Ben R Dickie1, Hervè Boutin1, Geoff JM Parker1,2, Stuart M Allan1, and Laura M Parkes1
1Division of Neuroscience and Experimental Psychology, University of Manchester, Manchester, United Kingdom, 2Bioxydyn Ltd, Manchester, United Kingdom
Synopsis
Blood-brain barrier (BBB) and blood-cerebrospinal fluid barrier (BCSFB) dysfunction
are increasingly recognised as pathological hallmarks of vascular dementia and
Alzheimer’s disease. Chronic hypertension increases the risk of developing both
types of dementia, and may contribute by disrupting the function of blood-brain
interfaces. Here we study the permeability of blood-brain and blood-CSF
barriers to water using our recently developed multi-flip angle multi-echo
(MFAME)-MRI protocol in spontaneously hypertensive rats (SHR). SHRs display increased
BBB permeability surface area product to water, relative to age matched
controls. Such changes may alter brain water and ion balance and/or contribute
to glymphatic dysfunction. Blood-CSF barriers were unaffected.
Introduction
Mid-life hypertension increases
the risk of developing dementia by approximately 25-30%1. Drainage
of interstitial fluid into the ventricular system is altered in hypertensive
rats2, which may contribute towards amyloid-β accumulation and
cerebral amyloid angiopathy3, possibly through dysfunctional fluid movement
across the blood-brain barrier (BBB), blood-cerebrospinal fluid barrier
(BCSFB), or through the glymphatic system. At a microscopic level, chronic hypertension
leads to altered expression and depolarisation of key BBB, BCSFB, and glial
cell transmembrane proteins that nominally regulate the permeability of
blood-brain and blood-CSF interfaces, including tight junctions4 and
aquaporin water channels5,6. In this study, we use our recently
developed multi-flip angle multi-echo (MFAME)-MRI method7 to probe trans-BBB
and trans-BCSFB water-exchange in spontaneously hypertensive rats (SHR) and
Wistar-Kyoto controls aged 13 months. Methods
Male spontaneously hypertensive (SHR) rats (n
= 7) and age-matched normotensive Wistar-Kyoto (WKY) controls (n = 9) aged 13
months were scanned using
a Bruker Avance III console interfaced with an Agilent 7T 16 cm bore magnet. High-resolution T2-RARE images
were acquired to enable accurate delineation of brain regions of interest
(ROIs) via registration with the Schwarz et al. rat brain atlas8.
Ventricle ROIs were generated by thresholding pre-contrast variable flip angle
T1 maps (CSF in ventricles was defined as voxels with T1
> 3 s). Measurements of the BBB and BCSFB permeability surface-area product
to water (PSw [mL min-1 mL-1]) were made using
MFAME-MRI as previously described7. In brief, 3D SPGR images
at multiple flip angles were collected following injection of Gd-DOTA (Table 1).
Estimates of blood T1 were then extracted from the superior sagittal
sinus pre- and post injection and used to estimate PSw from the
signal time-course in key ROIs using the two-site one exchange model. Estimates of PSw were log-transformed
to improve normality prior to statistical analysis. ANOVA tests were performed
on regional measures of BBB ln(PSw) to estimate the effects of group
(SHR/WKY) and brain region (repeated measure). Post-host t-tests were performed
to determine significance of individual regions. BCSFB estimates of ln(PSw)
were tested for SHR/WKY differences using a t-test. Results
ANOVA analyses
showed that BBB PSw was higher in SHR rats than WKY controls (Figure 1, p =
0.0070) and differed significantly across brain regions (p < 10-4).
BCSFB PSw did not differ between SHR and WKY rats (p = 0.23). PSw at the BCSFB was similar to PSw at the
BBB. Discussion
This is the first report of
BBB and BCSFB PSw measurements in SHRs. Our results indicate that water-exchange
across the BBB is greater in SHR than normotensive controls, whereas
water-exchange across the BCSFB did not differ between strains (Figure 1). Several
studies have detected increased aquaporin-4 expression on astrocyte end-feet in
hypertensive rats which may contribute to the increased trans-BBB water-exchange
observed in this study5,6. Importantly, aquaporin-4 channels are
thought to play a key role in maintaining glymphatic flow and aid clearance of
waste from the brain9, indicating MFAME-MRI may be indirectly
sensitive to glymphatic flow patterns. Increased PSw may also result
from subtle reductions in the expression of BBB tight junction proteins, as we
have observed in our previous work in transgenic Alzheimer’s disease rats7.
In summary we have shown increased BBB PSw in hypertensive rats,
which may reflect increased aquaporin-4 expression or subtle tight junction
loss at the BBB.Acknowledgements
The purchase, maintenance, and scanning of the SHR rats was
supported by Wellcome Trust ISSF scheme and EPSRC project EP/M005909/1. The MRI facility is supported through
an equipment grant from BBSRC UK (BB/F011350). References
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