Oliver C. Kiersnowski1, Gavin P. Winston2,3, Emma Biondetti1,4, Sarah Buck2, Lorenzo Caciagli2,5, John Duncan2, Karin Shmueli1, and Sjoerd B. Vos6,7
1Department of Medical Physics and Biomedical Engineering, University College London, London, United Kingdom, 2Department for Clinical and Experimental Epilepsy, University College London, London, United Kingdom, 3Department of Medicine, Division of Neurology, Queen's University, Kingston, ON, Canada, 4Institut du Cerveau – ICM, INSERM U 1127, CNRS UMR 7225, Sorbonne Université, Paris, France, 5Department of Bioengineering, University of Pennsylvania, Philadelphia, PA, United States, 6Centre for Medical Image Computing, Computer Science Department, University College London, London, United Kingdom, 7Neuroradiological Academic Unit, UCL Queen Square Institute of Neurology, University College London, London, United Kingdom
Synopsis
Although temporal lobe epilepsy (TLE) results in
widespread changes in MRI measures of tissue volume, diffusion and functional
connectivity, changes in tissue composition in TLE have not been investigated
with MRI. Quantitative susceptibility mapping (QSM) is sensitive to changes in tissue composition, in particular to
iron and myelin. Here, we show for the first time that QSM is sensitive to gray
matter abnormalities in 31 patients with temporal lobe epilepsy (TLE) compared to 23 healthy controls, and showed
significant susceptibility changes in the hippocampus in left TLE patients, and
in the bilateral thalamus in both left and right TLE.
Introduction
Hippocampal sclerosis (HS) is
the most common cause of drug-resistant temporal lobe epilepsy (TLE). Despite
focal pathology in the hippocampus, the disease results in widespread
alterations, with previous studies showing cortical and subcortical volumetric changes1,
alteration of white matter diffusion properties2, and functional connectivity
changes3. However, the sensitivity of prior work to alterations in
tissue composition has been limited. Recently, quantitative susceptibility
mapping (QSM) has been used in pediatric epilepsy patients with focal cortical
dysplasia to reveal changes in tissue calcium, zinc and iron content4.
Here, we extended the application of QSM in epilepsy to investigate susceptibility
differences in deep gray matter regions in temporal lobe epilepsy (TLE)
patients with hippocampal sclerosis (HS).Methods
We included 31 TLE patients with
unilateral HS (mean age 38.5
years, range 19-67 years; 20 female; 17 LTLE / 14 RTLE) who attended our
MRI unit for routine examination. We also included 23 healthy controls (mean age 29.4 years, range 17-55 years; 16
female).
Subjects underwent imaging on a
3T General Electric Discovery MR750 scanner with a 32-channel coil. Sequences
included a three-dimensional (3D) T1-weighted inversion-recovery fast spoiled
gradient recalled echo (TE/TR/TI=3.1/7.4/400 ms, field of view (FOV)
224×256×256 mm, matrix 224×256×256, 1 mm isotropic voxel size, parallel imaging
acceleration factor 2) and a multi-echo 3D gradient echo (SWAN) sequence,
saving full complex data (TE1/ΔTE/TE5=12.9/5.0/32.8
ms, TR=37.1 ms, flip angle=15°,
FOV=200×200×137 mm, matrix=384×384×114, reconstructed to a voxel size of=0.52×0.52×0.60
mm).
The 3D-T1 images were
segmented using GIF5 to obtain regions of interest (ROI) in the
amygdala, caudate, globus pallidus, putamen, and thalamus. Hipposeg6 was used to accurately segment the hippocampus in the presence of hippocampal pathology. The T1-weighted image was rigidly registered
using Niftyreg7 to the first-echo magnitude image of the QSM (SWAN) data.
For each subject, a total
field map and a noise map were obtained from a non-linear fit8,9 of the
multi-echo complex SWAN data over all echo times. Residual phase wraps were
removed with Laplacian unwrapping9,10. A brain mask $$$m$$$ was calculated using Otsu thresholding11
and thresholded at the mean of the inverse noise map to remove noisy voxels, except
within the ROIs. To account for oblique slice acquisition12, the
image volume was rotated into alignment with the main magnetic field $$$\mathbf{\hat{B}}_0$$$, using Niftyreg7
with trilinear interpolation13. Background fields were
removed with projection onto dipole fields (PDF)9,14. Susceptibility ($$$\chi$$$) calculation
was carried out using a non-linear weak harmonic (WH) formulation with total
variation regularisation15 (Eq.1) from the FANSI toolbox16-18:
$$\underset{\chi,\phi_h}{\text{arg min}} \left\Vert W\left( e^{i\left(F^HDF\chi+\phi_h\right)} - e^{i\phi}\right)\right\Vert_2^2 + \frac{\beta}{2}\left\Vert m \nabla^2 \phi_h \right\Vert_2^2 + \alpha \left\vert \nabla \chi \right\vert_1 \tag{1}$$
where $$$W$$$ is a weighting proportional to the magnitude
image, $$$F$$$ is the discrete Fourier transform and $$$F^H$$$ is its adjoint, $$$D=\gamma B_0 TE \left(\frac{1}{3}-\frac{k_z^2}{k^2}\right)$$$ is the dipole kernel in Fourier space, and $$$\phi_h$$$ contains residual harmonic background fields14
remaining after PDF. The WH weight chosen was $$$\beta$$$=150, ensuring that no
structural information was contained in $$$\phi_h$$$. An L-curve-based zero-curvature search19 ($$$\alpha$$$ values from 0.0631 to 3.9811×10-5) gave
an optimised $$$\alpha$$$=5.024×10-4. A
convergence tolerance of 0.1 was chosen with a maximum of 500 iterations. The
image volume was rotated back to the original orientation after $$$\chi$$$ calculation. This WH-QSM technique was used to reduce noise (due to the high resolution) and residual
background fields relative to iterative Tikhonov QSM20 (Fig. 1).
Based on the significant
difference in age between the groups (ANOVA p<0.01) mean ROI susceptibility
values were corrected for age, based on least-squares linear fits in the
healthy control subjects21. Three-group ANOVA was performed for each ROI to test
for significant mean susceptibility differences between LTLE, RTLE, and control
participants. Additionally, intra-subject left-right differences were
investigated per group with a paired t-test.Results
An example susceptibility map
is shown in Figure 1, alongside a first- and last-echo gradient-echo magnitude image.
The average susceptibility
values for each ROI and group are shown in Table 1, with significant group
differences for both thalami (p=0.024 left, p=0.035 right), left
putamen (p=0.001), and left globus pallidus (p=0.021) as observed
with ANOVA (Figure 2). Post-hoc t-tests revealed that: (i) the RTLE group had
significantly higher susceptibility in the bilateral thalami compared to
controls (p<0.01 left, p<0.05 right); (ii) the RTLE group
had significantly higher susceptibility in the left putamen compared to
controls (p<0.001) and the LTLE group (p<0.01); and (iii) the
LTLE group had significantly lower susceptibility in the left globus pallidus compared
to controls (p=0.013).
We found significant
susceptibility differences between left and right-sided ROIs: (i) in the
caudate (p=0.040) and globus pallidus (p<0.001) in healthy
controls; and (ii) in the hippocampus (p=0.036) in LTLE, with more
negative susceptibility in the pathological hippocampus compared to
contralateral and
control hippocampi (Table 1), a pattern also observed in RTLE, although not reaching significance.Discussion and Conclusion
The observed pattern of higher
susceptibility in the left vs. right globus pallidus and caudate in controls
matches previous findings22. The asymmetry in the hippocampal
susceptibilities in the LTLE group could reflect underlying hippocampal
pathology. The observed susceptibility changes in the thalamus match known
volumetry and connectivity differences in TLE1,3 and could reflect
demyelination. Future work will investigate associations with clinical factors
such as secondarily generalised tonic-clonic seizures.Acknowledgements
Note that KS and SBV contributed equally as senior authors. OCK is supported by the EPSRC-funded UCL Centre for
Doctoral Training in Intelligent, Integrated Imaging in Healthcare (i4health)
(EP/S021930/1). GPW was supported by a Medical Research
Council Clinician Scientist Fellowship (MR/M00841X/1). KS is supported by European
Research Council Consolidator Grant DiSCo MRI SFN 770939. We thank Dr Carlos Milovic for his assistance with FANSI. References
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