Petra Hnilicová1, Ema Kantorová2, Hubert Poláček 3, Štefan Sivák2, Michal Bittšanský1, Kamil Zeleňák4, Egon Kurča2, and Dušan Dobrota 5
1Division of Neurosciences, Biomedical Center Martin, Jessenius Faculty of Medicine in Martin, Comenius University in Bratislava, Martin, Slovakia, 2Clinic of Neurology, Jessenius Faculty of Medicine in Martin, Comenius University in Bratislava, Martin, Slovakia, 3Clinic of Nuclear Medicine, Jessenius Faculty of Medicine in Martin, Comenius University in Bratislava, Martin, Slovakia, 4Clinic of Radiology, Jessenius Faculty of Medicine in Martin, Comenius University in Bratislava, Martin, Slovakia, 5Department of Medical Biochemistry, Jessenius Faculty of Medicine in Martin, Comenius University in Bratislava, Martin, Slovakia
Synopsis
Multiple sclerosis (MS)
is considered as an autoimmune disease with expanding axonal and neuronal
degeneration in the spinal cord or cerebral cortex during the acute MS phase.
The hypothalamus (HYP) is often overlooked yet controls important homeostatic functions.
This 1H MRS study performed on 1.5 T MR scanner using 3D CSI
with 10×10×12.5 mm3 voxels was focused to altered HYP
metabolism in early MS. Considering our results, increased Glx ratios with
reduced mIns and tNAA ratios in HYP suggested glutamate excitotoxicity
associated with glial activity and neuronal damage. This indicated that HYP
plays an important role in early disease evolution.
INTRODUCTION
Multiple Sclerosis (MS)
is believed to result from a cell-mediated autoimmune response that initiates
myelin loss, axonal as well as neuronal damage and in the acute phase of
disease evolution leads to the progressive neurological dysfunction1,2. Signs and symptoms of MS
are usually attributed to demyelinating lesions across the white matter (WM)2,3. However, recent research
has shown that the neurodegenerative process is rather associated to extremely
complex neuro-axonal pathologies4,5. It is also proposed that deep gray matter
(DGM) is injured initially with high extension in the early stage of MS2,6. One of
the most essential DGM regions affected by MS is hypothalamus (HYP), which is involved
in many necessary body processes including
behavioral, autonomic and endocrine functions, such as metabolism, development,
and some fundamental systemic regulations (e.g. circadian rhythms, blood
pressure, thermoregulation)1,5,7.METHODS
To the study were enrolled 31 adult patients (27±6
years of age, 12 men/19 women) in early stage of MS and 31 age- and gender-
matched healthy volunteers. Measurements were performed on a 1.5 T
whole body MR scanner Magnetom Symphony using the 8-channel head coil for
signal reception (Siemens, Erlangen, Germany). The
study protocol contained T2-weighted and
FLAIR MRI sequences, anatomical T1-weighted
MP-RAGE scanning and B0 phase mapping
enabling to reach the eligible volume shimming (Figure 1), directly in the hypothalamic area outside of any B0
distortions visible on the B0 map. For 1H MRSI data
acquisition was used 3D CSI (PRESS, TR/TE=1500/30 ms, NA=4,
FOV=100×100×100 mm3, VOI=50×60×35 mm3) with
10×10×12.5 mm3 nominal voxel size (10×10×8 CSI grid
interpolated to 16×16×8 matrix) and total acquisition time of 7min 42s. In post-processing
(Figure 2), the two required CSI
voxels were placed in the right and left hypothalamus using jSIPRO interface
(Jiru & Skoch, Czech Republic). Spectra were evaluated in LCModel
software (S. Provencher, Canada) for obtaining integrals of N-acetylaspartate
with N-acetyl-aspartyl-glutamate (tNAA),
creatine containing compounds (tCr), glutamate with glutamine (Glx),
and myo-Inositol (mIns). All
MR spectra fulfilled defined spectral quality criteria, i.e.
spectral SNR ≥ 10 and the FWHM of tNAA peak ≤ 10 Hz.
Finally, differences in metabolite ratios (tNAA/tCr, Glx/tCr, Glx/tNAA, mIns/tCr, and mIns/tNAA) between patients and controls were evaluated using
paired-samples two-sided t-test
in SPSS software (Chicago, USA). The p-value <0.05 was considered
significant.RESULTS
In HYP of early MS
patients compared to the healthy controls were found
highly increased Glx metabolite ratios in contrast to significantly lower
tNAA/tCr (Table). Although, no group
differences were observed in mIns/tCr, the mIns/tNAA ratio was significantly
elevated for the MS group.DISCUSSION
Increased Glx ratios in HYP of MS patients may
reflect obvious glutamate excitoxicity which seems to be the most pronounced
pathology affecting the neurodegenerative processes in early stage of disease4,5,7. It is linked with
decline of tNAA ratios indicating axial and neuronal dysfunction and/or loss2,6.
Excessive glutamate concentrations may also affect
neuroglial homeostasis and cause microglial activation, both
associated with increased
mIns ratios2,5. Since tCr
and mIns are considered to be glial and tNAA neuronal markers2,3,4 the results postulated
slightly initiation of gliosis, whereas neurodegeneration occurs very
progressive. The involvement of HYP to MS pathology can explain
physiologic homeostasis instability, physical disability, and cognitive
impairment of patients, even in early MS stage1,7.CONCLUSION
Considering our results, during the early MS progression,
hypothalamic tissue shown increasing glutamate excitotoxicity causing marked
neuronal loss and slow glial activation. Therefore, there is a potential for
Glx ratios to be used as a marker of the progression and severity of MS, even
in patients at early stage of diseases. Furthermore, it is shown up that the
underlying pathological processes in DGM during MS are different from WM damage
and it is necessary to continue in further investigations.Acknowledgements
This
study was supported by the projects: “Biomedical Center Martin, ITMS: 26220220187“,
APVV-14-0088, and VEGA 1/0287/16, co-funded from
EU sources and European Social Fund.References
- Messina S, Patti F. Gray
Matters in Multiple Sclerosis: Cognitive Impairment and Structural MRI.
Mult Scler Int. 2014.
- Sajja BR, Wolinsky JS, Narayana PA. Proton Magnetic Resonance Spectroscopy in
Multiple Sclerosis. Nuroimaging Clin N Am. 2009; 19(1): 45-58.
- Ruiz-Peña JL, Piñero P, Sellers G, et al. Magnetic
resonance spectroscopy of normal appearing white matter in early
relapsing-remitting multiple sclerosis: correlations between disability and
spectroscopy. BMC Neurology. 2004; 4:8.
- Macrez R, Stys PK, Vivien D, et al. Mechanisms of glutamate toxicity in
multiple sclerosis: biomarker and therapeutic opportunities. Lancet Neurol. 2016;15(10):1089-102.
- Deckx N, Lee WP, Berneman ZN, Cools N. Neuroendocrine Immunoregulation in Multiple
Sclerosis. Clin Dev Immunol. 2013.
- Hulst HE, Geurts JJG. Gray matter imaging in multiple sclerosis: what have
we learned? BMC Neurology. 2011;
11:153.
- Zivadinov R, Pirko I. Advances in understanding gray matter
pathology in multiple sclerosis: Are we ready to redefine disease pathogenesis? BMC Neurol. 2012; 12: 9.