Manuela Moretto1,2, Erica Silvestri1,2, Marco Castellaro1,2, Mariagiulia Anglani3, Silvia Facchini1,4, Elena Monai1,4, Domenico D'Avella1,4, Alessandro Della Puppa5, Diego Cecchin1,6, Maurizio Corbetta1,4,7, and Alessandra Bertoldo1,2
1Padova Neuroscience Center, University of Padova, Padova, Italy, 2Department of Information Engineering, University of Padova, Padova, Italy, 3Neuroradiology Unit, University of Padova, Padova, Italy, 4Department of Neuroscience, University of Padova, Padova, Italy, 5Department of Neurosurgery, Neuroscience, Psychology, Pharmacology, and Child Health, University of Firenze, Firenze, Italy, 6Department of Medicine, Unit of Nuclear Medicine, University of Padova, Padova, Italy, 7Department of Neurology, Radiology, Neuroscience, Washington University School of Medicine, St Louis, MO, United States
Synopsis
Brain tumors can
alter not only functions located in the perilesional area, but also the distal
ones. Thus, the possibility to inform preoperatively surgeons about the state
of preservation/alteration of a network could be a powerful aid for a better
patient outcome. In this work we used independent component analysis (ICA) to
map resting state networks (RSNs) at the single-subject level characterizing
their alterations in terms of cosine similarity spatial patterns. Comparing the
patient-specific spatial maps with those obtained for a group of healthy
controls, we defined the presence of an alteration for each of the 44 analyzed
RSNs.
INTRODUCTION
Brain tumors are
considered an expansive source in terms of diagnostic and treatment
technologies needed to treat them1. Gross total resection (GTR) is
the gold standard in brain tumor therapy leading to a better patient outcome
and a prolonged survival2. However, GTR needs to be balanced with
brain functions deficits3. Recents studies4,5,6
have proposed resting state (rs) functional connectivity as a tool to map these
functions, but unfortunately they restrict the mapping to eloquent functions
located in the perilesional area, overlooking distal regions that could be altered by brain tumors7. Here
we propose a whole brain approach, based on independent component analysis
(ICA), to identify altered or preserved resting state networks (RSNs), without
a priori localization of the lesion.METHODS
Pre-surgical data
were collected from 18 patients (8F/10M; age 57.88±18.09y) diagnosed with brain
tumors. Healthy controls (HC) consisted of 308 subjects (125F/183M; age
36.96±18.40y) of the publicly available MPI-Leipzig Mind-Brain-Body dataset8.
Patients data were acquired on a 3T Siemens Biograph mMR scanner. The imaging
protocol included a T1-weighted 3D-MPRAGE (TR/TE 2400/3.24ms; TI 1000ms;
1x1x1mm), a 3D-FLAIR (TR/TE 3200/535ms; 1x1x1mm), rs-fMRI scans acquired with
EPI (TR/TE 1260/30ms; 3x3x3mm; 750 volumes; flip angle 68°; MBAccFactor 2; iPAT
0) and two spin echo-EPI acquisitions with opposed phase encoding (TR/TE
4200/70ms; 3x3x3mm). The HC data acquisition protocol is described in8.
In brief, it included a T1-weighted 3D-MP2RAGE (TR/TE 5000/2.92ms; TI1/TI2
700/2500ms), rs-fMRI scans (TR/TE 1400/39.4ms; 2.3x2.3x2.3mm; 657 volumes; flip
angle 69°; MBAccFactor 4) and two spin echo acquisitions (TR/TE 2200/52ms;
2.3x2.3x2.3mm). Imaging data of both groups underwent an analogous structural
and functional pre-processing. For each patient, 3D-FLAIR image was employed to
manually segment the tumor. Structural pre-processing was applied to the T1w
image for the oncological dataset, and to a pseudo-T1w image, obtained by
multiplying the T1w 3D-MP2RAGE image with its second inversion time, for the HC
group. The following steps were performed: bias field correction (N4BiasFieldCorrection9),
skull-stripping (MASS10),
non-linear registration11 to the symmetric MNI 2009c atlas12
excluding the tumor mask as suggested in13. Functional
pre-processing of rs-fMRI data included slice timing14, distortion
(TOPUP15) and motion correction (MCFLIRT16) and non-linear registration to the symmetric
MNI atlas17. Functional pre-processed data were then analyzed with
the GIFT toolbox (http://trendscenter.org/software/gift/). To
achieve a functional parcellation of the main RSNs, we performed a group-level
spatial-ICA with a high number (180) of independent components (ICs) as in18
on a subset of 140 HC. We visually inspected the spatial maps and the power
spectra of the group 180 ICs18,19 and selected 44 RSNs.
The RSNs were then grouped into 9 categories according to their functional
properties: visual (VIS), sensorimotor (SM), auditory (AUD),
cingolo-opercularis (CO), dorsal-attention (DA), fronto-parietal (FP),
default-mode (DMN), cognitive-control (CC), frontal (FR). Starting from the
group ICs we computed RSNs subject-specific spatial maps using the
group-information guided ICA (GIG-ICA) back-reconstruction algorithm20.
For each patient/control and each RSN, the alteration was evaluated with the
cosine similarity measure (CSM), computed between the group and the individual
map within the RSN group mask thresholded with a z-score of 1. To assess the
significance of the RSNs alteration, we performed a statistical test based on
the generation of 50000 random permutations (H0: no difference between the HC
group and patient, significance level=0.1). For each permutation we compared
the CSM distribution of 130 out of 140 HC against the single-patient CSM value,
using a 3 standard deviations threshold to reject H0. Furthermore, the spatial
overlap between the tumor and the altered RSN maps was calculated normalizing
them by the extension of each RSN separately.RESULTS AND DISCUSSION
For each patient, figure 2 shows which of
the RSNs resulted to be altered. Globally, the VIS was altered in 66.67% of all
patients, the SM in 0%, the AUD in 0%, the CO in 33.33%, the DA in 38.89%, the
FP in 83.33%, the DMN in 44.44%, the CC in 83.33%, the FR in 44.44%. Figure 3
shows the spatial map of a representative RSN, obtainedin HC at the group
level, and at the subject level for three patients with different alteration
grades: patient 1 had no alteration, patient 3 a medium level and patient 18 a
high level. Especially for patient 18, it is clear how the presence of the
tumor alters the RSN spatial pattern also in distal areas. As reported in fig
4, the spatial overlap between the tumor and the RSNs resulted to be small
(range: 0-0.44), confirming that the alteration is not only due to the presence
of the lesion in the perilesional area but also at distance.CONCLUSION
The CSM resulted to
be a sensitive index to highlight the variations in RSNs spatial patterns.The
proposed ICA-based approach is able to detect these alterations to better
characterize the functional connectivity at the whole brain level in brain
tumors patients resulting in an additive aid in the pre-surgical planning.Acknowledgements
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