Yujian Diao1,2,3, Catarina Tristão Pereira2,4, Ting Yin2, and Ileana Ozana Jelescu2,5
1Laboratory of Functional and Metabolic Imaging, Ecole Polytechnique Fédérale de Lausanne, Lausanne, Switzerland, 2CIBM Center for Biomedical Imaging, Lausanne, Switzerland, 3Animal Imaging and Technology, Ecole Polytechnique Fédérale de Lausanne, Lausanne, Switzerland, 4Faculdade de Ciências da Universidade de Lisboa, Lisbon, Portugal, 5Department of Radiology, Lausanne University Hospital, Lausanne, Switzerland
Synopsis
Impaired
brain glucose consumption is a possible trigger of Alzheimer’s disease (AD).
Previous work revealed affected
brain structure and function by insulin resistance in terms of functional
connectivity and white matter microstructure in a rat model of AD. Here,
functional and structural metrics were further used to classify Alzheimer’s from
control rats using logistic regression. Our study highlights the
MRI-derived biomarkers that best discriminate Alzheimer’s vs control rats early
in the course of the disease, with potential translation to human AD.
Introduction
Impaired
brain glucose consumption is a possible trigger of Alzheimer’s disease (AD)1. Brain insulin resistance and
AD-like features can be
induced in animals by an intracerebroventricular (icv) injection of streptozotocin (STZ)2–4. However, how brain insulin
resistance affects neurodegeneration is not fully understood.
We
performed a longitudinal study in the icv-STZ rat model to characterize
alterations in functional connectivity (FC) and white matter (WM)
microstructure using functional and diffusion MRI. Functional and structural
metrics were further used to classify STZ from control rats using logistic
regression (LR) and the importance of each feature was quantified.
Our
study highlights the MRI-derived biomarkers that best discriminate Alzheimer’s
vs control rats early in the course of the disease, with potential translation
to human AD.Methods
Experimental: All experiments were approved by the local
Service for Veterinary Affairs. Resting-state fMRI and diffusion MRI
data were acquired longitudinally at four timepoints (2, 6, 13 and 21 weeks
since icv injection) (see Fig. 1 for details).
Processing: FMRI data processing
followed the PIRACY pipeline5. FC matrices between 28
atlas-based ROIs were computed, co-varying for the global signal5. Diffusion MRI images were
denoised6, Gibbs-ringing corrected7 and EDDY-corrected8. Diffusion and kurtosis
tensors were calculated9 to extract typical metrics (AxD/RD,
axial/radial diffusivity, MK/AK/RK, mean/axial/radial kurtosis) and the
WMTI-Watson model10 parameters (axon diffusivity $$$D_a$$$,
density f, and dispersion $$$c_2$$$, extra-axonal
diffusivities $$$D_{e,||}$$$/$$$D_{e,⊥}$$$) were estimated in WM voxels. Corpus callosum, cingulum
and fimbria were automatically segmented using atlas-based registration. Tensor
and model metrics were averaged in each ROI. Group differences were tested
using t-test.
Classification: For fMRI-based
classification, FC matrices were vectorized by keeping only the upper triangle
so that each vector consisted of 378 correlation coefficients of each ROI pair
as features. Datasets were grouped as all timepoints (Pooled, N=162), or
Early (2&6 weeks, N=94) and Late (13&21 weeks, N=68).
STZ/CTL classification using LR was trained and tested on each subset (Pooled,
Early, Late), randomly split into training (70%) and test datasets (30%). In parallel, CTL/STZ functional connectivity differences
in Pooled, Early and Late datasets were tested using non-parametric permutation
tests (N=5000) with NBS11 and significant edges were
extracted.For
diffusion MRI-based classification, the datasets (N=83) were randomly split into training (70%) and test sets (30%).
Diffusion and kurtosis tensor metrics (N=5)
and WMTI-Watson model parameters (N=5)
in the 3 WM ROIs were first combined as features to classify STZ and CTL rats.
Second, they were separated as two feature vectors (DKI only and WMTI-Watson
only) and used independently in classification. Results
FC-based classification: When using all edges as features (N=378), accuracy on
the Pooled, Early and Late datasets was 0.75, 0.69 and 0.83, respectively. The
most relevant edges involved the anterior cingulate cortex (ACC), hypothalamus,
retrosplenial cortex (RSC), hippocampus and subiculum (Fig.
2) and correspond to edges found as significantly different between groups in
the NBS analysis (Fig. 3A).
In order to reduce dimensionality, significant edges from the
NBS analysis were selected as a reduced list of features for classification (N=49,
38 and 71 features in the Pooled, Early and Late datasets, respectively). Classification
accuracy improved to 0.79 for Pooled, 0.72 for Early and 0.90 for Late datasets
(Fig. 3B). Improved accuracy was not strictly related to feature reduction:
reducing features based on principal component analysis deteriorated
classification accuracy (data not shown). However, the top 10 features
identified in Fig. 3B did not have strong overlap with the top 10 features
identified previously (Fig. 2).
Diffusion-based classification: accuracy was 0.84, 0.80 and
0.84 on data using WMTI+DKI, DKI and WMTI features, respectively. The microstructure
features that best enabled classification included f, FA and RD in fimbria (Fig.
4A). Those metrics also showed significant group differences (Fig. 4B).Discussion and Conclusions
When using FC to classify STZ/CTL rats, the most important discriminating features were
edges involving the RSC, ACC, Subiculum and Hippocampus, which are regions of
the default mode network typically affected by AD12–14, as well as the Hypothalamus which is responsible for
recruiting alternative sources of energy to glucose, such as ketone bodies15–19. The classification accuracy was improved in the Late vs Early
timepoint, due to neurodegeneration progression. However, if only choosing
connections significantly different between groups (using NBS) as features,
mean classification accuracy naturally improves. In other words, edges
identified as driving group differences after diagnosis could be used as
features for classification in future diagnostic-blind studies.
For classification based on WM microstructure, the
performance using features from a biophysical model only (here WMTI-Watson) was
similar to using Pooled features (WMTI-Watson + DKI) and better than only using
DKI features. This suggests biophysical models have added value over empirical
tensor metrics in characterizing WM degeneration and classifying subjects. Microstructural
features in the fimbria played the most important roles in distinguishing STZ
rats, which was consistent with the fact that hippocampus is especially
vulnerable to AD20,21.
By classifying STZ rats from CTL rats using LR, we
highlighted the potential of FC and WM microstructure metrics in the diagnosis
of AD-related neurodegeneration, with possible translation to human studies.Acknowledgements
The authors thank Analina Raquel Da Silva, Mario Lepore and Stefan Mitrea for assistance with animal setup and monitoring, and acknowledge access to the facilities and expertise of the CIBM Center for Biomedical Imaging, a Swiss research center of excellence founded and supported by Lausanne University Hospital (CHUV), University of Lausanne (UNIL), Ecole polytechnique fédérale de Lausanne (EPFL), University of Geneva (UNIGE) and Geneva University Hospitals (HUG).References
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