Philipp Boehm-Sturm1,2, Till de Bortoli3,4, Stefan Paul Koch1,2, Melina Nieminen3, Susanne Mueller1,2, Giovanna Diletta Ielacqua5, Jan Klohs5, Ulrich Dirnagl1, Peter Vajkoczy3, and Nils Hecht3
1Department of Experimental Neurology and Center for Stroke Research Berlin, Charité – Universitätsmedizin Berlin, corporate member of Freie Universität Berlin, Humboldt-Universität zu Berlin, and Berlin Institute of Health, Berlin, Germany, 2Cluster of Excellence NeuroCure and Charité Core Facility 7T Experimental MRIs, Charité - Universitätsmedizin Berlin, Berlin, Germany, 3Department of Neurosurgery and Center for Stroke Research Berlin, Charité - Universitätsmedizin Berlin, Berlin, Germany, 4Charité Comprehensive Cancer Center, Charité – Universitätsmedizin Berlin, Berlin, Germany, 5Institute for Biomedical Engineering, University of Zurich & ETH Zurich, Zurich, Switzerland
Synopsis
Collateral flow is an
important, yet poorly understood compensatory mechanism in response to brain hypoperfusion.
Unilateral internal carotid artery occlusion in the mouse is a model to study
collateral growth of penetrating arterioles. We hypothesized that this process could
be assessed in vivo by high resolution
MR microangiography with iron oxide nanoparticles. Since our MR vessel density
measurements contradicted previous histological findings we established atlas tools
to validate angiograms with microscopy on vessel-stained tissue slices or with
whole brain serial two photon microscopy.
Introduction
Collateral outgrowth with flow
augmentation remains the most important mechanism for prevention of hemodynamic
ischemic stroke. In these cases, hemodynamic rescue is mainly provided by collateral
arterioles in the range of ~20-50 µm diameter1. However, the mechanism of cerebral collateralization (arteriogenesis)
remains poorly understood and reliable tools for in vivo assessment of its degree, morphology and dynamics are lacking2,3. Due to the blooming effect of ultra-small superparamagnetic iron oxide
nanoparticles (USPIO) we hypothesized that these vessels could directly be
visualized and quantified using contrast-enhanced MR microangiography with a
cryoprobe4. The goal of this study was to develop noninvasive and quantitative MR readouts
in order to characterize the collateral vasculature during cerebral
arteriogenesis. Methods
For simulation of chronic
cerebral hypoperfusion, male C57/Bl6 mice were randomized to undergo right side unilateral internal carotid artery occlusion (ICAO, n=8) or a sham procedure (n=8) as described previously2. 21 d after surgery, animals underwent MRI at 7T using a mouse head cryoprobe
(Bruker, Ettlingen, Germany). The protocol consisted of T2w MRI for atlas
registration (2D RARE, 39 contiguous 0.4 mm thick slices, (80 µm)2
in plane resolution, TR/TEeff=4.2 s/33 ms, RARE factor 8, 2
averages, TA=4:03 min), contrast-free angiography (3D TOF, (80 µm)3 resolution,
TR/TE=14 ms/2.1 ms, TA=6:02 min), contrast-enhanced MR microangiography of the
cortex (5.2 mm slab) by acquiring images (3D FLASH, (65 µm)3
resolution, TR/TE=54 ms/3.9 ms, TA=29:57 min per image) pre and post injection
of the USPIO Ferumoxytol (300 µmol Fe/kg, AMAG Pharmaceuticals, Waltham,
MA/USA) through the femoral vein, and DSC MRI of cerebral perfusion during
injection (GE-EPI, 15 0.4 mm slices, (293 µm)2 resolution, TR/TE=400
ms/7.2 ms, 200 repetitions. TA=1:20 min). Finally, animals received 100 µL
FITC-lectin (Merck, Darmstadt, Germany) to stain cerebral vasculature and were
transcardially perfused for confocal fluorescence microscopy (Leica TCS SP8,
Leica Microsystems, Wetzlar/Germany) on tissue slices. A subset of animals (n=2
ICAO, n=1 sham) was processed for 3D serial two photon tomography (STPT, (1.2
µm)2 in plane, 25 µm sections, TissueVision, Somerville, MA/USA). MR microangiograms were generated by
subtraction of image intensities Spre-Spost. From these,
vessel densities in left/right/whole cortex were calculated by a vessel tracing
algorithm by an independent lab as described previously4. The relative cerebral blood volume (rCBV) was mapped via change in transverse
relaxation rate ΔR2*=1/TE*ln(Spre/Spost)5. MR and histology images were mapped in common spaces using custom MATLAB
tools6. All data analyses were performed blind to the group assignment of
animals. Results
One animal (sham) was
excluded due to unsuccessful i.v. injection of the contrast agent, one (ICAO)
died during MRI leading to a final n=7 in each group. Qualitative inspection of
MR microangiograms revealed that penetrating arterioles and venules could be
visualized and that image intensity was apparently higher in the ICAO group (Fig.
1). However, quantitative analysis using the vessel tracing algorithm showed a
puzzling decrease in vessel density independent of parameter settings whereas rCBV
confirmed the increase in vasculature seen in previous studies (Fig. 2). Registration
of MRI on FITC-lectin stained tissue sections showed that vessels as small as
~25 µm were detectable by MRI (Fig. 3). Whole brain 3D STPT and MR microangiograms
were mapped into Allen brain atlas space for qualitative comparison (Fig. 4). However,
a voxel-wise comparison has not yet been possible due to the resolution gap (3D
histology <25 µm, MRI 65 µm plus blooming effect). A biophysical model to
quantitatively compare the two modalities is still work in progress.Discussion
Contrast-enhanced
MR microangiography visualizes changes in the collateral vasculature.
MR/histology image registration can help to assess the scales for which the
technique is valid. rCBV seems to be a more robust marker of
arteriogenesis but this remains to be confirmed by voxel-wise comparison to 3D
histology. Since vessel dilation has been shown to be absent 21 d post ICAO, it
is likely that the observed increase in rCBV paired with the apparent decrease
in vascular density is an artefact of the vessel tracing algorithm, e.g. that
two vessels that are too close to each other will be identified as a single object.
Our atlas registration tools to gold standard histology will thus allow
development of better vessel tracing algorithms.Conclusion
In the future, the quantitative
tools developed in this study will help to investigate mechanisms of cerebral
arteriogenesis in experimental models exploring novel strategies for therapeutic
stimulation of cerebral collateralization.Acknowledgements
Work was supported by the Deutsche
Forschungsgemeinschaft Cluster of Excellence NeuroCure (Exc 257) and the German
Federal Ministry of Education and Research (BMBF; 01EO0801, Center for Stroke
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