Lena Vaclavu1, Zelonna Baldew1, Sanna Gevers1, Veronica van der Land2, Henri JMM Mutsaerts3, Karin Fijnvandraat2, John C Wood4, Charles BLM Majoie1, Ed T vanBavel5, Bart J Biemond6, Aart J Nederveen1, and Pim van Ooij1
1Radiology, Academic Medical Center, Amsterdam, Netherlands, 2Pediatric Hematology, Emma Children's Hospital, Academic Medical Center, Amsterdam, Netherlands, 3Sunnybrook Research Institute, Toronto, Canada, 4Cardiology, Children's Hospital Los Angeles, Los Angeles, CA, United States, 5Biomedical Engineering and Physics, Academic Medical Center, Amsterdam, Netherlands, 6Internal Medicine, Hematology, Academic Medical Center, Amsterdam, Netherlands
Synopsis
Hemodynamic
parameters such as wall shear stress(WSS) may be adversely affected in Sickle
Cell Disease(SCD). Vaso-occlusion is a common complication leading to ischemic
organ damage. We investigated how impaired hemodynamics (velocity, WSS, flow
and lumen area) relate to ischemic white matter lesions(WMLs). Our aim was to
quantify age-related changes in hemodynamics and to investigate their
relationship with WMLs. 14 controls and 69 patients underwent 4D-flow MRI. We
assessed intracranial velocity, WSS, flow and lumen area in the circle of
Willis. We show that 4D-flow parameters are decreased in patients with WMLs,
but age is an important factor in this relationship.
Introduction
Wall
shear stress (WSS) is the force exerted on vascular endothelial cells by blood
flow, and is an important factor in autoregulation. In Sickle Cell
Disease (SCD), adhesive forces between blood cells and their aggregates with the
vessel wall facilitate vaso-occlusion1 and require high shear stress
for removal from the endothelial wall2. In parallel to painful vaso-occlusive
episodes, at least 30% of SCD patients have ischemic cerebral white matter
lesions (WMLs)3. We investigated the relationship between impaired
hemodynamics (low velocity, WSS, flow) and WMLs. Hemodynamic parameters are
known to be age-dependent4, hence our aim was also to quantify the age-related
range of intracranial hemodynamic parameters velocity, flow, WSS, and lumen
area, in patients and controls. We hypothesized that patients with WMLs have
impaired hemodynamics on the aforementioned parameters measured with 4D-flow
MRI.Methods
14
healthy controls (median[IQR] age: 20[18–43], 8 male)and 69 patients (median[IQR]
age: 15[11–23], 42 male) were included based on genotype(HbSS/HbSb0), informed consent, and age(8-60years). Hematocrit(Hct) measurements from
blood were used to calculate patient-specific viscosity values(figure 1A), based on shear rates5
derived from 4D-flow MRI, and hence, 3D WSS estimation6 incorporated
subject-specific blood viscosity. All subjects underwent 4D-flow MRI and patients
separately also had standard clinical FLAIR MRI at 3T (Intera/Ingenia, Philips
Healthcare, Best, The Netherlands) with an 8/16/32-channel receive head-coil
and body-coil transmission. FLAIR MRI images were used to score white matter
lesions7. 4D-flow images were acquired in the circle of Willis with
retrospective cardiac gating over four cardiac phases, TE/TR=3.2/6.5ms, flip
angle=15-20º, VENC=100cm/s in three principal directions, spatial resolution=0.5mm3,
slices=30-36 and scan duration=5-8mins. Background phase offset correction was
performed automatically on the MR system. Data post-processing included vessel segmentation
in Mimics(Materialise, Leuven, Belgium) using magnitude images at the timeframe
with the highest signal intensity. Data were unwrapped and time-averaged
velocity, WSS and diameter values were calculated in Matlab. Segments of
interest included the middle cerebral artery, anterior cerebral artery, and the
proximal internal carotid artery(figure
1B). Flow and lumen area were computed in single cross-sections placed
perpendicular to the vessels of interest in GTFlow software(Gyrotools, Zurich,
Switzerland). Statistics included t-test and ANOVA with age as covariate for
group comparisons, exponential fit to assess age-related changes associated
with 4D-flow MRI parameters: velocity, WSS, flow and lumen area. Linear
regression was used to model WMLs with age and WSS data, while correlation coefficients
were calculated to assess the strength and direction of the relationships
between age/WSS/velocity and WMLs.Results
Subject characteristics are provided in table 1, which furthermore shows that time-averaged
velocity, flow and lumen area were significantly higher in patients. WSS was
lower in patients, but only when age was included in the ANOVA analysis. R-values
for the exponential fit of 4D-flow parameters with age are given in the final
column. This age-related change in 4D-flow parameters is shown in figure 2 for the MCAs. FLAIR images in figure 3A show a young patient without
WMLs and an elderly patient with many WMLs. Their respective WSS maps are shown
in 3B, revealing lower WSS in the
older patient with more WMLs. There was a significant inverse relationship
between mean WSS of the ICA, MCA and ACA vessels and WMLs, as shown in figure 3C(r=-0.43,p<0.001). WMLs were
also inversely related to mean velocity of the ICA, MCA and ACA(r=-0.50,
p<0.001, figure 3D). However, WMLs
also correlated significantly with age (r=0.74,p<0.001,3E). ANCOVA revealed that although there were significant effects
of mean velocity (p<0.001) and mean WSS (p=0.02) alone on WMLs, mean WSS was
no longer significantly associated with WMLs when age was accounted for (p=0.49),
similarly, mean velocity was not associated with WMLs when corrected for age (p=0.17).
This is revealed in table 2, which
provides correlation coefficients and age-corrected coefficients for individual
vessels of interest.Discussion
Our findings
show that lumen area was not associated with age in patients. Velocity, flow
and WSS showed an age-dependent decline, with an initial steep decline in late
childhood, as previously reported in healthy subjects4. The large
variation around the age of 10 may reflect the age of high risk for overt
stroke, which is reported in literature at age 9, and is associated with high Transcranial
Doppler velocities8. WSS and velocity were individually associated
with WMLs, but this relationship was lost when age was taken into account. Conclusion
Age is an
important factor when comparing patients with controls on hemodynamic 4D-flow
MRI parameters, and while white matter damage appears to coincide with low
velocity and low WSS in SCD patients, age is a significant factor precluding
the direct establishment of a causal relationship.Acknowledgements
Fonds Nuts Ohra (Dutch Foundation)References
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