Minhui Ouyang1,2, John Detre3, Jessica L Hyland1, Kay Laura Sindabizera1, Yun Peng4, J. Christopher Edgar1,2, and Hao Huang1,2
1Department of Radiology, Children's Hospital of Philadelphia, Philadelphia, PA, United States, 2Department of Radiology, Perelman School of Medicine, University of Pennsylvania, Philadelphia, PA, United States, 3Department of Neurology, Perelman School of Medicine, University of Pennsylvania, Philadelphia, PA, United States, 4Department of Radiology, Beijing Children’s Hospital, Capital Medical University, Beijing, China
Synopsis
Infancy is one of the most prominent times of daily energy expenditure
across the lifespan. Here, using cutting-edge pCASL with high-resolution at isotropic 2.5mm and phase-contrast MRI, we delineated the developmental trajectory
of the infant’s global and regional cerebral blood flow (rCBF) supporting the
metabolic needs for brain development in 0-28months. Significant age-related CBF increases during infancy were better
modeled with biphasic linear models, with break-point ages observed earlier in
sensorimotor and auditory cortices and later in association cortices. The established
population-averaged rCBF maps across infancy can serve as normative rCBF
atlases for neuroscientific research or clinical care.
Introduction
Infancy, especially from birth to 12 months of age, is one of the most prominent
times of daily energy expenditure across the lifespan1. The adjusted
total expenditure increases rapidly during infancy, with a break point around
0.7 years of age1. The infant brain consumes greater than 20% of
total body metabolism 2,3 to meet the high energy needs for striking
development4. Cerebral blood flow (CBF) is closely related to regional
metabolism 5,6. Delineating the developmental
pattern of global and regional CBF (rCBF) during infancy may provide insight
into the physiological basis of brain development during this critical stage. Here,
we sought to determine the normative developmental pattern of infant global CBF
obtained from phase-contrast MRI, as well as high-resolution rCBF with
isotropic 2.5mm, acquired with a 3D multi-shot, stack-of-spirals pseudo-continuous
arterial spin labeled (pCASL) sequence optimized for infant brains.Methods
Infant subjects and acquisition of perfusion
pCASL and phase-contrast MRI:
Phase-contrast (PC) MRI was acquired in 99 typically developing infants (51M/48F,
age range: 0 to 28 months) at 4 feeding arteries to quantify global CBF 7 (Fig.
1). High-resolution ASL images were acquired in forty-three of these infants with
a 3D multi-shot, stack-of-spirals pCASL sequence 8,9 in a 3T Siemens
Prisma system. The pCASL MRI parameters were: four-shot acquisition, field of
view = 192×192 mm2, matrix = 76×76, in-plane resolution = 2.53×2.53
mm2, 48 slices, slice thickness = 2.5 mm, no gap between slices,
labeling duration=1600ms, post labeling delay (PLD) = 1800ms, center of
labeling slab located between cervical vertebrae C2 and C3 (Fig. 1), repetition
time = 4s, echo time = 12ms, number of controls/labels = 10 pairs. In addition,
high-resolution T1-weighted images (T1w) with a voxel size of 0.8 mm3
were acquired. rCBF quantification:
rCBF were calculated using the single-compartment model 10:$$$ rCBF=(6000*\lambda\cdot\triangle M*exp(\frac{PLD}{T_{1a}}))/(2\alpha\cdot M_b^0\cdot {T_{1a}}\cdot(1-exp(\frac{-LabelDur}{{T_{1a}}}))) $$$ where ΔM is the
difference between dynamic-averaged signal intensity in the control image versus
the label image; labeling efficiency was assumed to be 0.85, and blood T1 value
of arterial blood was assumed to be 1800ms11, $$$ M_b^0 $$$values were estimated with the M0 images from
the acquisition. Establishment of
population-averaged rCBF maps: All infants’ rCBF maps were mapped to
the JHU atlas space 12. Briefly, infants’ T1w images were first
registered to their M0 images in the native CBF space. Then, a 12-parameter
affine registration transformed the co-registered T1w image of each infant to
the template T1w image in the JHU atlas space, followed by a non-linear
transformation. Six population-averaged rCBF maps across infancy (age-groups: 0-3, 3-6, 6-9, 9-12, 12-18 and 18-28 months)
were then generated. Age-related
changes in global and regional CBF: Trajectories of age-related CBF
changes were modeled using biphasic linear regression. Clustering of rCBF across cortex: A data-driven clustering
approach based on nonnegative matrix factorization (NMF) identified the
cortical voxels with similar rCBF changing patterns 13,14.Results
The developmental trajectory of global CBF during infancy was better
fitted with a biphasic linear model than a linear model (ANOVA, F(2,97)=12.89,
p<1.2x10-5). As shown in Fig. 2, the global CBF values demonstrated
significant age-related increases (r=0.768, p<6.5×10-8).
Specifically, global CBF rose at a rate of 3.49ml/100g/min per month from birth
to the break point at 9.8 months of age, followed by sequentially slower change.
Fig. 3 shows high-resolution population-averaged rCBF maps from six
representative infant age groups. RCBF increases can be seen from the
representative axial slices across age groups. Distinct rCBF distribution
patterns at different ages are easily observed after mapping to the template cortical
surface. Whereas in younger age groups high
rCBF values are prominent in the primary auditory/sensorimotor cortices (white
arrows in Fig. 3), in the older age groups high rCBF values are located in the
frontal and parietal cortices. To reveal the rCBF development pattern across the
cortex, instead of using cortical parcellations predefined based on adult brains,
we adopted the NMF method on rCBF maps. Five distinct clusters were identified
(Fig. 4A). Similarly, rCBF trajectories reproduced the biphasic pattern seen in
the analysis of global CBF trajectory, with the age break point varying across
clusters (Fig. 4B). Notably, a younger break-point age of 6.6months was
observed in cluster 2 (sensorimotor cortices) and cluster 3 (primary auditory cortex).
Clusters 4 and 5 were located predominately in the frontal and parietal
cortices, and had a break point at 11.2 and 7.8months respectively. Cluster 1,
covering primary visual and visual association areas, had a later break point
at 11.8months. Discussion and conclusion
The present study demonstrated that CBF increases
during early infancy in a biphasic fashion. Interestingly, the global CBF had a
similar rise and break point as the adjusted total expenditure during infancy1,
consistent with the notion that much of infant whole-body metabolism is
dedicated to brain development15. The break point of rCBF increases varied across the cortex - earlier in primary
cortices and later in association cortices. Using an optimized infant pCASL protocol with isotropic 2.5mm
resolution, the established
population-averaged rCBF maps throughout infancy can serve as normative rCBF
atlases for neuroscientific research or clinical pediatric care. Analysis to
determine the optimal rCBF cluster number is underway. Acknowledgements
This study is funded
by NIH MH092535, MH092535-S1, MH123930, EB031284 and HD093776.References
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