Zahra Hosseinpour1, Olayinka Oladosu2, Mahshid Soleymani1, G Bruce Pike2, and Yunyan Zhang2
1Biomedical Engineering program, Schulish School of Engineering, University of Calgary, Calgary, AB, Canada, 2Department of Radiology and Clinical Neurosciences, Hotchkiss Brain Institute, University of Calgary, Calgary, AB, Canada
Synopsis
Multiple sclerosis (MS) lesion characterization using
MRI is valuable for monitoring MS and probing remyelination therapies. However,
there is a lack of in-vivo MRI metrics in clinical studies. We assessed MS
lesion types using statistical texture measures of advanced and conventional
MRIs, accompanied by random forest classification and percentile
statistics, to differentiate MS lesions based on myelination. The best texture parameters
and percentiles that classified re- and de-myelinated lesions were derived from
histology-verified MRI. Applying the
established parameters from postmortem to in-vivo MRI identified two types of
lesions: highly demyelinated and potentially remyelinated.
Introduction
Multiple sclerosis (MS) is an inflammatory
demyelinating disease of the central nervous system, characterized by a variety
of pathological components including demyelination and remyelination1.
This makes lesion properties highly heterogenous2,3 and difficult to
characterize in-vivo. There are various studies searching for MRI
biomarkers of de- and re-myelination in MS using advanced MRI4,5. However,
there is still lack of MRI metrics to measure MS lesion types in clinical
studies. Here, we aimed to evaluate
lesion types, including de- and re-myelination, using texture analysis of advanced
and conventional MRIs in postmortem MS patients, and then, using knowledge generated from postmortem data,
in living MS patients. This is beneficial to monitor
disease development or remyelination treatment. Method
In postmortem assessment, texture analysis was
conducted on fresh postmortem MRIs from 15 MS patients. MS tissue included de-
and re-myelinated lesions and normal appearing areas in white and grey matter plus
diffusely abnormal white matter. Texture maps were calculated from
T2-weighted MRI (TR = 4000 ms, TE =
19.1/38.2/57.3, FOV=100×80mm2 , matrix=1000×80) and diffusion
tensor MRI (b=1500, 30 directions, FOV=100×80mm2 ,
matrix=50×40). The former used a grey level co-occurrence
matrix (GLCM) method, with measures including angular second moment (ASM),
entropy, contrast, correlation, dissimilarity, and an entropy filter. In
diffusion texture analysis, we interpolated the number of diffusion directions
from the initial 30 to 90 prior to texture analysis. A new voxel-based approach was employed to
calculate ASM and entropy maps from diffusion MRI6. For comparison,
we included advanced MRI measures, such as fractional anisotropy (FA) from diffusion MRI and magnetization transfer ratio
(MTR). A random forest (RF) algorithm with cross-validation
was used for classifying MS tissue types including de- and re-myelinated
lesions. Subsequently, employing a feature ranking algorithm, recursive feature
elimination (RFE), the most predictive parameters were selected (Figure1). Classification
accuracy was assessed using kappa statistics, where higher kappa represents
more reliable accuracy7. Afterwards, we applied a percentile
approach, using the best parameters selected by the RFE and cross-validated RF algorithm,
to determine how they differentiate highly demyelinated lesions from
remyelinated ones. Percentiles tested were: 15th, 20th,
and 25th for remyelinated lesions, and percentile >75% were used
to define highly demyelinated lesions, similar to the literature8.
For In-vivo analysis, FLAIR MRI (TR/TE = 6000/84 ms, FOV=240×240mm2 , matrix =512 x512) was
used to calculate texture maps from 70 relapsing-remitting MS (RRMS) patients participated
in a clinical study (Figure 2). In-vivo lesion segmentation was done employing
LST9, on registered FLAIR to T1-weighted MRI. Diffusion tensor
imaging was also conducted in-vivo and diffusion texture metrics were calculated
using the same approach as ex-vivo. Mean texture values were calculated in
lesions for further analysis. Based on the best parameters and the associated percentile
threshold selected from the histology-verified data, we evaluated in-vivo data from
the RRMS patients. Similarly, in-vivo lesions were divided into highly
demyelinated and potentially remyelinated. Results
We had moderate to near perfect accuracy (kappa: 0.55 - 0.94) in
classifying different tissue types including de- and re-myelinated lesions employing
RF in postmortem analysis of MRI texture. Contrast and dissimilarity were the
most important parameters and followed by entropy, and entropy filter (Table
1). The 25th percentile of
contrast and dissimilarity showed the most accuracy for detecting re-myelinated
lesions (Figure 3). Using the 75th percentile threshold, 29.5% of
postmortem white matter lesions were categorized as highly demyelinated.
Utilizing these parameters
on in-vivo data, contrast values lower than the 25th percentile
resulted in 2391 (24.8%) lesions as potentially
remyelinated lesions, which were seen in 98.5% of patients. Using both contrast and
dissimilarity values lower than the 25th percentile, we found 11% of
lesions as potentially remyelinated, which were found in 87% of patients
(Figure 4). However, the percentage of lesions identified as remyelinating varied
significantly across patients. Employing contrast values higher than the 75th
percentile, we found 2412 lesions (25%) as highly demyelinated across all
patients. When considering both contrast and dissimilarity values higher than
75th percentile, we categorized 6% of lesions as highly demyelinated.
More than 78% of patients had this type of lesions (Figure 4). Discussion
We utilized texture analysis to differentiate highly demyelinated and
potentially remyelinated MS lesions. The approach was validated using histology-verified
data first and then applied to in-vivo data. We found that most MS patients
possess both types of lesions, but with different proportions, (0-38)%: potentially
remyelinated, and (6-41)%: highly demyelinated lesions. This is consistent with
a recent study that found both types of MS lesions, regarding the severity of
the lesions, existed in most of their subjects5. Using contrast and
dissimilarity, we detected 10-25% of lesions as potentially remyelinated, which
is accordant with that reported in the literature10. The two lesion
types identified here, may be useful to monitor the disease or treatment by estimating
the level of damage or repair in lesions. Conclusion
Texture analysis
of conventional MRI is promising for detection of MS lesions with de- or
re-myelinated alteration. The approach proposed here to
detect potentially
remyelinated lesions may become a valuable MRI biomarker for
in-vivo studies to monitor disease progression or remyelination treatment. The
association between the proportion of the detected lesion types and clinical disability
deserves further investigation.Acknowledgements
This research was funded by Natural Science and
Engineering Council of Canada (NSERC), MS Society of Canada, and Alberta
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