Nienke P.M. Wassenaar1, Esther N. Pijnappel2, Remy Klaassen2, Femke Struik1, Jaap Stoker1, Jurgen H. Runge1, Hanneke W.M. van Laarhoven2, Johanna W. Wilmink2, Aart J. Nederveen1, and Oliver J. Gurney-Champion1
1Department of Radiology and Nuclear Medicine, Cancer Center Amsterdam, Amsterdam University Medical Centers, University of Amsterdam, Amsterdam, Netherlands, 2Department of Medical Oncology, Cancer Center Amsterdam, Amsterdam University Medical Centers, University of Amsterdam, Amsterdam, Netherlands
Synopsis
Stromal
deposition can become a physical and biological barrier that prevents
chemotherapy from reaching pancreatic ductal adenocarcinoma (PDAC). In this
study, 34 patients were treated with LDE225, which specifically targets tumour
stroma, gemcitabine and nab-paclitaxel. Pancreatic tumour response was assessed
using intravoxel incoherent motion (IVIM) MRI. We found that the diffusion in
PDAC increased after chemotherapy, which may be explained by reduction of
stroma or tumour necrosis. Furthermore, a positive correlation was found
between overall survival and the change in tumour perfusion, underlining the
fact that reperfusion of PDAC by LDE225 improves prognosis.
Introduction
For
patients with metastatic PDAC palliative chemotherapy is the standard of care[1-2].
But despite the progress made in treatment of advanced PDAC over the past
years, survival remains poor. Stromal deposition is thought to play a crucial
role in preventing chemotherapy efficacy, being a physical and biological
barrier that limits the vascularization of the tumour[2-5]. Hence, chemotherapy
efficacy may be improved by targeting the stroma alongside the tumour.
Therefore, we designed a study in which we treated PDAC patients with LDE225 combined
with conventional chemotherapy of gemcitabine and nab-paclitaxel. LDE225 is
thought to specifically target the tumour’s stroma[5-6]. By imaging tumour
microenvironment, we may get a better insight in how this novel treatment affects
PDAC in this patient population.
A promising
microenvironment imaging approach is IVIM MRI[7]. IVIM provides information on
tissue diffusion and perfusion, two very promising biomarkers in the context of
stroma and treatment response[8]. Stroma contains dense tissue, resulting in restricted
diffusion and limiting vascularity, leading to poor perfusion. The goal of this
research is to assess PDAC’s response to LDE225 and gemcitabine+nab-paclitaxel
with IVIM MRI and to correlate IVIM parameters with the overall survival (OS) of
these patients. Method
34 patients
with metastatic PDAC were included in this study. As part of the study, they received
treatment with LDE225 and gemcitabine+nab-paclitaxel. As we combined the data
from the phase 1 and phase 2 part of the trial, the dose of LDE225 differed per
patient from 200mg(n=18), 400mg(n=8), 600mg(n=3) to 800mg(n=4). All patients
underwent a baseline MRI scan before the start of the chemotherapy and 21
patients also underwent a second MRI scan after 8 weeks of treatment. Furthermore,
the OS of 28 patients was recorded of whom 18 underwent both MRI scans.
All MRI
examinations were conducted using a 3T MRI scanner (Ingenia, Philips, Best,
Netherlands). Diffusion Weighted Imaging (DWI) was performed using single shot
2D echo planar imaging with TR/TE:2145/46ms, SENSE factor:1.3, SPIR and
gradient reversal for fat suppression, b-values(directions/averages):0(15),10(9),20(9),30(9),40(9),50(9),75(4),100(12),150(4),250(4),400(4),600(16).
Respiratory triggering with a diaphragm navigator was used.
Per voxel,
the IVIM model was fitted to the signal decay as a function of the b-value
using a bi-exponential fit to obtain diffusion (D), pseudodiffusion (D*)
and perfusion fraction (f) maps. The
pancreatic tumour was manually delineated on baseline and post-treatment MRI
scans under guidance of a post-contrast MRI from the same scan session (Figure
1). The mean parameter values from within the ROIs were used for further analysis.
All
statistical tests were two-tailed and a significance level of 0.05 was used. Data
were first tested on normality using the Shapiro-Wilk test. The overall effect
of the chemotherapy on the tumour was assessed by a Wilcoxon signed-rank test between
MRI scans at baseline and post-chemotherapy for all IVIM parameters. To test
whether IVIM parameters correlated to OS, a Spearman’s Rank Correlation test
was done. Subsequently, a Receiver Operating Characteristic (ROC) analysis was performed
to determine the specificity and sensitivity (using the Youden’s index) of baseline
IVIM parameters and the relative change in parameter value during treatment to
predicting OS of PDAC patients receiving chemotherapy. OS of this cohort was
between 35 days and 1,5 years. The mean OS, 230 days, was taken as cut-off
value to determine survivors for the purpose of the ROC analysis.Results
The Wilcoxon test showed that only D significantly increased during chemotherapy
(Figure 2+3). Furthermore, significant correlations were found between the OS
and baseline f (rs=-0.46,p=0.016)
and between OS and the relative difference of f (Δf)
between baseline and post chemotherapy (rs=0.50,p=0.040). The AUC,
sensitivity and specificity of each parameter can be seen in Figure 4.
Noticeably, f (Figure 5b) showed high
AUC values. No relation was found between OS and dose of LDE225.Discussion
We showed
that IVIM is able to detect treatment effects from combined LDE225, gemcitabine
and nab-paclitaxel in PDAC patients. We showed that diffusion significantly increased
during treatment. Furthermore, we showed that an increase in perfusion fraction
during treatment resulted in a better prognosis. We believe that two mechanisms
contributed to this increase, namely necrosis and the decrease in stroma. The
accompanying lower cellularity causes a higher diffusion[9].
Whether or
not the increase in D found in this population, and accompanying
reduction in stroma, also increased tumour perfusion, turned out to be
patient-specific (i.e. figure 3). In fact, on average, the perfusion decreased
slightly. Potentially, there is an interplay between perfusion increasing
factors, such as LDE255-induced reduction in stroma, and perfusion decreasing
factors, such as the effect of regular chemotherapy. A positive correlation
between the Δf and the OS was found, where patients that had larger increase
in f had better prognosis. We believe
this highlights that when the LDE225-induced stroma reduction indeed leads to
more perfusion, patients had better OS. Our findings highlight the importance
of measuring IVIM during LDE255 chemotherapy to predict treatment efficacy. Conclusion
This study shows
that after treatment of PDAC with the combination of LDE225 and gemcitabine+nab-paclitaxel,
the diffusion of the tumour increased based on IVIM parameters. Furthermore,
there seems to be a positive correlation between OS and the change in f due to chemotherapy. Acknowledgements
No acknowledgement found.References
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