Subechhya Pradhan1,2,3, Kushal Kapse1, Reka Kovacs1, Linda White1, and Catherine Limperopoulos1,2,3
1Developing Brain Research Laboratory, Children's National Health System, Washington, DC, United States, 2Diagnostic Imaging and Radiology, Children's National Health System, Washington, DC, United States, 3Pediatrics, The George Washington University School of Medicine, Washington, DC, United States
Synopsis
Knowledge of metabolite
changes in the fetal brain will provide insight into the biochemical changes in
the developing brain. Findings from measurement of metabolite concentration as
a function of increasing GA are reported.
Significant increases in NAA, Cr, Cho and scyllo-Inositol with
increasing GA in the fetal brain was observed in this study. Changes in myo-Inositol with GA did not reach
significance.
Introduction
Information
about the emerging metabolic profile in the human fetal brain can provide critical
insights into the chemical maturational changes that take place in the womb. However, currently there is limited
information available to delineate the normal biochemical evolution of
important metabolites in the fetal brain as a function of advancing gestational
age (GA). N-acetyl aspartate (NAA) is a
neuronal marker, creatine (Cre) is a marker of energy-dependent systems in the
cell, choline (Cho) is a marker of cell membrane turnover, myo-inositol (mI) is
an osmolyte and essential for cell growth and scyllo-inositol is a naturally occurring
stereoisomer of inositol. NAA has been
shown to increase with increasing GA and rapidly during the first 2 years of
life (1), some studies have used Cre or Cho as a
reference metabolite (2,3) to study metabolite ratios across different GAs in
neonates. The purpose of this study was to investigate the normative trajectory
of fetal brain biochemical evolution in the second half of gestation using
serial in vivo fetal MR spectroscopy.
Methods
157 healthy pregnant
women were scanned during the second and third trimester of pregnancy with GA
ranging from 18 to 39 weeks on a 1.5T GE scanner using protocols approved by our
Institutional Review Board. 92 fetuses were scanned twice at a mean GA of 27(±4)
and 35(±3) weeks of gestation at the first and second MRI scan,
respectively. SSFSE images acquired in
all three planes were used as a guide to place the voxels in the central brain
of the fetal brain for spectroscopic measurements. Spectra were acquired using
PRESS localization sequence (TE/TR: 144/1500 ms). 128-192 averages of water suppressed spectra
were acquired along with 16 averages of water unsuppressed spectra from a
30x30x30 mm3 voxel placed in the central brain. Phase and frequency correction were performed
using programs written in Matlab and spectra were quantified in the ‘LCModel’ (4) program using water as an internal
reference. Data with CRLB >20% for
total Choline (tCh) were excluded from further analysis. For all other metabolites, exclusion criteria
included CRLB>100%. Given that NAA
and Cre concentrations are lower at early GAs, exclusion criteria of
CRLB>100% was used in this study which is higher than 20% that has
traditionally been used to avoid biasing the metabolite concentrations to
higher values (5). Statistical analysis included linear
regression to assess metabolic trajectory as a function of GA and a paired
t-test to study the trajectory within subject. Results
Figure 1 shows
voxel placement and LCModel analysis result of a typical spectrum acquired from
the fetal brain. NAA, Cre, Cho and mI
were consistently measured in > 85% of the spectra. Table 1 shows averaged
metabolite concentration during the two visits in pregnant women who underwent
two sets of MRI scans. The preliminary results
showed significantly increased NAA, Ch, Cre and scyllo-Inositol with increasing
GA in both set of analyses. No significant
difference was observed in mI concentration across different GAs. All fetuses
had a structurally normal brain MRI study.Discussion
Our results are in
keeping with existing literature describing metabolic changes in the fetal and neonatal
brain studied at one time point (6,7). This is the first study to delineate metabolite changes within
the same fetus as a function of in utero third trimester brain maturation. We
also report for the first time on the presence and evolution of scyllo-inositol
levels in the fetal brain. We currently have an ongoing validation study
underway to evaluate the reproducibility of this metabolite measurement in the
developing brain. Although the exact
function of scyllo-inositol in the human brain is poorly understood it has been
observed to be tightly coupled with mI concentration in the adult brain and could
likely be involved in cellular growth. Extracting
information about its levels and role in the immature developing warrants
further study.
Conclusion
This study
demonstrates that high quality MRS data can be successfully acquired from the
fetal brain with a success rate of 85%. Information about normative levels of
metabolites and expected trajectory in a healthy developing brain may help
identify the compromised fetus that is showing deviations from normal biochemical
development in-utero and lead to better surveillance in the high-risk
pregnancy.
Acknowledgements
Supported
by NIH R01HL116585-01References
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