3D-T1 MPRAGE, TR/TE
2300/2.98 ms, inversion time 900 ms, resolution 1.0×1.0×1.1 mm³),
T2-weighted (T2-w, TR/TE 4000/83 ms, resolution 0.9×0.9×3.0 mm³),
3-dimensional fluid-attenuated inversion recovery (FLAIR, TR/TE
8880/129 ms, resolution 0.9×0.9×3.0 mm³), and pre- and
post-gadolinium T1-weighted spin-echo (T1SE, TR/TE 650/14 ms
resolution, 1.0×1.0×3.0 mm³.
In PwMS,
hyperintense WM lesions were manually segmented, and probability
masks were generated using Jim (v6.0, http://www.xinapse.com/) based on T2-w intensities in lesions.
To improve individual lesion detection within areas of confluence, we
detected clusters resembling the center of each lesion by calculating
the hessian matrix of the probability mask,⁴
as demonstrated in figure 1-A. Once Individualized, lesions were
registered to the standard space
(Montreal
Neurological Institute [MNI152 09c sym]) and gadolinium enhanced and
small lesions were removed from further analyses.
The
PET protocol consisted of an intravenous bolus injection of 198.4 ±
22.9 MBq of [18F]-DPA-714
at the beginning of a 90-min dynamic acquisition.
Images
were reconstructed using the 3D ordinary Poisson ordered subset
expectation maximization algorithm and the point spread function was
modeled within the reconstruction to minimize partial volume effect
(PVE).⁵
Applying
the Logan graphical method for DPA-PET distribution volume ratio
(DVR) calculation,⁵
a threshold to define the presence of significant inflammation in an
area (rim/center with a volume >50 mm³, figure 1-B) was
calculated based on a comparison between PwMS and HC in the standard space.⁶
Each lesion
was classified with a regard to whether the persisting inflammation
is present in the rim or the center. We defined 3 lesions subtypes:
homogeneously-active (lesion’s center classified “active”),
rim-active (“inactive” center with an “active” perilesional
rim) or non-active as illustrated in figure 1-C. We measured
longitudinal atrophy using the Jacobian Integration method⁷
and we defined patients who will develop pathological cortical
atrophy in the coming 2 years (atrophy>0.41%).⁸Results
Out of 1335
non-gadolinium enhanced MS lesions, 53% were classified
homogeneously-active (median:17/PwMS), 41% non-active (14/PwMS) and
6% rim-active (1/PwMS). both homogeneously-active and rim
active-lesions were more frequent in patients in the progressive form
compared with the relapsing form as shown in figure 2-A and 2-B. The
number of homogeneously active lesions was the strongest predictive
metric of longitudinal brain atrophy (beta =0.44, p=0.018), cortical atrophy
(rho=0.43, p=0.024) and EDSS-stepwise-change (rho=0.37, p=0.025).
Both Homogeneously active and rim active were more frequent in
patients with a pathological cortical atrophy compared to the rest of
the cohort (homogeneously-active: median in patient with pathological
cortical atrophy =27.5, median in patients without pathological
cortical atrophy= 10, p=0.025 figure 2-C; rim-active: median in
patient with pathological cortical atrophy= 4, median in patients
without pathological cortical atrophy = 0.5, p = 0.038 figure 2-D). Only homogeneously active lesions were significantly more
frequent in patients with clinical worsening compared to clinically
stable (homogeneously-active: median in patients with clinical
worsening = 28.5, median in clinically stable patient = 9.5, p =
0.013 figure 2-E and 2-F).Conclusion
[18F]-DPA-714-PET
revealed that an unexpectedly high proportion of MS lesions have a
smoldering component, which predicts atrophy and clinical
progression. This suggests that following the acute phase, most
lesions develop a chronic inflammatory component which can persist
for several years, promoting neurodegeneration and clinical
progression.Acknowledgements
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