Merel M. van der Thiel1,2,3, Whitney M. Freeze2,3,4, Alida A. Postma1, Inge I.C.M. Verheggen1,2,3, Sau M. Wong1, Joost J.A. de Jong1, Frans R.J. Verhey2,3, Inez H.G.B. Ramakers2,3, Walter H. Backes1,3, and Jacobus F.A. Jansen1,3
1Department of Radiology and Nuclear Medicine, Maastricht University Medical Center, Maastricht, Netherlands, 2Department of Psychiatry and Neuropsychology, Maastricht University, Maastricht, Netherlands, 3School for Mental Health and Neuroscience, Alzheimer Center Limburg, Maastricht, Netherlands, 4Department of Radiology, Leiden University Medical Center, Leiden, Netherlands
Synopsis
Spectral analysis using non-negative least squares in intravoxel incoherent motion enables estimation of an intermediate component in the diffusion spectrum between parenchymal diffusion and microvascular pseudodiffusion. However, the precise source of the intermediate component remains unknown. By studying the relation of the intermediate component with vascular (i.e. WMH volume) and neurodegenerative (i.e. hippocampal atrophy) biomarkers, the current study aimed to gain more knowledge about the interpretation of the intermediate peak in relation to cognitive status and its underlying pathology. The intermediate peak seems to be a promising imaging biomarker for microvascular and neurodegenerative pathology in Alzheimer’s disease and its prestages.
Introduction
Intravoxel
incoherent motion (IVIM) has the ability to separate parenchymal diffusion from
microvascular pseudo-diffusion1. IVIM can quantify exactly two or three
components when using bi- or tri-exponential models1,2, respectively. In contrast, the spectral analysis method using the
non-negative least squares (NNLS) method lays no constraints on the number of
estimated components3. Spectral analysis has been used to identify
an intermediate peak between two classical components, which is argued to
represent increased interstitial fluid within enlarged perivascular spaces
(ePVS)3. Wong et al.3 showed that the amplitude of the
intermediate peak relates to the number of ePVS and the volume of white matter
hyperintensities (WMH). An increased amplitude of this peak has been suggested
to be related to an impaired glymphatic system4, but the precise
source of this diffusion signal still remains unknown. In addition, no studies
have looked at the role of the intermediate component in memory clinic
patients, who are expected to have an impaired glymphatic system. The current study aims to investigate the intermediate peak in a population of
individuals from a memory clinic with a range of cognitive abilities and a
variation in neurovascular and neurodegenerative pathology. By studying the
relation of the intermediate diffusion component with vascular (i.e. WMH volume)
and neurodegenerative (i.e. hippocampal atrophy) biomarkers, the current study
aims to gain more knowledge about the interpretation of the intermediate peak in
relation to cognitive status and its underlying pathology.Methods
Subjects: Eighty-five patients (17 Alzheimer’s disease (AD), 19 mild cognitive impairment (MCI) and 9 vascular cognitive impairment (VCI) patients) and 39 healthy controls were included in this study.
MRI acquisition: All subjects underwent an MRI protocol (Philips 3.0 Tesla) with a 32-channel head coil, as previously described in more detail5. Diffusion MR images were acquired using single-shot spin-echo echo planar imaging (EPI) sequence in orthogonal 3 directions (TR/TE = 6800/84ms; matrix = 112x112x58; pixel size = 2.4mm, transverse slice thickness = 2.4mm), after cerebrospinal fluid suppression (TI = 2230ms). Fifteen diffusion sensitive b-values were employed (b = 0,5,7,10,15,20,30,40,50,60,100,200,400,700 and 1000 s/mm2).
Image analysis: Trace images were calculated and corrected for head displacements, eddy current and EPI distortions (ExploreDTI version 4.8.4)6 and smoothed with a 3mm FWHM Gaussian kernel (FSL version 6.0.1)7. Freesurfer version 5.1.0 was implemented to automatically segment anatomical T1 images, with manual inspection8. WMH were identified, as previously described5,9. White matter (WM) was separated into WMH and normal appearing WM (NAWM). The following regions of interest (ROIs) were coregistered to native IVIM space via the T1 anatomical images (FLIRT, FSL)10: cortical gray matter (GM), subcortical GM, WMH and NAWM. WMH and hippocampal volume were corrected for total intracranial volume.
ePVS were rated in the basal ganglia (BG) and centrum semiovale (CSO) as follows: 0=<10 ePVS, 1=10-20 ePVS, 2=>20 ePVS (see Figure 1). Spectral analysis using NNLS was conducted to analyze the IVIM data in a voxel-based manner3. The intermediate diffusion component was identified as 1.5<D<4.0*10-3 mm2/s, and the contribution of the intermediate component to the signal was determined by quantifying fint, while correcting for T1 and T2 relaxation effects3. The median value of the fraction and diffusivity values were extracted for each individual ROI. Spearman’s rho correlations adjusted for age and gender were computed between variables of interest (i.e. hippocampal atrophy, WMH volume, BG ePVS and CSO ePVS) and fint for each ROI (IBM SPSS statistics version 25). Results
Table 1 provides information on the demographics, vascular
and neurodegenerative markers and fint for each ROI. An example of a diffusion spectrum in the GM of an AD patient including the parenchymal,
intermediate and microvascular peak is displayed in Figure 2.
Table 2 contains all significant Spearman’s rho
correlations of fint with vascular and neurodegenerative markers,
adjusted for age and sex. For example, a negative association can be observed
between hippocampal volume and fint in the subcortical GM in the AD
group, while this relationship was absent within the other clinical groups (see
Figure 3). In contrast, a positive correlation can be found within the MCI
group, where increased WMH volume is associated with a higher fint
in subcortical GM (see Table 2). Additionally, significant correlations have
been identified between CSO ePVS and fint in WMH in both controls
and MCIs, between BG ePVS and WMH fint in MCI, and between BG ePVS
and NAWM fint in AD.Discussion
In this explorative study, we found multiple
associations between the IVIM intermediate volume fraction and WMH volume,
hippocampal atrophy, and ePVS score in the BG and CSO in a sample of memory
clinic patients and controls with various degrees of vascular and degenerative
pathology. We thereby identify fint as a promising imaging biomarker
for microvascular and neurodegenerative pathology in AD and its prestages. Additionally,
the findings of this study suggest that both vascular and neurodegenerative
processes are associated with variation in intermediate peak fraction in memory
clinic patients and cognitively normal individuals. Future longitudinal life-span studies may be able to reveal the mechanistic temporal relation between changes in fint, vascular pathology, neurodegeneration and cognitive decline. Conclusion
fint is a promising imaging biomarker
for microvascular and neurodegenerative pathology in AD and its prestages.Acknowledgements
This research was supported by Alzheimer Nederland (research grant
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