Leonie Petitclerc1,2, Lydiane Hirschler1, Jack A. Wells3, David L. Thomas4,5,6, and Matthias J.P. van Osch1,2
1C.J. Gorter Center for High Field MRI, Department of Radiology, Leiden University Medical Center, Leiden, Netherlands, 2Leiden Institute for Brain and Cognition (LIBC), Leiden, Netherlands, 3UCL Centre for Advanced Biomedical Imaging, Division of Medicine, University College London, London, United Kingdom, 4Neuroradiological Academic Unit, Department of Brain Repair and Rehabilitation, UCL Queen Square Institute of Neurology, University College London, London, United Kingdom, 5Dementia Research Centre, UCL Queen Square Institute of Neurology, University College London, London, United Kingdom, 6Wellcome Centre for Human Neuroimaging, UCL Queen Square Institute of Neurology, University College London, London, United Kingdom
Synopsis
In order to
measure the function of the blood-CSF barrier (BCSFB), a modified ASL
experiment is introduced. This is accomplished with multiple time-points, including
long labeling duration and post-labeling delay, and an echo train of 8 TEs from
10-1837ms. Long-T2 ASL signal, attributable to the CSF, was found
both in the choroid plexus and around the cortex. Fitting of this signal to two
models (a simple triexponential and a dynamic compartmental model) reveals an
amount of CSF signal about 5 times lower than the perfusion. The transfer time
of water across the BCSFB is estimated at around 100s.
Introduction
The
emerging field of glymphatics studies waste clearance pathways in the brain,
mediated through the cerebrospinal fluid (CSF). A key component of this system
is thought to be the blood-CSF barrier (BCSFB); a membrane through which water
and other molecules are exchanged. Assessing BCSFB function is of
importance, as an imbalance in CSF volume could disrupt waste clearance, associated
with many neurodegenerative disorders (e.g. Alzheimer’s disease)1.
Arterial spin labeling (ASL) measures perfusion
by magnetically labeling blood water. Leveraging the long T1 and T2
of CSF (~4200 and 1500 ms, respectively), modified ASL experiments in mice
measured CSF-signal around the choroid plexus (ChP)2, thought to be the main site of CSF production.
Here we expand upon this approach and capture the transfer of labeled blood
water to CSF compartments in the human brain.Methods
This study
consists of two protocols: a multi-PLD acquisition to image time-dependent
dynamics of ASL label arising in CSF (5 female subjects, 24-61 years, with informed
consent in accordance with IRB-regulations), and a validation session (in
three of the same subjects) to confirm that the observed signal is reproducible
and not artefactual.
All data
were acquired on a Philips Achieva 3T system (Philips, the Netherlands) with a
32-channel head-coil. For the multi-PLD protocol, six pCASL scans were
performed with labeling duration (LD)=1000, 1000, 1500, 2000, 3000, 3000ms and
post-labeling delay (PLD)=500, 1000, 1500, 2000, 2500, 4000ms. The 3D-GRaSE
readout (4 shots, 3x3x6mm3) was extended to 8 echo times (TE=10+(n-1)*261ms).
To estimate M0, an additional scan was acquired without labeling. For
the validation protocol, performed on a separate day, the last pCASL scan was
repeated, as well as a scan with the labeling plane placed symmetrically above
the brain.
Analysis
was performed in MATLAB. Perfusion images were calculated by pair-wise
subtraction of label and control. These were smoothed with a 2x2 voxel gaussian
kernel (σ=2 voxels). Two separate processing approaches were used: (i) a
triexponential fit (Stotal=Sblexp(-TE/T2bl)+SGMexp(-TE/T2GM)+SCSFexp(-TE/T2CSF))
with set T2s was used to separate the ASL-signal residing in blood,
gray matter (GM) and CSF for each LD/PLD combination; and (ii) a dynamic
compartmental model3 (figure 3) to obtain whole-brain
maps of cerebral blood flow (CBF or f), arterial transit time (ATT or δ), Tbl->GM and Tbl->CSF, the water transfer-time
from the blood to GM and CSF, respectively. Using these maps, the fractions of signal
coming from the compartments could be calculated at arbitrary time points to
facilitate dynamic visualization.Results
The
ASL-signal at long TE becomes visible at longer LD/PLD, indicating the inflow
of labeled water into CSF (Figure 1a). The intensity and location of the signal
are reproducible across sessions (Figure 1b,c), and no significant signal is created
when the labeling plane is situated above the head (Figure 1d). Note that label
not only reaches the CSF in the choroid plexus (ChP), but also around the
cortex, in the subarachnoid space. Figure 2 shows distinct spatial and temporal
patterns for the three compartments with the simple triexponential fit. Figure
3 describes the model and results of dynamic fitting. CBF (Figure 4a) pattern
and values are consistent with literature4. ATT (Figure 4b) shows short values in the
circle of Willis and the expected X-pattern of longer ATT in the white matter (Figure
4d, top). Tbl->CSF values are shorter in the ChP and cortical
area (Figure 4d, bottom, circles) (avg±SD 102±75s and 103±54s, respectively) and longer in the white
matter. Finally, the animated GIF in Figure 5 shows dynamically the early arrival of label in the
blood compartment, prolonged stay in tissue, and delayed arrival and decay in
CSF. The two processing approaches extracted a non-negligible fraction of CSF-signal, on a scale about 5 times lower than blood and gray matter signal (Figures
2 and 5), with slightly differing patterns. Discussion
We show
that imaging of ASL-signal in the CSF can be achieved in the human brain. Our
results appear to contradict the common belief that the vast majority of water-exchange
from blood to CSF occurs in the ChP. As Figure 1 already shows, at medium to
long LD/PLD, ASL-signal with a long T2 (indicating the presence of labeled
water that travelled from the blood to the CSF), is present both in the
ventricles and around the cortex. This unexpectedly high CSF-signal could be
explained by recent studies showing BCSFB exchange sites in the leptomeningeal
vasculature5. It should be noted that water exchange
during the (1.8s!) echo-train is neglected in the triexponential fit, while it
is taken into account by the dynamic model; this is likely to explain differences
in results observed by the two approaches (Figures 2 and 5). Similar Tbl->CSF
values estimated in the ChP and cortex appear to point towards similar exchange pathways.
For the dynamic model, we assumed no venous
outflow, instantaneous mixing within compartments, and no exchange between the GM
and CSF (figure 3a). The T2s of blood, GM and CSF were set at 150, 60 and
1500ms, respectively. In future experiments, these assumptions could be
challenged, and the T2s could be varied or fitted. The
presence of some ASL-signal in CSF will also have a minor effect on partial
volume correction methods that currently ignore CSF-signal.Acknowledgements
This
work is part of the programme Innovational Research Incentives Scheme Vici
(project 016.160.351), financed by NWO.
David Thomas is supported by the UCL Leonard Wolfson Experimental Neurology
Centre (PR/ylr/18575), UCLH NIHR Biomedical Research Centre, and the Wellcome
Trust (Centre Award 539208).
Jack Wells is supported by the Wellcome
Trust/Royal Society (204624/Z/16/Z).
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