Abdol Aziz Ould Ismail1, Drew Parker1, Simon Alexander2, Steven Brem3, and Ragini Verma1
1Penn Patho-Connectomics Lab, Radiology, University of Pennsylvania, Philadelphia, PA, United States, 2Synaptive Medical, Victoria, BC, Canada, 3Neurosurgical Oncology, University of Pennsylvania, Philadelphia, PA, United States
Synopsis
There is a growing interest in characterizing the
peritumoral regions in neoplasms, in order to distinguish primary and secondary
neoplasms, improve tractography for surgical planning, and create radiomic
markers of infiltration. Free water estimation is expected to reflect the
differences in water content of the peritumoral region between these tumor
types. In this work, we compare glioblastoma
(primary) and metastatic (secondary) tumors based on their free water estimated
using standard clinical diffusion MRI (dMRI). Results demonstrate significant
difference in these tumor types based on the free water measures, fractional
anisotropy post-correction and the coverage of the peritumoral region by
tractography.
INTRODUCTION
Since
pathophysiological processes vary depending on the origin of neoplasms, the
characteristics of their peritumoral regions are expected to differ. Extracellular
free water (FW) is a product of various pathophysiological processes including
the impairment of ATP-dependent sodium pumps, obstruction, and change in pressure
and osmotic gradients1. The tensor properties in voxels contaminated
by FW are misleading, and do not correspond to the underlying tissue properties,
rendering the non-invasive investigation of the pathological properties further
challenging. We hypothesize that the FW content as estimated by free water
elimination, its extent of correction on fractional anisotropy (FA) and
increased volume of tractography in the peritumoral region should be able to
elucidate patterns of edema and infiltration that distinguish primary and
secondary neoplasms. In this work, we use FW content, corrected FA and tracking
coverage after FWE to distinguish between glioblastoma multiforme (GBM) and
metastatic (Mets) tumors.METHODS
a- Datasets and
preprocessing:
Data
from 88 GBM and 50 Met patients were selected for this study. All patients
underwent 30 direction DWI (TR/TE= 5000/86ms, b = 1000s/mm2, 3 b0),
T1, T1 post-contrast, T2 and FLAIR MRI acquisitions. DTI preprocessing steps
included denoising, motion and eddy current correction, and skull-stripping;
the four structural scans were each nonlinearly registered to the DTI image. Two
tensor models were fitted: a standard tensor model and Fernet2, a free-water eliminated (FWE) tensor model. FW
maps were obtained for every subject using Fernet.
b- Tractography: Deterministic
tractography was performed on each subject with Diffusion Toolkit3. Bilaterally, representations of five
white-matter tracts (corticospinal tract, inferior fronto-occipital, inferior
longitudinal, arcuate and uncinate fasciculi) were extracted in each patient
for each tensor model using the shape-based clustering algorithm RecoBundles4. Mask of the
peritumoral region was obtained using GLISTR.
For each subject, the percentage change of the edema volume covered between the
standard tensor and Fernet tensor
models was calculated.
c- Statistical
Analysis: A
paired t-test was used to compare the tracking coverage in the peritumoral region
before and after FWE. Regression analysis using age, sex, and diagnosis as
covariates was employed to investigate the difference in tracking coverage, FA
from standard tensor fit, Fernet FA, FA difference post FWE, and FW component
in Mets and GBMs. P-values were corrected for multiple comparisons using the
Benjamini-Hochberg procedure to control for false discovery rate (FDR).
RESULTS
Fig.1
shows an increase in tracts covering the peritumoral region using FWE as compared
to the standard tensor-based streamlines that stopped prematurely. The analysis
of tractography showed a significant increase in peritumoral region coverage
using FWE tractography (t=6.9, p<1×10-9) compared to standard
diffusion tensor tractography (Fig.2). Regression analysis using age, sex, and
diagnosis as covariates revealed that the increase in coverage was greater in
patients with Mets than GBM (t=4.6, p<1×10-7) (Fig.3). The FW
maps showed that mean FW volume fraction in the peritumoral region was higher
in Mets (t=4.4, p<1×10-4), as seen in Fig.2 and Fig.4. Mean standard
FA was significantly lower in Mets (t=-2.6, p<0.01), while mean Fernet FA
was significantly higher (t=2.3, p<0.05). Finally, the difference map between
FA from standard fit and Fernet show significant differences in the peritumoral
area in these two tumor types (t=4.1, p<0.001).DISCUSSION
The
findings of this study hold high clinical significance as they show that the change
in tracking coverage, FW volume fraction and difference in FA after FWE were each
sufficient to distinguish between vasogenic (secondary neoplasm) and cytotoxic edema
(primary neoplasm). These findings can be explained by the decrease of the
available space for FW in GBMs due to intracellular swelling following cellular
necrosis5. Furthermore, the
increase of tracking coverage and Fernet FA in Mets is consistent with previous
reports6 that suggest that the vasogenic edema is reversible. This
edema is characterized by an increase in the apparent diffusivity due to the
contamination of free water, while the underlying tissue remains undamaged6.
Hence, when FW was eliminated, we were able to retain a higher tracking
coverage in the peritumoral region in secondary neoplasm.CONCLUSION
We have shown that free water estimation can provide three crucial
markers of the peritumoral region: change in tracking coverage, FW volume
fraction, and the difference in FA after FWE. This can help discriminate primary
and secondary brain neoplasms. These findings are well aligned with the current
state of knowledge regarding edema in brain tumors. Our investigation suggests
the potential of use of these measures as radiomic markers of tumor type and
infiltration, aiding in potential digital biopsy, prognosis, diagnosis and
monitoring treatment.Acknowledgements
This research was supported by the National Institutes of Health (NIH) grant 1R01NS096606 (PI: Ragini Verma), and research grant from Synaptive
Medical 30071788 (PI: Ragini Verma).References
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