Cerebral small vessel disease (SVD) is a major vascular contributor to dementia and stroke, being associated with age-related cognitive decline. In this work, we aim to assess the potential of spontaneous BOLD fluctuations metrics to predict cognitive impairment in a group of SVD patients, therefore providing sensitive SVD biomarkers. The amplitude of low-frequency fluctuations (ALFF) and fractional ALFF (fALFF) were computed in four different frequency bands as metrics of spontaneous BOLD signal fluctuations. Results from multiple linear regression analyses demonstrated that spontaneous BOLD fluctuations metrics contribute to the prediction of cognitive impairment in executive function, processing speed and working memory.
Materials and Methods
A group of 11 patients with sporadic SVD (sSVD) (52±7 yrs) and 6 patients with CADASIL (47±11 yrs) was studied on a 3T Siemens scanner, including: T1-weigthed MPRAGE (1mm isotropic), T2-weighted FLAIR (0.7x0.7x3.3mm3), and ~6.5min resting-state BOLD-fMRI (2D GE-EPI, TR/TE=2500/30ms, 3.5x3.5x3.0mm3). Data were analyzed using FSL (https://fsl.fmrib.ox.ac.uk/fsl), ANTs (http://stnava.github.io/ANTs/), MATLAB (R2016b), and R software. BOLD fMRI pre-processing steps included: fieldmap unwarping for correction for EPI distortions, motion correction, spatial smoothing (FWHM=5mm) and regression of motion parameters and a second order polynomial for removal of low-frequency drifts. The following ALFF and fractional ALFF (fALFF) (obtained by normalizing ALFF by the total power across the detectable frequency range, 0-0.2Hz) metrics were computed in specific frequency bands4: ALFF (0.01-0.10Hz), fALFF1 (0.010-0.023Hz), fALFF2 (0.023-0.073Hz) and fALFF3 (0.073-0.20Hz). For each metric, voxelwise maps were derived and average values were calculated across gray matter (GM) and NAWM ROIs obtained by segmentation of the structural images, resulting in 8 metrics. SVD patients were evaluated in 4 cognitive domains using a battery of neuropsychological tests: Stroop and Trail Making Test Part B, for executive function; Trail Making Test Part A, for processing speed; WAIS-III Digit Span, for working memory; and WMS-III, for long-term memory. The Pearson correlation was computed between each of the 8 metrics of interest and the normalized score of each of the 4 cognitive domains. The Pearson correlation was also computed between the 8 metrics of interest and the following demographic and structural imaging covariates: age, normalized brain volume (nBV) and normalized white matter hyperintensity lesion volume (nLV). Multiple linear regression (MLR) models of the cognitive scores were then estimated using stepwise analysis including the metrics that demonstrated significant correlations with cognitive scores as well as the demographic and structural covariates.Results
Fig.1 shows the ALFF, fALFF1, fALFF2 and fALFF3 maps, averaged across all patients, displaying the distribution of each metric across the brain. Fig.2 presents the Pearson correlation analysis between the neuropsychological scores in each of the four cognitive domains and the eight different metrics. Only processing speed was predicted with significance using single predictors, namely: fALFF2 and fALFF3 in NAWM (p=0.033 and p=0.015, respectively) and ALFF in GM and NAWM (p=0.014 and p=0.017, respectively). Correlation analyses between metrics and covariates are displayed in Fig.3. Significant correlations (p<0.05) between metrics can be observed, with the exception of fALFF1, which only correlates with fALFF3 in GM. In contrast, covariates generally did not present significant correlations with metrics and among themselves. Fig.4 displays results from MLR analyses, including the covariates and the corresponding significant processing speed predictors (ALFF in GM and NAWM, and fALFF2 and fALFF3 in NAWM). The model that best explained processing speed scores (49,74% of variance, p=0.018) included the ALFF metric in NAWM (predictor with the lowest p-value, p=0.005) in addition to the covariates: group, nBV and nLV (p=0.047, p=0.044 and p=0.026, respectively). Further MLR analyses of all four cognitive domains were also performed using only the covariates, the covariates and the composite scores (principal components explaining at least 80% of the variance) of GM metrics, NAWM metrics, and the combination of GM and NAWM metrics. These results are displayed in Fig.5.1. Pantoni L. Cerebral small vessel disease: from pathogenesis and clinical characteristics to therapeutic challenges. The Lancet Neurology, 1;9(7):689-701, 2010.
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