Marian A. Troelstra1, Julia J. Witjes2, Anne-Marieke van Dijk2, Anne Linde Mak2, Jurgen H. Runge1, Joanne Verheij3, Max Nieuwdorp2, Adriaan G. Holleboom2, Aart J. Nederveen1, and Oliver J. Gurney-Champion1
1Department of Radiology and Nuclear Medicine, Amsterdam UMC, location AMC, Amsterdam, Netherlands, 2Department of Internal and Vascular Medicine, Amsterdam UMC, location AMC, Amsterdam, Netherlands, 3Department of Pathology, Amsterdam UMC, location AMC, Amsterdam, Netherlands
Synopsis
In this study we have developed an unsupervised
physics-informed deep neural network (IVIM3-NET) to fit a
tri-exponential model to intravoxel incoherent motion (IVIM) data from 35
non-alcoholic fatty liver disease (NAFLD) patients. Diagnostic performance was compared
to a tri-exponential least squares (LSQ) fit. Visually, IVIM3-NET showed
high-quality parameter maps with less noise than the LSQ-fit. IVIM3-NET
showed slightly higher correlations between fit parameters and histology and
more significant differences between levels of fibrosis and inflammation than
the LSQ-fit. Correlations between f2 and fibrosis and inflammation
grade, potentially highlighting NAFLD-induced vascular changes, warrant further
investigation of the IVIM3-NET in NAFLD patients.
Introduction
Non-alcoholic fatty liver disease (NAFLD) is characterised
by accumulation of lipids within hepatocytes, potentially causing hepatic
ballooning, inflammation, and fibrosis[1]. The increasing prevalence of
NAFLD[2] has brought a growing interest
in non-invasive techniques for detecting the presence and severity of disease[3]. Intravoxel incoherent motion
(IVIM) imaging has been proposed as a biomarker for assessing and staging NAFLD,
particularly fibrosis[4]. While IVIM is typically
fitted using bi-exponential models, the liver’s complex structure shows
increased fit accuracy using tri-exponential models[5–7]. Herein, an extra exponent is
added to improve fitting of rapid signal decay at very low b-values:
S(b)/S(b=0s/mm2)=(1-f1-f2)*exp(-b*D)+f1*exp(-b*D1)+f2*exp(-b*D2)
where diffusion(D), slow(D*1) and fast pseudo-diffusion(D*2),
and slow(f1) and fast perfusion fraction(f2) are estimated.
Conventional nonlinear least squares (LSQ) fitting methods typically lead to
noisy parameter maps. Recent work has shown considerable improvements in parameter
map accuracy using an unsupervised physics-informed deep neural network for
fitting the bi-exponential IVIM model (IVIM-NET)[8,9]. The aim of this study was to
develop a similar approach for fitting a tri-exponential IVIM model and assess
diagnostic performance compared to the conventional LSQ-fit in NAFLD patients.Methods
Thirty-five patients from the Amsterdam NAFLD cohort
(ANCHOR) with known hepatic steatosis on ultrasound, BMI>25 and elevated
ALAT/ASAT were included. All individuals underwent an MRI scan (3T Philips
Ingenia) and liver biopsy. The IVIM scan consisted of a free-breathing
multi-slice diffusion-weighted single-shot echo-planar imaging sequence. Scan
parameters are listed in Table 1. The
entire liver was manually segmented. A tri-exponential equivalent to IVIM-NET (IVIM3-NET)
and LSQ tri-exponential model were fitted voxel-wise for segmented voxels.
The LSQ-fit was fitted
in three stages: (1) D and S0 were determined from a
mono-exponential fit to data with b≥150s/mm2; (2) D*1 and f1 were
determined for 150s/mm2≥b≥15s/mm2
(after subtracting (1); (3) D*2 and f2 were obtained for
b≤30s/mm2 (idem). Constraints were
implemented such that 0<D<5×10-3mm2/s, 5×10-3<D*1<80×10-3mm2/s, 60×10-3<D*2<0.5mm2/s
and perfusion fractions were positive and summed to 1.
We developed IVIM3-NET
based on IVIM-NET[9]: a fully-connected 4-layer network per IVIM
parameter and a physics-informed loss function minimizing the root-mean-square
error between input voxel signals and predicted signal decay. IVIM3-NET
accommodated a tri-exponential fit in its loss function. A three-stage scheme similar
to the LSQ-fit was implemented to guide training initialisation, training 15 epochs
per parameter set. The network estimating D was trained considering b≥150s/mm2 while freezing network
weights for other parameters. Then networks estimating D*1 and f1
were trained from data with 150s/mm2≥b≥15 s/mm2,
etc. After these 3x15 initialisation epochs, the entire pre-trained network was
trained normally and as a whole with all parameters unfrozen until the stopping
criterion was met (no improvement for 10 consecutive epochs).
Histology specimens
were analysed according to SAF[10] for levels of steatosis (0-3), ballooning
(0-2), inflammation (0-2) and fibrosis (0-4). Correlations between IVIM and
histology were assessed according to Spearman’s rank correlation.
Kruskal-Wallis (KW) tests, followed by Dunn’s post-hoc analysis where
appropriate, were used to assess difference in medians between histological
grades for IVIM parameters. Results
Example datasets of tri-exponential IVIM parameters for
patients with varying levels of fibrosis can be found in Fig.1. Visual
assessment revealed improvement in noise levels for all IVIM parameters using
IVIM3-NET compared to the LSQ-fit. Furthermore, f2 visually decreased with
increasing fibrosis grade. IVIM3-NET and LSQ-fit both showed significant correlations
with histology, with slightly stronger correlations for the IVIM3-NET (Fig.2).
KW tests showed significant differences in medians between fibrosis and f1 and
f2 for the IVIM3-NET and D*1 for the LSQ-fit (Fig.3), as well as between
inflammation grade and f2 (Fig.4) for both IVIM3-NET and LSQ-fit. Discussion
In this study we implemented IVIM3-NET which fitted
a tri-exponential model to IVIM data and showed its clinical relevance. IVIM3-NET provided
parameter maps that were substantially less noisy than the LSQ-fit, potentially
allowing for assessment of qualitative images at an individual patient level.
Furthermore, IVIM3-NET had slightly higher correlation between fit
parameters and histology and more significant differences between histological
grades. KW tests showed a significant difference in medians between fibrosis
and IVIM3-NET f1 and f2, as well as inflammation
and IVIM3-NET f2. Although LSQ-fit also showed similar
correlations with D* parameters, the use of IVIM3-NET f parameter
maps is more desirable, as D* maps were noisy, thus raising questions about
reliability and clinical applicability.
In this cohort we found the strongest correlations between f2
and fibrosis and to a lesser extent inflammation grade, thus providing
clinically relevant information exclusively attainable from a tri-exponential
fit and previously unexplored in patients with NAFLD. The precise origins of both
perfusion components are yet unclear, however, f1 could potentially
be attributed to slower incoherent capillary perfusion typically aimed at with
IVIM whereas f2 could account for rapid dephasing of coherent flow
in opposing directions or laminar flow profiles in larger vessels[7]. NAFLD is known to lead to
vascular changes, causing reduced liver perfusion even in the absence of cirrhosis[11]. This phenomenon may explain
the decreasing f1 and f2 values as disease severity increases. Conclusion
The novel IVIM3-NET enabled generation of high-quality
parameter maps of tri-exponential IVIM data in NAFLD patients. Promising correlations
between f2 and fibrosis and inflammation grade, potentially caused by
NAFLD-induced vascular changes, warrant further investigation of the
tri-exponential IVIM model in NAFLD patients.Acknowledgements
MN is supported by a personal ZONMW-VIDI grant
2013 [016.146.327]. The work was also partly supported by an IMI 2 LITMUS grant
(777377) and a Le Ducq consortium grant (17CVD01). AGH is supported by the
Amsterdam UMC fellowship, the Gilead Research Scholarship and Health~Holland.References
1. Parthasarathy G, Revelo X, Malhi H.
Pathogenesis of Nonalcoholic Steatohepatitis: An Overview. Hepatol Commun.
2020;4(4):478-492. doi:10.1002/hep4.1479
2. Younossi ZM, Koenig AB, Abdelatif D,
Fazel Y, Henry L, Wymer M. Global epidemiology of nonalcoholic fatty liver
disease-Meta-analytic assessment of prevalence, incidence, and outcomes. Hepatology.
2016;64(1):73-84. doi:10.1002/hep.28431
3. Stefan N, Häring HU, Cusi K.
Non-alcoholic fatty liver disease: causes, diagnosis, cardiometabolic
consequences, and treatment strategies. Lancet Diabetes Endocrinol.
2019;7(4):313-324. doi:10.1016/S2213-8587(18)30154-2
4. Li YT, Cercueil J-P, Yuan J, Chen W,
Loffroy R, Wáng YXJ. Liver intravoxel incoherent motion (IVIM) magnetic
resonance imaging: a comprehensive review of published data on normal values
and applications for fibrosis and tumor evaluation. Quant Imaging Med Surg.
2017;7(1):59-78. doi:10.21037/qims.2017.02.03
5. Cercueil J-P, Petit J-M, Nougaret S,
et al. Intravoxel incoherent motion diffusion-weighted imaging in the liver:
comparison of mono-, bi- and tri-exponential modelling at 3.0-T. Eur Radiol.
2015;25(6):1541-1550. doi:10.1007/s00330-014-3554-6
6. Chevallier O, Zhou N, Cercueil J, He
J, Loffroy R, Wáng YXJ. Comparison of tri‐exponential decay versus bi‐exponential
decay and full fitting versus segmented fitting for modeling liver intravoxel
incoherent motion diffusion MRI. NMR Biomed. 2019;32(11):1-11.
doi:10.1002/nbm.4155
7. Riexinger A, Martin J, Wetscherek A,
et al. An optimized b‐value distribution for triexponential intravoxel
incoherent motion (IVIM) in the liver. Magn Reson Med.
2020;(June):mrm.28582. doi:10.1002/mrm.28582
8. Barbieri S, Gurney-Champion OJ,
Klaassen R, Thoeny HC. Deep learning how to fit an intravoxel incoherent motion
model to diffusion-weighted MRI. Magn Reson Med. 2020;83(1):312-321.
doi:10.1002/mrm.27910
9. Kaandorp MPT, Barbieri S, Klaassen R,
et al. Improved unsupervised physics-informed deep learning for
intravoxel-incoherent motion modeling and evaluation in pancreatic cancer
patients. November 2020. http://arxiv.org/abs/2011.01689.
10. Bedossa P. Utility and appropriateness of
the fatty liver inhibition of progression (FLIP) algorithm and steatosis,
activity, and fibrosis (SAF) score in the evaluation of biopsies of
nonalcoholic fatty liver disease. Hepatology. 2014;60(2):565-575.
doi:10.1002/hep.27173
11. Pasarín M, Abraldes JG, Liguori E, Kok B,
Mura V La. Intrahepatic vascular changes in non-alcoholic fatty liver disease:
Potential role of insulin-resistance and endothelial dysfunction. World J
Gastroenterol. 2017;23(37):6777-6787. doi:10.3748/wjg.v23.i37.6777