Joshua S Greer1,2,3, Mubeena Abdulkarim1, Gerald F Greil1,3, Ayesha Zia1, Ananth J Madhuranthakam2,3, and Tarique Hussain1,2
1Pediatrics, UT Southwestern Medical Center, Dallas, TX, United States, 2Radiology, UT Southwestern Medical Center, Dallas, TX, United States, 3Advanced Imaging Research Center, UT Southwestern Medical Center, Dallas, TX, United States
Synopsis
In this study, pulmonary perfusion
imaging using arterial spin labeling (ASL) was demonstrated in pediatric
patients with pulmonary embolism. A method to quantify pulmonary vascular obstruction
was proposed using ASL to estimate improvements in pulmonary perfusion following
treatment, which moderately agreed with obstruction measured by CTA. Perfusion
defects were successfully detected in all patients. A follow-up ASL scan also showed
significantly improved perfusion in a patient following treatment, and a few
patients had residual perfusion defects in ASL images that were not seen by
CTA, suggesting that perfusion to the microvasculature was not immediately
restored following resolution of the emboli.
Introduction
Pediatric
venous thromboembolism (VTE), clinically presenting as deep venous thrombosis
(DVT) and pulmonary embolism (PE), has dramatically increased in the past
decade and now affects 1 in 200 hospitalized children (1). PE has explicitly experienced a more rapid rise in incidence, nearly
200%, disproportionately affecting adolescents (2). Pulmonary perfusion defects measured by SPECT
may persist in up to 50% of PE patients 6 months after treatment (3). The clinical significance of residual
perfusion defects is unclear, though unpredictable rates of thrombus resolution
make it challenging to differentiate between recurrent PE and residual defects (4). Exposure to ionizing radiation by CT
or SPECT also makes it challenging to monitor residual perfusion defects over
time in pediatrics (5, 6). The
purpose of this study was to demonstrate pulmonary perfusion imaging using
arterial spin labeled (ASL) MRI in pediatric patients with PE to evaluate the
extent of PE burden, and to develop a measure of pulmonary vascular obstruction
(PVO) to evaluate patient’s response to treatment or changes in embolic burden
over time without exposure to ionizing radiation. Methods
Six pediatric patients (16 ± 1.3 years,
2 male) with history of PE underwent ASL perfusion scans during cardiac MRI assessment
of right heart function on a 1.5T scanner (Ingenia, Philips Healthcare, The
Netherlands). Each patient had a CT angiography (CTA) scan performed for the
clinical evaluation of PE, which were retrospectively reviewed and used to
quantify PVO for comparison with ASL. One patient also had follow-up CTA and
ASL scans 6 months following tPA treatment to evaluate improvements in
perfusion.
ASL-MRI
Sagittal ASL images were acquired in
each patient using multi-slice FAIR (MS-FAIR) (7, 8), with 5-8 slices across each lung
with 15mm slice thickness, post-labeling delay of 1 R-R interval (9), ECG-triggered
SShTSE acquisition at diastole, 3 averages, and scan time = 2.5 minutes per
lung. Images were acquired during free-breathing with four non-selective FOCI
inversion pulses for background suppression to reduce respiratory motion
artifacts (7, 8). A separate M0 image was acquired for
perfusion quantification (10, 11). Pooled blood in the major pulmonary
vasculature was masked before measuring perfusion from each lobe of the lungs (10).
Quantification of pulmonary vascular obstruction
PVO was quantified using the
obstruction index proposed by Qanadli et al. for CTA (12). Briefly, the pulmonary arteries in
each lung are divided into ten branches, and occlusion of each segment is
scored from 0-2 for no, partial, or complete obstruction. Percent PVO was
reported as the sum of the occlusion scores in each lobe out of the maximum
possible score for that lobe.
An ASL-based PVO score was developed
to compare the severity and location of perfusion defects measured by ASL and
CTA. This was calculated as the percent reduction in perfusion from the minimum
perfusion value expected in healthy patients of 400 mL/100g/min (9). This is
similar to an approach used for SPECT (13), but makes use of the quantified ASL
perfusion values, allowing for meaningful comparison of PVO scores over time. Results
Figure 1A shows quantified MS-FAIR
perfusion images in a patient with significant clot burden and large filling
defects visible in the right lung. Figure 1B shows the calculated PVO map overlaid
on the perfusion images.
Figure 2 shows a patient with PE and subsequent
pulmonary infarct of the middle right lobe. They received 3 CTA scans over the
course of their anticoagulant treatment, with progressive reduction in the clot
burden and infarct size shown by CT at 3 and 7 months. Despite this reduction
in vascular obstruction, a significant perfusion defect could be seen by ASL at
the pulmonary infarct location 7 months after treatment began, in agreement
with previous observations by SPECT (3).
Figure 3A shows significant perfusion
defects across both lungs of a patient with PE. CTA shows occluded pulmonary vessels
that correspond well with regions of reduced ASL perfusion. Figure 3B shows the
same patient 6 months after tPA treatment, with significantly improved vascular
filling and pulmonary perfusion shown by CTA and ASL, respectively.
Figure 4 shows the expected negative correlation
between CTA-based PVO and quantified ASL perfusion (A) and the positive
correlation between PVO measured by CT and ASL across each lobe of all
patients.Discussion
MS-FAIR detected perfusion deficits in
all patients in a clinically-acceptable scan time. There was a moderate correlation between ASL
parameters and CT obstruction, likely due to them representing different
physiological processes. For example, in Figure 2, the vasculature was no
longer physically occluded, but perfusion had not been restored to the
infarcted region. A similar “no-reflow phenomenon” has been described following
myocardial infarction (14).
MS-FAIR has the potential to be a
valuable tool to monitor patients with a history of PE and determine whether
perfusion defects have resolved over time and following treatment. This
technique can additionally show perfusion defects not captured by CT without
exposing patients to ionizing radiation.Acknowledgements
No acknowledgement found.References
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