David A Edmondson1,2, Sébastien Hélie3, and Ulrike Dydak1,2
1School of Health Sciences, Purdue University, West Lafayette, IN, United States, 2Department of Radiology and Imaging Sciences, Indiana University School of Medicine, Indianapolis, IN, United States, 3Department of Psychological Sciences, Purdue University, West Lafayette, IN, United States
Synopsis
Manganese (Mn) is a
neurotoxin that can lead to symptoms similar to Parkinson’s disease. Welders exposed
to welding fume can accumulate quantities of Mn in their brain eliciting T1 contrast
effects. Mn exposure estimates are useful for determining a welder’s risk for
symptoms, but quantifying Mn in the brain would be more beneficial. While R1
(1/T1) is proportional to local Mn accumulation, the relationship is likely non-linear,
complicating interpretation of R1. Therefore, we propose a support vector
machine model using whole-brain R1 maps to predict classes as determined by
group, Mn air exposure, and excess brain Mn accumulation.
Introduction
Mn,
a T1 contrast agent, accumulates in the brains of welders when being exposed to
occupational levels of Mn contained in welding fume. Consequently, T1-W images
taken during magnetic resonance imaging (MRI) scans (Figure 1) reveal hyperintensities primarily in the basal ganglia,
but also in cortical grey and white matter. Although it is widely assumed that
R1 (1/T1) is proportional to Mn accumulation, previous studies1,2 suggest that the relationships between Mn exposure, Mn accumulation, and changes in R1 are likely non-linear. To better understand
these relationships, we used R1 maps to predict Mn exposure and Mn deposition
in the brain using a series of support vector machine models.Methods
Data was used from a
prior study involving 89 subjects (57 welders, 32 controls). Scans were
performed on a 3T GE Signa MRI scanner (GE Healthcare) using an 8-channel head
coil. Whole brain 3D R1 relaxation maps were calculated from two spoiled
gradient echo images resulting in a quantitative measure of Mn deposition in
the brain3. R1 maps were then segmented into 192 regions
using Freesurfer. The distribution of R1 in each region (Figure 2) was summarized by five statistics: mean, variance, skew,
minimum, and maximum. Three targets were predicted using R1: study group (welder or control), 8-hr time
weighted average of Mn exposure (MnTWA), and Excess Mn (MnEX) in the brain.
MnTWA was calculated using acquired air samples from the workplace and
accounting for factors that reduce the total amount of Mn inhaled into the
lungs4. MnEX was calculated from a biokinetic model5 that predicted Mn accumulation in the brain given MnTWA
and a detailed work history for each subject. Finally, data analysis was
performed using Python’s Scikit-Learn machine learning module6. A support vector machine was used for
classification (SVC) at increasing thresholds in MnTWA and MnEX for each
summary statistic using a penalty term to account for unbalanced classes. Leave one out
cross-validation was used to measure accuracy of each SVC. Finally, for each
threshold, SVCs for each summary statistic were aggregated and the final
prediction was determined by a majority rule. Accuracy was used as a final
performance measure.Results
Individual and aggregated
prediction accuracies are found in Table 1. We found that
while individual statistics performed slightly better than chance, the
aggregated SVC model for predicting welder or control (study group) was about 74% accurate. Overall, we had better prediction accuracy for SVC models
targeting MnTWA and MnEX (Figure 3)
in differing threshold levels. For MnTWA, accuracy greater than 80% was found for
air exposure levels of 0.13, 0.14, and 0.15 mg/m3. MnEx performed a
little poorer overall but had accuracies greater than 80% for a threshold
greater than or equal to 10 mg. Discussion
Results
indicate that we have the ability to use R1 maps to predict Mn exposure in
subjects with reasonably high accuracy. While a SVC model was able to
discriminate between welders and controls fairly well three-quarters of the
time, better accuracies were found when we separated the groups based on
exposure or excess Mn in the brain. In the MnTWA model, subjects exposed to air
Mn concentrations greater than 0.11 mg/m3 had larger signatures that
allowed the SVC to classify with greater accuracy, suggesting that Mn
accumulation in the brain can be readily seen in the brain at these levels.
When looking at separate statistics, minimum is a better predictor in lower
thresholds while skew and maximum are better predictors in higher thresholds. The
slightly lower level of performance of the MnEX model may reflect a difference
in the storage location of Mn in the brain. Mn that is bound to macromolecules or stored in cells may not readily affect R1 as
well as free Mn7,8. Therefore, while our model may predict the amount of excess Mn
in the brain, it does not predict the amount of free Mn and thus, a more complex biokinetic model may be necessary.Conclusion
This
study is a representation of how MRI and machine learning can be used to synergistically
analyze a set of data with low signal. We found that R1 can be used to
differentiate between subjects at different exposure levels. Because our SVC’s
prediction accuracy increased in the higher MnTWA threshold values, the results
suggest that R1 as a marker for Mn accumulation in the brain may not have a
linear relationship with Mn accumulation in the brain. To further elucidate
this relationship, future studies should take into account whether Mn in the
brain is in a free or bound state.Acknowledgements
This
study was supported by NIEHS F31 ES028081
and NIEHS R01 ES020529.References
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