Stephan Duewel1,2,3, Christian Hundshammer1,2, Malte Gersch4, Benedikt Feuerecker1, Axel Haase3, Steffen J Glaser2, Markus Schwaiger1, and Franz Schilling1
1Department of Nuclear Medicine, Technical University of Munich, Munich, Germany, 2Department of Chemistry, Technical University of Munich, Garching, Germany, 3Institute of Medical Engineering, Technical University of Munich, Garching, Germany, 4Medical Research Council Laboratory of Molecular Biology, Cambridge, United Kingdom
Synopsis
Pathologies which overrule natural pH
regulatory mechanisms such as ischemia, inflammation or tumors can trigger
local pH changes in the human body. Currently, clinical routine measurement of extracellular
pH is limited to measuring systemic blood pH. We synthesized, characterized,
calibrated and applied [1,5-13C2]zymonic acid (ZA) as a
novel hyperpolarized 13C pH biosensor. With its demonstrated
features both in vitro and in vivo (bladder, healthy kidney, Mat B III adenocarcinoma),
we believe that ZA could help localize and quantify regions with aberrant
acid-base balance, allowing for improved understanding, diagnostics and therapy
of common diseases.
Introduction
Local pH changes in the human body are often triggered by pathologies that
overrule natural pH regulatory mechanisms, such as ischemia, inflammation or tumors1-3. However,
clinical routine measurement of pH is currently limited to measuring the systemic blood pH by blood gas analysis.
A reliable and non-invasive pH imaging method could localize and quantify
regions with aberrant acid-base balance, allowing for improved understanding,
diagnostics and therapy of common diseases4. Although many
non-invasive pH-imaging methods have been developed, only methods to measure the intracellular pH have successfully passed
beyond preclinical studies. Here we report hyperpolarized [1,5-13C2]zymonic
acid (ZA)5,6 as a novel sensor
molecule for in vivo measurements of pH using 13C magnetic resonance imaging.Methods
ZA
is synthesized from [1-13C]pyruvic acid in a one-step-synthesis, purified using reversed phase HPLC and freeze dried in vacuo. Its structure is confirmed using mass spectrometry (HR-MS-spectrum using a Thermo Finnigan LTQ-FT) and high-field NMR (14.1 T Avance III Bruker BioSpin). ZA is copolarized (Hypersense, Oxford Instruments) together with [13C]urea being used as a chemical shift
reference and both are injected into phantoms in vitro either for calibration experiments or in order to test for the method's robustness. Hyperpolarized spectra and images are acquired on a 7T small animal MR scanner (GE/Agilent) with a 72 mm dual tuned 1H/13C birdcage coil for signal transmission and a two channel 13C flexible coil receive array (Rapid Biomedical). 1H images are acquired with a fast spin echo (FSE) sequence, 13C imaging experiments are performed using a free induction decay chemical shift imaging (FIDCSI) sequence (5 kHz bandwidth, 512 points, 16×16 nominal matrix size, 5 mm slice thickness, 6 cm FOV, 4° flip angle, 118 ms repetition time, 208 excitations, k-space sampled in centric order) and reconstructed by zero-filled Fourier transform in three dimensions in Matlab (MathWorks)7. Electrode pH values were recorded with a standard pH electrode (ProLab 4000, SI Analytics). Animals were anesthetized with 3-5% isoflurane. Tumors are induced by injecting 200 µL PBS containing 1×106 Mat B III tumor cells subcutaneously into the right flank. Copolarized ZA and [13C]urea are injected in vivo directly into the rat bladder or via tail vain catheter before acquiring localized spectra. pH
sensitive 13C chemical shift differences between the fitted ZA
peak pair and urea are being used to back calculate up to three pH values per voxel on a
voxel-by-voxel basis using a scaled logistic function.Results & Discussion
ZA's pH sensitivity
in the physiological range is due to the value of its second acid dissociation
constant pKa2 =
6.90 while ZA's changes in chemical shift can conveniently be modelled and
fitted by a scaled logistic function (Fig. 1). pH measurements using ZA are
demonstrated both in buffer phantoms and blood, and are robust towards changes
in temperature and possible complexation by calcium ions (Fig. 2). Measurements
using ZA in the rat bladder result in a pH of 6.48±0.02 (n = 9 pixels, mean±s.d.), in good agreement with the pH of 6.55±0.01
determined via pH electrode in the urine, sampled from the bladder directly
after the MR measurement (Fig. 3). pH measurements in the kidneys of healthy
rats showed up to three pairs of ZA peaks within the same voxel forming three
pH clusters with a pH of 7.40±0.01, 6.94±0.05 and 6.55±0.03 (n = 4 rats,
mean±s.d., Fig. 4). Based on literature values8,
the pH clusters were attributed to the cortex, medulla and calyx/ureter,
reflecting the transition effects of the blood pH before, during and after
processing, filtering and renal metabolism. Measurements in Mat B III
adenocarcinoma tumors resulted in an acidic tumor compartment of pH 6.94±0.12 (n = 5 rats, mean±s.d.), a neutral tumor compartment of pH 7.40±0.05 (n = 5 rats, mean±s.d.) and a neutral pH of 7.39±0.05 (n = 5 rats,
mean±s.d.) near the vena cava (Fig. 5).Conclusion
We synthesized, characterized, calibrated and applied ZA as a novel
hyperpolarized 13C pH biosensor in vitro and in vivo.
Electrode pH and 13C pH measurements in phantoms under various conditions
are reproducible, they correlate well in urine within the rat bladder and the detected clusters of pH values in the
kidney agree with data reported in
literature from cortex, medulla and calyx/ureter. Mat B III tumors show an acidic compartment in line with the Warburg effect9. Given the robustness of the presented pH imaging approach, ZA's low toxicity and the diagnostic value of imaging pH in the context of tumors, ischemia or inflammation, we believe that our novel pH reporter molecule could prove valuable for studying many biological phenomena.
Acknowledgements
EU
Grant No. 294582 (MUMI), BMBF (FKZ 13EZ1114), DFG (SFB 824)References
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