Richard Mair1,2, Alan Wright1, Colin Watts2, and Kevin Brindle1
1CRUK Cambridge Institute, University of Cambridge, Cambridge, United Kingdom, 2Division of Neurosurgery, Cambridge University Hospitals NHS Trust, Cambridge, United Kingdom
Synopsis
Heterogeneity at both a genomic and phenotypic
level is extant within glioblastoma. We hypothesised that imaging
of the flux from hyperpolarised [1-13C]pyruvate to [1-13C]lactate
may inform upon this heterogeneity. We used patient derived orthotopic
xenograft cohorts to identify differential lactate labelling and have related
this to both glycolytic enzyme and c-Myc expression.
Introduction
Cancer
progression and response to treatment depends on the interplay between tumor
genotype and microenvironment. Modern genomic techniques are being used for in vivo genotype analysis however the
ability to identify phenotype, such as highly glycolytic tumor regions, may
enable the deployment of novel therapeutics as well as more precise targeting
of heterogeneous areas within a tumor for radiotherapy (1,2). We have
explored the extent to which 13C hyperpolarised MRSI can interrogate
tumor metabolic phenotype (and underlying genotype) within cohorts of
patient-derived orthotopic xenograft (PDOX) models of glioblastoma (GB). We
have demonstrated metabolic heterogeneity that correlates with expression of
c-Myc and glycolysis-related enzymes, which has implications for
prognostication and targeted therapy.Methods
PDOX
cohorts were generated from samples taken at surgery from 5 GB patients
(GB1-5). Samples were passaged in vitro
in serum-free conditions before orthotopic implantation into nude rats. Tumor
latency was between 4 and 12 months with expression of nestin in vitro and GFAP in vivo further distinguishing these tumors from commercially
available cell line derived tumor models (3). 13C magnetic resonance spectroscopic imaging (MRSI)
was used to measure the [1-13C]lactate/[1-13C]pyruvate
ratio (LPR) in tumor regions following injection of 184 mM hyperpolarized [1-13C]pyruvate.
Excised brain tissue was analysed using immunohistochemistry (IHC) and western
blotting to identify correlations between glycolytic enzymes and transporters
expression, intracellular signalling molecules and lactate labeling.
Multi-region samples from four patients with GB were analysed for correlations
between glycolytic enzyme expression and intracellular signalling molecules. Results
We
demonstrated consistency within, and differences between, PDOX tumors in terms
of both latency and histological appearance as well as LPR over the tumor
region (Fig. 1). High LPR correlated with increased expression of c-Myc, LDHA
and HK2 but did not with cell turnover (Ki67/TUNEL staining) (Fig. 2). IHC
demonstrated increased plasma membrane expression of MCT1 and MCT4 in tumors
with increased LPR (Fig. 3). One PDOX cohort had low LPR despite high c-Myc,
LDHA, HK2 and MCT plasma membrane expression. This cohort demonstrated
significantly higher hypoxia (HIF1α expression) compared to the other cohorts.
Induction of hypoxia (via treatment with bevacizumab – a monoclonal antibody to
VEGF A) in a previously high LPR cohort also produced a significant reduction
in LPR (Fig. 4). Analysis of multiple regions from GB tumors in 4 different
patients identified significant heterogeneity in c-Myc, HK2 and LDHA expression.
The correlation between c-Myc, LDHA and HK2 expression observed in the PDOX
models was also observed in the different tumor regions of these 4 patients
(Fig. 5 a+b).Discussion
We
have used hyperpolarised [1-13C]pyruvate to reproducibly interrogate
metabolic flux in biologically apposite PDOX models of GB and thus identify
distinct metabolic phenotypes. These phenotypes correlated with c-Myc, LDHA and
HK2 expression alongside plasma membrane expression of MCT1 and MCT4 in vivo suggesting that labeling of
lactate with a hyperpolarized 13C label provides a surrogate measure
of glycolytic flux in these tumors. The ability to identify differential tumor
metabolism in vivo may enable
prognostication as well as the delivery of precision therapy (2). Moreover this technique may demonstrate areas of metabolic
heterogeneity within as well as between tumors. This would enable alternate
radiotherapy doses to be targeted to regions demonstrating high glycolysis, and
putative radio-resistance. Tumor hypoxia has previously been shown to reduce
LPR within tumors responding to bevacizumab (4). This likely represents a reduction in pyruvate delivery with a
subsequent reduction in label exchange.Conclusion
We
have identified circumstances whereby hyperpolarised [1-13C]pyruvate
imaging could identify tumor metabolic phenotypes in vivo. This may enable patient metabolic stratification and also
the targeting of radiotherapy alongside the use of precision medicines.Acknowledgements
CRUK Cambridge institute core facilities
Neuro oncology team at Cambridge University Hospitals NHS Foundation Trust
Funding: CRUK/Addenbrooke's Charitable Trust
References
1. Chang, S. M. et al. Integration
of preoperative anatomic and metabolic physiologic imaging of newly diagnosed
glioma. J Neurooncol 92, 401–415 (2009).
2. Tateishi, K. et al.
Myc-driven glycolysis is a therapeutic target in glioblastoma. Clinical
Cancer Research 1–40 (2016). doi:10.1158/1078-0432.CCR-15-2274
3. Lee, J. et al.
Tumor stem cells derived from glioblastomas cultured in bFGF and EGF more
closely mirror the phenotype and genotype of primary tumors than do
serum-cultured cell lines. Cancer Cell 9, 391–403 (2006).
4. Bohndiek, S. E.,
Kettunen, M. I., Hu, D.-E. & Brindle, K. M. Hyperpolarized (13)C
spectroscopy detects early changes in tumor vasculature and metabolism after
VEGF neutralization. Cancer Research 72, 854–864 (2012).