Eva Heckova1, Alexandra Lipka1, Assunta Dal-Bianco2, Bernhard Strasser1, Gilbert Hangel1,3, Paulus Rommer2, Petra Hnilicová4, Ema Kantorová5, Lukas Hingerl1, Stanislav Motyka1, Fritz Leutmezer2, Stephan Gruber1, Siegfried Trattnig1,6, and Wolfgang Bogner1
1High Field MR Centre, Department of Biomedical Imaging and Image-guided Therapy, Medical University of Vienna, Vienna, Austria, 2Department of Neurology, Medical University of Vienna, Vienna, Austria, 3Department of Neurosurgery, Medical University of Vienna, Vienna, Austria, 4Biomedical Center Martin, Jessenius Faculty of Medicine in Martin, Comenius University in Bratislava, Martin, Slovakia, 5Clinic of Neurology, Jessenius Faculty of Medicine in Martin, Comenius University in Bratislava, Martin, Slovakia, 6Christian Doppler Laboratory for Clinical Molecular MR Imaging, Vienna, Austria
Synopsis
To enhance the detection of diffuse pathological alterations associated with multiple sclerosis, high-resolution
MR spectroscopic imaging was performed at 7T, together with clinical MRI, in 68 MS patients with different levels of clinical disability and 20 healthy controls. Increased myo-inositol, a marker of
neuroinflammation-induced astrogliosis, was found in white matter regions appearing normal on clinical MRI, even in subgroup of MS patients
with no evidence of clinical disability. Myo-inositol/N-acetylaspartate
ratio in the NAWM and cortical gray matter correlated with EDSS, suggesting that reactive
astrogliosis and axonal injury play important role in the evolution of MS-related disability.
Introduction
Although conventional
MRI has a well-established role in the diagnosis and monitoring of focal
demyelinating activity in multiple sclerosis (MS), it is unable to provide a
full picture of MS pathology in vivo, and
to explain severity of many clinical symptoms, particularly in progressive
phase of the disease1.
MR spectroscopic
imaging (MRSI) can estimate spatial distribution of additional 6-8 neurometabolites
relevant to the MS pathology. Previous MRSI studies reported reduced
N-acetylaspartate (NAA), which reflects reduced neuronal/axonal integrity, and
increased myo-inositol (mI), a marker of astroglial hypertrophy and hyperplasia,
in normal-appearing white matter (NAWM) of MS patients2,3. However, due to limited
spatial resolution and cortical coverage, these metabolic abnormalities could
not be properly visualized and investigation of cortical gray matter (CGM) has
not been feasible at all.
The
aim of this study was to evaluate the disseminated pathology in the NAWM
and CGM using novel 7T ultra-high-resolution MRSI with full in-plane cortical
coverage and an acquisition time of ~6min in a larger cohort of MS patients and to evaluate the association of metabolic abnormalities with clinical
disability.Methods
High-resolution
MRSI, T2-weighted 3D-FLAIR and T1-weighted 3D-MP(2)RAGE were performed at 7T. In
total, 68 MS patients (63 relapsing-remitting/5 secondary-progressive
MS; 32 men/36 women; median age, 32.7 years [range, 20.3-70.5 years]; median
EDSS, 2 [range, 0-7.5]) and 20 healthy controls (eight men/12 women; median
age, 30.1 years [range, 25.4-48]) were examined. Subgroup analysis based on patient’s
EDSS was performed. Detailed characteristics of the study subgroups are
summarized in Figure 1.
Single-slice
FID-MRSI4,5 was performed with
acquisition delay/TR, 1.3/200ms; spatial resolution, 2.2×2.2×8mm3; matrix size,
100×100;
flip angle, 29°; WET water suppression; four-fold 2D-CAIPIRINHA acceleration6; and acquisition time,
6:06min. Automated MRSI data processing was performed with in-house developed
software. This included MUSICAL coil combination7, 2D-CAIPIRINHA
reconstruction, lipid signal removal via L2-regularization8, and LCModel spectral fitting
using a basis set of 17 simulated metabolites and a measured macromolecular
spectrum9.
Metabolic
profiles were calculated within the segmented NAWM and CGM regions created using FAST segmentation and
FLIRT co-registration of FSL package10. Only spectra with a minimum
content of 95% of WM, or 75% of GM, respectively, were analyzed. T2-hyperintense
lesions were carefully excluded from ROIs. Mean metabolic values of segmented
regions were compared among the study subgroups using an analysis of covariance
with age as a covariate, followed by Sidak post-hoc adjustments for multiple
comparisons. Metabolic images were compared visually with MRI. Correlation
analyses between EDSS and mean metabolic values were assessed using Pearson’s
partial correlation coefficient while controlling for age.Results
The
vast majority of lesions were clearly hyperintense on mI/NAA maps. In addition,
with the high-spatial resolution and full cortical coverage, even small
subcortical/juxtacortical lesions could be well visualized (Figure 2A). Increased
mI and reduced NAA were visible also on metabolic images in 33 MS patients
(48%) in NAWM regions with no, or only diffuse, pathology on MRI. In six
patients (9%), increased mI also appeared without a decrease in NAA (Figure 2B).
Metabolic
ratios in NAWM of MS patients were significantly altered compared to normal WM
in healthy controls (HC)(Figure 3). Mean mI/tCr and mI/NAA were significantly
increased in centrum semiovale by +14%/+19% (both P<0.05) in subgroup of patients with no clinical disability
(EDSS 0-1), by +23%/+36% (both P<0.01)
in patients with mild disability (EDSS 1.5-3) and by +22%/+42% (both P<0.01) in severely disabled patients
(EDSS 3.5+). Mean NAA/tCr was decreased by up to -14% in subgroups of patients
with mild (EDSS 1.5-3) and severe disability (EDSS 3.5+)(both P<0.05). Elevated mI/tNAA, mI/tCr and decreased
NAA/tCr were also observed in the parietal and frontal NAWM, but statistically
significant differences from the HC were reached only in groups of patients
with EDSS 1.5-3 and with EDSS 3.5+ (Figure 4A).
The
cortical GM was less affected than the NAWM. Metabolic alterations of mI/NAA
(~+20%,P<0.01) and NAA/tCr (~-15%,P<0.05) were observed in subgroups of
patients with clinical disability in cingulate cortex, but also in the frontal
and parietal CGM (Figure 4B).
Mean
mI/NAA correlated significantly with clinical disability, as measured by the
EDSS, in the centrum semiovale (r=0.49,P<0.001)
and other NAWM and CGM regions (Figure 5).Discussion
High-resolution
spectroscopic imaging in MS revealed localized metabolic alterations, including
elevated mI with, but also without reduced NAA (as yet), in regions of white matter with
no pathology visible on clinical MRI, which may indicate early pathological changes in the NAWM that remain unnoticed on high-resolution MRI. An
early increase of mI may reflect a pathologically important process related to
neuroinflammation, and may precede the decrease of NAA, which reflects the
neurodegenerative component of the disease. Together, they correlate with the
level of clinical disability in several NAWM and CGM regions.
Metabolic
abnormalities in the NAWM and CGM were more pronounced in subgroups of patients
with higher EDSS. These results suggest that reactive astrogliosis and axonal
injury play important role in the evolution of MS, and that high-resolution
MRSI is an appropriate tool with which to visualize this pathology in clinical
setting.Conclusion
MRSI
at 7T allows in vivo visualization of
disseminated MS pathology beyond demyelinating lesions. Metabolic abnormalities
in the NAWM and CGM, reflecting loss of axonal integrity and
neuroinflammation-induced astrogliosis, are associated with clinical
disability.Acknowledgements
This study was supported by the Austrian Science Fund (FWF): KLI 718, P 30701 and P 34198.References
- Lassmann
H, van Horssen J, Mahad D. Progressive multiple sclerosis: pathology and
pathogenesis. Nat Rev Neurol. 2012;8(11):647-656.
- Llufriu S, Kornak J, Ratiney H,
et al. Magnetic Resonance Spectroscopy Markers of Disease Progression in
Multiple Sclerosis. JAMA Neurol. 2014;71(7):840-847.
- Fernando KTM, McLean MA, Chard
DT, et al. Elevated white matter myo‐inositol in clinically isolated syndromes
suggestive of multiple sclerosis. Brain. 2004;127(6):1361-1369.
- Hangel
G, Strasser B, Považan M, et al. Ultra-high resolution brain
metabolite mapping at 7 T by short-TR Hadamard-encoded FID-MRSI. Neuroimage.
2018;168:199-210.
- Bogner W, Gruber S, Trattnig S,
Chmelik M. High-resolution mapping of human brain metabolites by free induction
decay 1H MRSI at 7 T. NMR Biomed. 2012;25(6):873-882.
- Strasser
B, Považan M, Hangel G, et al. (2 + 1)D-CAIPIRINHA accelerated
MR spectroscopic imaging of the brain at 7T. Magn Reson Med.
2017;78(2):429-440.
- Strasser B, Chmelik M, Robinson
SD, et al. Coil combination of multichannel MRSI data at 7 T: MUSICAL. NMR
Biomed. 2013;26(12):1796-1805.
- Bilgic B, Chatnuntawech I, Fan
AP, et al. Fast image reconstruction with L2-regularization. J Magn Reson Imaging. 2014;40(1):181-191.
- Považan
M, Hangel G, Strasser B, et al. Mapping of brain macromolecules
and their use for spectral processing of 1H-MRSI data with an
ultra-short acquisition delay at 7T. Neuroimage. 2015;121:126-135.
- Jenkinson M, Beckmann CF, Behrens
TEJ, Woolrich MW, Smith SM. FSL. Neuroimage. 2012;62(2):782-790.