Henk M. De Feyter1, Monique A. Thomas1, Kevan L. Ip1, Kevin L. Behar2, and Robin A. de Graaf3,4
1Department of Radiology and Biomedical Imaging, Yale University, New Haven, CT, United States, 2Department of Psychiatry, Yale University, New Haven, CT, United States, 3Department of Radiology and Biomedical Imaging, Yale University, NEW HAVEN, CT, United States, 4Department of Biomedical Engineering, Yale University, New Haven, CT, United States
Synopsis
Previously we
reported high tumor uptake of exogenous choline in rodent brain tumor models
when using Deuterium Metabolic Imaging (DMI) during intravenous infusion of [2H9]-choline.
The small differences in chemical shifts of [2H9]-labeled
choline, phosphocholine, glycerophosphocholine and betaine exclude accurate
peak assignment, and therefore it is unclear whether blood-borne choline is
metabolized intracellularly. Using different 2H-labeling strategies
of choline and high resolution 2H NMR in tumor tissue extracts we identified
the choline-containing metabolites observed during intravenous infusion, as
well as after 24 hrs.
Introduction
For decades 1H
MRS has been used to detect increased levels of total choline (tCho) in high
grade brain tumors in vivo. This composite peak at ~3.2 ppm consists of overlapping
signals from choline (Cho), phosphocholine (PC) and glycerophosphocholine (GPC).
The increased level of tCho has often been attributed to a higher membrane
turnover in growing tumors. Since Cho is an essential nutrient, growing tumors can
also have increased capacity for Cho uptake from the blood. Accordingly, PET
imaging of radiolabeled Cho has been used to study Cho uptake in various cancer
types (1). Recently we described how deuterium
metabolic imaging (DMI) showed strong image contrast between tumor and
normal-appearing brain due to high uptake of blood-borne [2H9]-Cho,
in rodent models of glioblastoma (2). However, similar to 1H MRS,
the 2H MR spectral resolution is insufficient to differentiate [2H9]-labeled
Cho metabolites. To what extent the plasma-borne Cho is metabolized by the
tumor is therefore unknown. Here we further investigated the use of DMI and [2H9]-Cho
in a rat glioblastoma model, relying on high resolution 2H NMR and
alternatively 2H-labeled Cho to identify Cho metabolites in brain
tumor tissue extracts. Methods
Rat glioma
cells, RG2 (ATCC), were grown in T75 flasks using Dulbecco’s modified Eagle’s
medium (DMEM) and standard cell culture conditions. Glioma-bearing rats were
generated by intracerebral injection of RG2 cells (10,000 cells) in Fischer344 rats (n=8), as
described previously (3). Animal studies were performed on an
11.74 T Magnex magnet (Magnex Scientific Ltd.) interfaced to a Bruker Avance
III HD spectrometer running on ParaVision 6 (Bruker Instruments, Billerica, MA),
as previously described (4).
Glioma-bearing rats
were infused intravenously via tail vein for ~36 min with [2H9]-choline
chloride (Cambridge Isotopes Laboratories, Cambridge, MA), or [1,1,2,2-2H4]-choline
chloride (CDN Isotopes, Quebec, Canada) dissolved in water (400 mM), using a
bolus-continuous infusion protocol. DMI data were acquired during the [2H9]-Cho
infusion, or 20-24 hrs later (Fig. 1). DMI acquisition was similar as described
previously, except for the use of
a 20x15mm2 2H surface coil, and 2.5x2.5x2.5mm3
spatial resolution (4).
Infusion of [1,1,2,2-2H4]-Cho was
performed as bench experiments only. All animals were euthanized using focused
beam microwave fixation, brain and tumor tissue harvested, and metabolite
extracts made using a perchloric acid extraction protocol, for analysis with
high resolution 2H NMR. High-resolution
2H NMR scans were performed on a 500MHz Bruker Avance MR
spectrometer equipped with a 5-mm probe optimized for 1H and
broadband acquisitions, operating at 500.13 MHz (1H) and 76.77 MHz (2H).
All 1H MRI and 2H DMI data, and high-resolution 2H
NMR data were processed with home-written graphical user interfaces in Matlab (MathWorks,
Natick, MA).Results
DMI data acquired
both during, and 24 hrs after intravenous infusion of [2H9]-Cho
demonstrate high uptake and retention of labeled Cho in brain tumor lesions of
RG2-bearing rats (Fig. 2). The in vivo 2H MR spectra show a peak
around 3.2 ppm, consistent with tCho, but does not allow for distinguishing
individual resonances of Cho metabolites. Even in high resolution 2H
NMR spectra of tumor metabolite extracts all the different Cho species cannot be
identified unambiguously because of overlap of particularly PC and betaine.
Using [1,1,2,2-2H4]-Cho
provides the advantage to identify Cho species at different, less overlapping
chemical shifts than the tri-methyl resonance of [2H9]-Cho.
Figure 3 shows the 2H NMR spectra of different tumors harvested
immediately after [1,1,2,2-2H4]-Cho infusion, and 24 hrs
later. The limited spectral overlap of downfield resonances allows clear
identification of Cho (3.50 and 4.06 ppm), PC (3.58 and 4.16 ppm), GPC (3.66
and 4.31 ppm), and a small peak likely from betaine (3.89 ppm). The data from
acutely harvested tissue show both Cho and PC, indicating some level of Cho
kinase activity within the first 36 min of Cho infusion. In the sample
collected 24 hrs later, no free Cho is detected but PC and GPC are clearly
present. Discussion and conclusion
Using DMI during
infusion of [2H9]-Cho confirmed earlier results of high blood-borne
Cho uptake in rodent models of glioblastoma, generating high image contrast
with surrounding normal-appearing brain (2). Interestingly, even 24 hrs after a 36
min [2H9]-Cho infusion there is a strong signal of 2H-labeled
tCho present in vivo. Detecting 2H-labeled tCho this late after the
infusion could indicate that the peak consists predominantly of phosphorylated Cho
that is trapped intracellularly, and thus point towards active metabolism of
blood-borne Cho. The 2H NMR spectra from tissue extracts support
this hypothesis, clearly showing a lack of free Cho but presence of PC and GPC
24 hrs after infusion. These data are in general agreement with the turnover
rate of Cho metabolism as observed in glioma cells in vitro (5). While [1,1,2,2-2H4]-Cho
facilitated the identification of different Cho metabolites, [2H9]-choline
is the preferred 2H-labeled Cho for in vivo DMI studies.
Using high-resolution 2H
NMR allowed to show active metabolism of blood-borne Cho in rat glioblastoma.
The 24 hrs delayed in vivo detection of [2H9]-tCho with
DMI in glioblastoma reflects Cho metabolism, while DMI scans during [2H9]-Cho
infusion are predominantly detecting Cho uptake. Intravenous choline chloride infusion
is used clinically in patients receiving parenteral nutrition, indicating this
DMI approach could be translated to the clinic (6). Acknowledgements
The authors thank Xiaoxian Ma and Bei Wang for
their assistance with animal preparation. This research was funded, in part, by
NIH grant NIBIB R01-EB025840, and supported by a research grant program from Cambridge
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