Maria Petracca1, Simona Schiavi2, Catarina Saiote1, Lazar Fleysher1, and Matilde Inglese1
1Icahn School of Medicine, New York, NY, United States, 2University of Genoa, Genoa, Italy
Synopsis
Diffuse
white matter (WM) injury is prominent in primary progressive multiple sclerosis
(PPMS). Diffusion Kurtosis Imaging (DKI) allows the quantification of non-Gaussian
water diffusion, offering the possibility of more detailed characterization of
WM damage, in comparison with that provided by diffusion tensor imaging metrics.
Here we
present application of DKI metrics in PPMS using a Tract-Based Spatial Statistics
approach.
We observed
a diffuse WM microstructural damage, manifested as axonal water fraction, mean
kurtosis and fractional anisotropy decrease. In line with histopathological
studies, our results suggest the prevalence of axonal damage over demyelination
in progressive MS.
Purpose
Diffuse
white matter (WM) injury is prominent in primary progressive multiple sclerosis
(PPMS) pathology and is a potential biomarker of disease progression associated
with increase of disability from disease onset. Diffusion Kurtosis Imaging
(DKI) allows the quantification of non-Gaussian water diffusion [1], offering
the possibility of more detailed characterization of WM damage, in comparison
with that provided by traditional diffusion tensor imaging (DTI) metrics, such
as fractional anisotropy (FA) and mean diffusivity (MD).
In this work we present for the first time a validation of DKI metrics
in PPMS using a Tract-Based Spatial Statistics (TBSS) approachMethods
26 PPMS
patients (14F, mean age 50.92±10.30 years, median Expanded Disability Status
Scale-EDSS 4.0, EDSS range 1.5-6.0) and 20 healthy controls (HC) (11F, mean age
51.05±9.80 years) were enrolled for this study. DKI single-shot EPI images
where acquired on a 3T Achieva scanner, Philips with a voxel size of 2×2×2 mm3,
30 directions for each b-values=1000,2000s/mm2 and one b=0s/mm2.
Diffusion
and Kurtosis tensors were calculated using Diffusional Kurtosis Estimator (DKE)
software [2], to obtain FA, MD and mean kurtosis (MK) spatial maps. A
2-compartment biophysical model of WM fiber bundles was used to derive spatial
maps of axonal water fraction (AWF), intra-axonal diffusivity (Daxon),
extra-axonal axial diffusivity (De||), extra-axonal radial diffusivity (De┴)
and tortuosity of the extra-axonal space spatial maps. Voxelwise statistical
analysis of the DTI metrics was carried out using TBSS [3], part of FSL. Non-parametric
permutation inference using randomise was used for voxelwise statistics (5000
permutations, TFCE, p=0.05).Results and Discussion
The comparison of PPMS and HC disclosed the presence
of a widespread decrease in FA, MK and AWF in body of the corpus callosum,
right anterior thalamic radiation, inferior longitudinal fasciculus, inferior
fronto-occipital fasciculus, posterior thalamic radiation and optic radiation.
Similar findings were identified for tortuosity,
mainly right lateralized, with decrease in body and splenium of the corpus
callosum, posterior thalamic radiation, right anterior limb of internal capsule
and bilateral posterior internal capsule.
MD was increased in the splenium of the corpus
callosum, posterior thalamic radiation, optic radiation and inferior
fronto-occipital fasciculus.
Significant decrease in Daxon was detected in right anterior and
posterior limbs of the internal capsule, right cerebellar peduncle, right
anterior corona radiata, and left posterior thalamic radiation.
No significant changes were detected in De|| and De┴.Conclusion
Damage of
WM microstructure in PPMS patients was observed in most WM tracts, mainly
manifested as AWF, MK and FA decrease. Our results suggest, in line with histopathological
studies [4], the prevalence of diffuse chronic axonal damage over demyelination
in the progressive phenotype. AWF and Mean Kurtosis appear to be the most
sensitive metrics to tissue damage while De|| and De┴ seem to be the least sensitive.Acknowledgements
NMSS RG 5120A3/1References
[1] Lu H,
Jensen JH, Ramani A, Helpern JA. Three-dimensional characterization of
non-Gaussian water diffusion in humans using diffusion kurtosis imaging. NMR
Biomed. 2006 Apr;19(2):236-47.
[2] Tabesh
A, Jensen JH, Ardekani BA, Helpern JA. Estimation of tensors and tensor-derived
measures in diffusional kurtosis imaging. Magn Reson Med. 2011
Mar;65(3):823-36.
[3] Smith
SM, Jenkinson M, Johansen-Berg H, Rueckert D, Nichols TE, Mackay CE, Watkins
KE, Ciccarelli O, Cader MZ, Matthews PM, and Behrens TEJ. Tract-based spatial
statistics: Voxelwise analysis of multi-subject diffusion data. 2006 Jul
15;31(4):1487-505.
[4] Lassmann
H, van Horssen J, Mahad D. Progressive multiple sclerosis: pathology and
pathogenesis. Nat Rev Neurol. 2012 Nov 5;8(11):647-56