Lucas Soustelle1,2, Andreea Hertanu1,2, Arnaud Le Troter1,2, Soraya Gherib1,2, Samira Mchinda1,2, Patrick Viout1,2, Lauriane Pini1,2, Claire Costes1,2, Sylviane Confort-Gouny1,2, Adil Maarouf1,2,3, Bertrand Audoin1,2,3, Audrey Rico1,2,3, Clémence Boutière1,2,3, Maxime Guye1,2, Jean-Philippe Ranjeva1,2, Gopal Varma4, David C. Alsop4, Jean Pelletier1,2,3, Olivier M. Girard1,2, and Guillaume Duhamel1,2
1Aix Marseille Univ, CNRS, CRMBM, Marseille, France, 2APHM, Hôpital Universitaire Timone, CEMEREM, Marseille, France, 3APHM, Hôpital Universitaire Timone, Service de neurologie, Marseille, France, 4Division of MR Research, Radiology, Beth Israel Deaconess Medical Center, Harvard Medical School, Boston, MA, United States
Synopsis
Active lesions in Multiple
Sclerosis (MS) present successive phases, from formation through their chronic
stage. Characterizing these phases may help us better comprehend the disease
evolution. In this work, multiparametric MRI was performed in a 12-month
longitudinal study of MS patients presenting new active lesions. An exponential
recovery model was proposed to characterize the evolution of MR metrics in these
lesions, allowing derivation of the recovery rates of inhomogeneous MTR,
conventional MTR, DTI and T1-weighted images. Results show that recovery
capacities are patient-dependent and that metrics differ in performance, presumably
due to their respective sensitivity to the underlying MS mechanisms.
Introduction
Multiple
sclerosis (MS) is a chronic inflammatory and demyelinating disease of the
central nervous system, characterized by focal areas of tissue damage. These
lesions present singular phases from their formation to their chronic stage,
characterized by several features such as blood-brain barrier disruption,
microglial activation, edema and inflammation, axonal loss, demyelination and
remyelination1. From the
acute active phase to stabilization, it is expected that lesion myelination and
inflammatory characteristics should vary in a positive manner2, and that
this evolution can be assessed in MR imaging.
The inhomogeneous magnetization transfer (ihMT)
technique3 whose
contrast relies on its capacity to isolate dipolar order effects4,5, was
previously proposed as an imaging technique sensitive and highly specific to
myelination6,
demyelination and remyelination7. The ihMT
ratio (ihMTR) also demonstrated a sensitivity to the MS pathology8.
In this work, we investigate the contribution of the
ihMTR for monitoring and characterizing the dynamic evolution of active MS
lesions over a 12-month period starting at detection. A comparison with conventional
MTR, radial diffusivity (RD) and the T1-weighted (T1w) signal intensity from an MPRAGE sequence was performed.Methods
Eleven relapsing-remitting
MS patients presenting new active lesions received follow-up scans with a 3D MRI protocol five times over twelve
months (M0, M2, M4, M6 and M12)
on a 1.5T MRI system (Avanto, Siemens Healthineers, Erlangen, Germany) with
body coil transmission and a 32-channel receive-only head coil. The protocol
included a T1w-MPRAGE, T2w-FLAIR and multiparametric imaging (Table 1). MS
patients (demographics in Table 1) were included based on the occurrence of
brain active lesions at baseline from T1w contrast-enhancement post Gadolinium
injection.
For each subject, all
images were rigidly co-registered onto their respective anatomic T1w-MPRAGE
volume using the
Advanced Normalization Tools (ANTs)9. Active and non-active lesions’ masks were manually
segmented on the FLAIR image. Active lesions were further segmented into two clusters
using Atropos10 based on the MPRAGE signal at baseline11: the lesion's core is defined as the cluster with the highest
contrast with respect to the normal-appearing white matter (NAWM), and the
lesion’s edge as the other cluster (Figure 1). NAWM masks were computed from
the MPRAGE image using FreeSurfer12, excluding all lesions. Lesions’ edge was discarded from the
analyses to focus on the seemingly most affected core region on a T1w basis.
Twenty-three active
lesions were selected for the analysis. The time evolution of ihMTR, MTR, RD
and MPRAGE signals was investigated by calculating the Relative Variation to a
Contralateral region (RVtoC), chosen in NAWM:
$$\text{RVtoC}(t_i)=\frac{P_i-P_i^C}{P_i^C}~~~~\text{(1)}$$
where $$$P_i$$$ and $$$P_i^C$$$ are the average metric values at a given
timepoint $$$t_i$$$ calculated over the lesions’ core and over the corresponding
contralateral region, respectively.
An exponential recovery
model was proposed to fit the time evolution of all MR metrics:
$$\text{RVtoC}(t)=(\text{RVtoC}(t_0)-A)\times e^{-R(t-t_0)}+A~~~~\text{(2)}$$
where $$$A$$$ is the long-time RVtoC
asymptotic value and $$$R$$$ denotes the recovery rate of the metric. Only lesions
for which the coefficient of determination (ρ²) was higher than 0.75 for all
metrics were considered for analysis.
Results
Figure 2 shows boxplots of
MR metrics in the core of lesions at different time points. At baseline, ihMTR presented the highest median relative variation to contralateral
NAWM (RVtoC=-38.6%) compared to RD (RVtoC=-32.6%), MTR (RVtoC=-28.3%) and
MPRAGE (RVtoC=-26.3%). Significant differences in RVtoC values were found
between M0 and M4, M6 and M12 for all metrics (Kruskal-Wallis; corrected p<0.05),
whereas no difference was found between M0 and M2 except for the MPRAGE signal.
Figure 3 shows an example
of RVtoC values fitted to the exponential model for ihMTR (3a) and barplots of
recovery rates derived from all metrics and averaged across lesions for each patient
(3b). ihMTR yielded the most uniform values across patients, spanning from 0.12
to 1.26 month-1, whereas conventional MTR and RD showed much wider
dispersion spanning from 0.17 to 4.18 and 0.28 to 12.80 month-1,
respectively. No correlation (Pearson) was found between recovery rates derived from
MPRAGE and ihMTR. Conversely, significantly low correlations were found between
MPRAGE and MTR (r²=0.27, p<0.05) and MPRAGE and RD (r²=0.44, p<0.05). Of
interest, patient P07 presented the highest recovery rate for ihMTR, but the
lowest one for MTR.
Discussion and conclusion
Among all metrics, ihMTR
showed the most uniform recovery rates across patients. In light of improved
specificity of ihMTR for myelin content6, it could be postulated that ihMTR describes a myelin
recovery dynamics, and that the variability of other investigated contrasts
could be explained by additional sensitivity to other physiopathological
mechanisms.
Overall, the presented
recovery rate methodology can be employed for MS lesion characterization of
both inflammation/edema and demyelination/remyelination processes, and these promising
results could be further validated in vivo by use of myelin-specific PET markers
such as the Pittsburgh compound B13.Acknowledgements
This
work was supported by the SATT Sud-Est (France), the French Association pour la
Recherche sur la Sclérose En Plaques (ARSEP), Roche Research Foundation
(Switzerland) and French National Research Agency, ANR [ANR‐17‐CE18‐0030].References
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