Florian Siedek1, Franziska Grundmann2, Kilian Weiss1, Daniel Pinto dos Santos1, Sita Arjune2, Stefan Haneder1, Thorsten Persigehl1, Roman-Ulrich Mueller2, and Bettina Baessler1
1Radiology, University of Cologne, Cologne, Germany, 2Department II of Internal Medicine, University of Cologne, Cologne, Germany
Synopsis
Novel biomarkers for a more sensitive and quick
assessment of ADPKD patients especially in those cases where kidney function is
still preserved and can be maintained is urgently needed. We analyzed in 139 patients
and 10 healthy controls if magnetic resonance T2 mapping of the kidneys allows
a sufficient differentiation of cyst fraction as a surrogate marker for disease
severity. The new biomarker parenchyma-T2 showed the strongest correlation to renal
cyst fraction and was faster to determine than the established biomarker htTKV.
Consequently, parenchyma-T2 has the potential to serve as a novel predictive
biomarker especially in early stages of disease.
Introduction
The Autosomal
dominant polycystic kidney disease (ADPKD) results in end-stage renal disease
in approximately 75% of patients 1-3 and accounts for about 5-10% of
the dialysis population in Western societies. Risk of progression to end-stage
disease may be highly variable and since compensatory hyperfiltration occurs in
intact glomeruli, ADPKD patients may present with preserved glomerular
filtration rate (GFR) in earlier stages of the disease 4. Thus, detecting
at-risk patients in earlier stages of the disease is crucial to identify those
who may benefit from early therapeutic intervention including targeted
therapies 5. As all currently available biomarkers - including height-adjusted total
kidney volume (htTKV) - have important drawbacks in the everyday clinical setting, the
identification of novel, sensitive and quickly assessable biomarkers is
inevitable to optimize patient care in ADPKD. Franke et al. 6 demonstrated
that T2 values which are strongly dependent on the amount of water present in
tissue showed a significant increase for the whole kidney with increasing
cystic burden. Following this study, we want to evaluate whether magnetic
resonance T2 mapping of the kidneys can deliver easily obtainable and accurate
biomarkers for improved patient counselling and selection of targeted treatment
options. Methods
All patients in
this retrospective study were part of the AD(H)PKD registry (NCT02497521) which
is a prospective observational study recording radiological data apart from
others. In- and exclusion criteria included the diagnosis of ADPKD, typical
renal phenotype of ADPKD (Mayo Class 1), absence of a kidney tumor, sufficient
MR image quality and no medication with Tolvaptan (Fig. 1). In addition
to 139 participants with ADPKD (42.4±12.2 years, 80 women), 10 healthy controls
were included (30.7±5.3 years, 4 women) and underwent MRI on a clinical 1.5T system
(Ingenia, Philips Healthcare, Best, Netherlands) including acquisition of a
Gradient-Spin-Echo (GraSE) T2 mapping sequence covering both kidneys amongst
other clinical sequences.
HtTKV was calculated based on standard T2-weighted imaging. The kidney cyst
fraction was measured in the T2 mapping sequence using the CMRSegTool-plugin 7
(P. Croisille, INSA-Lyon, France) for OsiriX (Pixmeo Sarl, Bernes, Switzerland)
which allows a semiautomatic three-dimensional volumetric registration of the
kidneys and subsequent cyst extraction from the total kidney volume after
manual segmentation (Fig. 2). The rationale for using T2 maps instead of
regular T2-weighted images is that T2 mapping might allow for a better
discrimination between smaller cysts and non-cystic parenchyma (Fig. 3).
The CMRSegTool was also used for calculation of the whole kidney-T2 relaxation time
(kidney-T2) including parenchyma and
kidney cysts. For evaluation of T2 relaxation times of the residual kidney
parenchyma (parenchyma-T2), a single
circular region of interest (ROI, ≈1cm2) was manually placed in residual parenchyma in the images
of the T2 mapping-sequence on three representative slices of the upper, middle
and lower pole in both kidneys using OsiriX (Fig. 2). The results were
averaged over all 6 ROIs.
Also, time needed to
measure each of the three parameters (htTKV, kidney-T2, parenchyma-T2) as well
as intra-reader and inter-reader agreement of parenchyma-T2 was measured.Results
Mean acquisition
time for calculating htTKV was 6-fold faster (4.78±1.17min), for calculating
kidney-T2 10-fold faster (7.59±1.57min) compared to calculating parenchyma-T2 (0.78±0.14min).
Parenchyma-T2
revealed a strong correlation to cyst fraction (r=0.77, p<0.001) and allowed
for the most distinct separation of patient groups divided according to cyst
fraction (Fig. 4). Kidney-T2
(r=0.76, p<0.001) revealed a comparable correlation. In contrast, htTKV
revealed only a moderate correlation to cyst fraction (r=0.48, p<0.001) and
did not allow for clear group separation (Fig.
4). These observations became even more distinct when considering not the
whole collective but only patients with preserved kidney function (Fig. 5): For these patients,
parenchyma-T2 showed indeed a higher correlation to cyst fraction (r=0.81,
p<0.001) which was slightly better compared to kidney-T2 (r=0.79,
p<0.001) with a further improved separation of patient groups according to
cyst fraction (Fig. 5). The correlation
of htTKV to cyst fraction remained poor (r=0.48, p<0.001).
The intra-reader
analysis of parenchyma-T2 showed an excellent agreement with an ICC of 0.97
with a 95%CI of 0.92 and 0.99. The inter-reader analysis of parenchyma-T2 also
revealed a great agreement with an ICC of 0.91 with a 95%CI of 0.77 and 0.96.Conclusion
The T2-value in
the residual parenchyma in ADPKD patients (parenchyma-T2)
allows for a clear and better separation of all cyst fraction groups compared
to whole-kidney T2-values (kidney-T2)
as well as the established imaging biomarker htTKV. Additionally, parenchyma-T2 can be acquired much faster than
htTKV 8 and kidney-T2. Interestingly, parenchyma-T2 seems to be best
suited for disease assessment in patients with preserved kidney function
allowing to easily identify those who may benefit from a unique therapy such as
Tolvaptan. In comparison, htTKV only shows moderate results concerning the
correlation and separation of patients according to cyst fraction making an
early disease assessment less reliable or even impossible.
In terms of test
validation, we found a high consensus between both readers as well as a high
consistency in repeated ratings of a single reader.
In conclusion, considering
that the cyst fraction is the key parameter of ADPKD assessment 9, especially
the rapidly assessable parenchyma-T2 shows a strong association with disease
severity and is far superior to the established imaging biomarker htTKV. Acknowledgements
No acknowledgement found.References
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