Matteo Figini1, Antonella Castellano2, Valentina Pieri2, Samira Bouyagoub3, Andrea Falini2, Daniel C Alexander1, Mara Cercignani3, and Eleftheria Panagiotaki1
1Centre for Medical Image Computing, Department of Computer Science, University College London, London, United Kingdom, 2Neuroradiology Unit and CERMAC, Vita-Salute San Raffaele University and IRCCS San Raffaele Scientific Institute, Milano, Italy, 3Clinical Imaging Sciences Centre, Brighton and Sussex Medical School, Brighton, United Kingdom
Synopsis
We
used the VERDICT framework to find
clinically useful microstructural models to characterize vasculature in brain
tumors. We correlated the vascular fractions, estimated by all possible
three-compartment models, with perfusion MRI metrics (plasma volume and
cerebral blood volume) derived from independent measurements on the same
patients. The models with the strongest correlation with the perfusion MRI and
clinical data incorporate spherical restriction for the intracellular
compartment, isotropic diffusion for the extracellular compartment, and
isotropically hindered or restricted pseudo-diffusion for the vascular
compartment.
INTRODUCTION
Characterizing the microenvironment of brain tumors
is crucial for diagnosis and therapy follow-up assessment, but current
noninvasive imaging techniques fall short of this goal and clinicians often
have to rely on invasive procedures, such as biopsy and histopathology1.
The cellular and vascular components of the tumor
tissue are the most clinically relevant to characterize tumor biological
attitude. Cellular composition can be assessed by diffusion-weighted MRI (dMRI):
in areas of high cellularity, diffusion is strongly hindered or restricted. On
the other hand, the vascular component is usually studied with perfusion MRI
techniques such as dynamic contrast enhanced (DCE) or dynamic susceptibility
contrast (DSC) MRI, which require contrast agent injection2,3. Alternatively,
perfusion can also be detected by dMRI as areas of very high diffusivity
(pseudo-diffusion)4.
VERDICT (Vascular, Extracellular, and Restricted
Diffusion for Cytometry in Tumors) is a framework for multi-compartment modeling
the vascular, extracellular and restricted component of tumor tissues5.
It has shown diagnostic utility and high repeatability in body tumors,
especially prostate cancer6,7.
The aim of this study is to use the VERDICT framework
to find a clinically useful microstructural model for brain tumors. In particular,
we focus on the vascular component, and correlate our results (derived from
dMRI) with independent perfusion MRI metrics such as the DCE-derived plasma
volume (Vp), and the DSC-derived cerebral blood volume (CBV).METHODS
Data were collected from 5 patients (4 males, age
23-70); 3 had IDH wild-type anaplastic astrocytoma, one had a melanoma
metastasis and one an IDH wild-type astrocytoma.
MRI was acquired at 3T (Ingenia CX, Philips
Healthcare). A series of dMRI scans were acquired according to the scheme in Table 1. Four of the patients also had perfusion MRI including dynamic contrast
enhanced (DCE) 3D spoiled gradient echo sequences (TE/TR=1.8/3.9 ms, flip angle
15°) and dynamic susceptibility contrast (DSC)
fast field echo EPI sequences (TE/TR=31/1500 ms, flip angle 75°).
Additionally, 3D-FLAIR images and post-contrast 3D T1-weighted
images were acquired. Regions of interest (ROI) masks for the whole tumor were
segmented on 3D-FLAIR images and for the tumor core on post-contrast 3D-T1
images, in order to outline the core and the periphery of the tumors (Figure
1).
After denoising, removal of Gibbs artifacts, motion
and distortion correction, we fit multiple three-compartments models to the
data in Matlab (MathWorks). Using the terminology in previous works8,
a sphere was always used for intracellular restriction, whereas combinations of
ball, zeppelin, tensor, stick, astrosticks and Watson-distributed sticks were
used for the extracellular and vascular compartments, constraining the
diffusivity to be at least 3·10-9 m2/s in the latter
case. The name of each model is formed by the vascular
compartment first, then the extracellular compartment, and finally the
restricted compartment. As a reference we also fitted BallBallBall, which is equivalent
to the triexponential extension of IVIM9.
Perfusion MRI data were analyzed with Olea Medical
software (v 3.0, Olea Medical Solutions) to obtain parametric
maps of Vp and CBV. The correlations between the derived metrics and the
vascular fraction estimated by each model were evaluated with the Pearson
coefficient.RESULTS
Figure 2 shows an example of the restricted and
vascular fraction maps, with both fractions higher in the contrast-enhancing tumor
core than in the periphery as expected.
Indeed, most of the models detected higher
restriction in the tumor core than in the peritumoral areas, except for
BallAstrosticksSphere and BallWatsonsticksSphere (not shown). BallBallBall,
BallBallSphere and AstrosticksBallSphere detected higher vascular fractions in
the contrast-enhancing core than in the peritumoral zone, but
BallZeppelinSphere, BallTensorSphere and BallAstrosticksSphere actually estimated
higher vascular fractions in the periphery (Figure 3).
The
vascular fraction from AstrosticksBallSphere had the highest correlation with Vp:
r=0.74, followed by BallBallBall (r=0.72) and BallBallSphere (r=0.71). The
correlations with CBV were r=0.74 for BallBallBall, r=0.68 for
AstrosticksBallSphere and 0.64 for BallBallSphere (Figure 4).DISCUSSION and CONCLUSION
We have
tested multiple three-compartment models for the characterization of brain tumor
microenvironments. Our preliminary results show that BallBallSphere and the
more complex AstrosticksBallSphere could be able to characterize both restriction
and vascularity of the tumors. As expected, they provided higher intracellular
and vascular fractions in the core of the tumor than in the peritumoral area.
There was a certain degree of variability among patients, which could reflect
the diverse biological features of the different lesions. In particular the
highest values for both fractions are found in the melanoma metastasis of
patient 4. The typical histopathological characteristics of this lesion include
neoangiogenesis and densely-packed cells with high mitotic activity, possibly
reflected by our models.
BallZeppelinSphere,
BallTensorSphere and BallAstrosticksSphere estimated unrealistically high
vascular fractions in the periphery areas, which likely correspond to areas of
very high diffusivity which could not be properly modelled in the extracellular
compartment by Zeppelin, Tensor or Astrosticks respectively. Similarly,
BallAstrosticksSphere and BallWatsonsticksSphere estimated unrealistically high
intracellular fractions in the periphery areas. This suggests that a Ball
compartment needs to be included for extracellular diffusion in brain tumors.
If
these results can be confirmed in a larger patient cohort and with further
histopathology validation, our proposed models could significantly improve the
diagnosis and therapeutic management of brain tumors, by providing a tool for
the simultaneous evaluation of cellularity and vascularity of the lesions
without need for contrast injection.Acknowledgements
This work is supported by EPSRC grants EP/M020533/1, EP/N018702/1, EP/N021967/1 and EP/R006032/1 and the NIHR UCLH Biomedical Research Centre
References
1. Ellingson BM, Wen PY, van den
Bent MJ, Cloughesy TF. Pros and cons of current brain tumor imaging. Neuro
Oncol 2014;16(Suppl7):vii2-vii11
2. Villanueva-Meyer JE, Mabray
MC, Cha S. Current Clinical Brain Tumor Imaging. Neurosurgery
2017;81(3):397-415
3. Svolos P, Kousi E, Kapsalaki
E, et al. The role of diffusion and perfusion weighted imaging in the
differential diagnosis of cerebral tumors: a review and future perspectives.
Cancer Imaging 2014; 14(1): 20
4. Le Bihan D. What can we see
with IVIM MRI? Neuroimage 2019;187:56-67
5. Panagiotaki E, Walker-Samuel
S, Siow B, et al. Noninvasive quantification of solid tumor microstructure
using VERDICT MRI. Cancer Res 2014;74(7):1902-12
6. Panagiotaki E, Chan RW,
Dikaios N, et al. Microstructural characterization of normal and malignant
human prostate tissue with vascular, extracellular, and restricted diffusion
for cytometry in tumours magnetic resonance imaging. Invest Radiol.
2015;50(4):218-27
7. Johnston EW, Bonet-Carne E,
Ferizi U, et al. VERDICT MRI for Prostate Cancer: Intracellular Volume Fraction
versus Apparent Diffusion Coefficient. Radiology. 2019;291(2):391-397
8. Panagiotaki E, Schneider T,
Siow B, et al. Compartment models of the diffusion MR signal in brain white
matter: a taxonomy and comparison. Neuroimage. 2012;59(3):2241-54
9. Ueda Y, Takahashi S, Ohno N,
et al. Triexponential function analysis of diffusion-weighted MRI for
diagnosing prostate cancer. J Magn Reson Imaging. 2016;43(1):138-48