Jingwen Yao1,2,3, Caleb Tan4, Ararat Chakhoyan1,3, Catalina Raymond1,3, Noriko Salamon3, Linda Liau5,6, Phioanh Nghiemphu7, Albert Lai6,7, Whitney Pope3, Timothy Cloughesy7, and Benjamin Ellingson1,2,3,6,8,9
1Brain Tumor Imaging Laboratory (BTIL), Center of Computer Vision and Imaging Biomarker, David Geffen School of Medicine, University of California, Los Angeles, Los Angeles, CA, United States, 2Department of Bioengineering, Henry Samueli School of Engineering and Applied Science, University of California, Los Angeles, Los Angeles, CA, United States, 3Department of Radiological Sciences, David Geffen School of Medicine, University of California, Los Angeles, Los Angeles, CA, United States, 4Department of Chemistry and Biochemistry, University of California, Los Angeles, Los Angeles, CA, United States, 5Department of Neurosurgery, David Geffen School of Medicine, University of California, Los Angeles, Los Angeles, CA, United States, 6UCLA Brain Research Institute (BRI), David Geffen School of Medicine, University of California, Los Angeles, Los Angeles, CA, United States, 7Department of Neurology, David Geffen School of Medicine, University of California, Los Angeles, Los Angeles, CA, United States, 8Physics and Biology in Medicine, David Geffen School of Medicine, University of California, Los Angeles, Los Angeles, CA, United States, 9Department of Psychiatry and Biobehavioral Sciences, David Geffen School of Medicine, University of California, Los Angeles, Los Angeles, CA, United States
Synopsis
In the current study we used amine
CEST-EPI, a
pH-sensitive
fast chemical exchange saturation transfer (CEST) technique, as a potential non-invasive imaging biomarker
for treatment response in recurrent GBM patients treated with bevacizumab. Results
suggest a significantly lower MTRasym at 3.0ppm in recurrent GBM tumors after bevacizumab
treatment may be associated with better patient outcome (PFS), indicating that
pH-weighted amine CEST MRI could serve as a potential non-invasive imaging
biomarker for treatment response evaluation. The colocalization of recurrence
tumor site and high MTRasym contrast post-treatment further suggest pH-weighted
amine CEST may provide valuable information for early detection of tumor
progression.
INTRODUCTION
Glioblastoma
(GBM) is an aggressive form of brain tumor with median overall survival (OS) around
15 months despite the intensive therapy, including gross surgical resection
followed by radiation therapy and concurrent chemotherapy1. Bevacizumab,
a monoclonal antibody
against vascular endothelial growth factor (VEGF) that targets angiogenesis, was
approved by the Food and Drug Administration for the treatment of recurrent GBM
in 2009 based on the ability to improve progression-free survival (PFS);
however, subsequent studies have not demonstrated an OS benefit2.
Regardless, bevacizumab remains one of the most widely used therapies for
recurrent GBM and almost all patients with GBM are exposed to bevacizumab at
some time during their treatment.
Tumor
angiogenesis is a characteristic feature of malignant transformation. The vasculature of GBM is
tortuous, disorganized, and highly permeable3. The malfunction of
tumor vasculature and frequent microvascular thromboses promotes intratumoral
hypoxia and decreases extracellular pH4. Apart from vessel malfunction
and hypoxia, enhanced metabolism and shifted glucose utilization toward
glycolysis (i.e. the Warburg effect) also contributes to tumor acidosis5. Imaging biomarkers sensitive to extracellular pH changes may provide a noninvasive
measure of metabolism, potentially predicting early treatment response and
therapeutic benefit. In the current study we used amine CEST-EPI, a fast chemical
exchange saturation transfer (CEST) technique that has been shown to have
increased contrast with increasing amino acid concentration and decreasing pH6, as a potential non-invasive imaging biomarker for treatment
response in recurrent GBM patients treated with bevacizumab.
METHODS
Patient: A total of 8 males and 3 females
recurrent GBM patients from the ages of 45 to 75 years old undergoing bevacizumab
treatment were scanned with CEST MRI before and after treatment in the current
pilot study. Amine CEST-EPI: Amine CEST-EPI was collected on Siemens 3T scanner
(Prisma/Skyra) with previously described CEST-EPI sequence6 or CEST-SAGE-EPI
sequence7. Off-resonance saturation was applied using a pulse
train of 3x100ms Gaussian pulses with peak amplitude of 6µT. The saturation
pulses excite amine protons which resonate at 3.0ppm with respect to water
proton frequency. The amine proton exchanges with water proton pool based on a
base-catalyzed exchange rate, transferring the saturation effect to water
proton signal, which results in the pH-sensitivity of CEST signal. We
calculated the magnetization transfer ratio asymmetry (MTRasym) at
amine proton resonance frequency (3.0ppm) as the metric of CEST contrast. Data Analysis: The T2 hyperintense
lesion (T2 lesion) and contrast enhancing lesion (CE lesion) regions of
interest (ROIs) were semi-manually defined as previously described8. A
paired t-test was used to evaluate the difference in MTRasym before and after bevacizumab
treatment. Spearman’s rank correlation test was performed to evaluate the
correlation between MTRasym response and volume response, as well as between
MRI metrics and patient outcome (PFS and OS).RESULTS
Consistent
with previous reports9, we observed dramatic decrease in T2 lesion and CE
lesion volumes after bevacizumab treatment (T2 lesion: p=0.00094; CE lesion: p=0.0014;
Figure 1(A,D)). MTRasym at 3.0ppm was also significantly lower in
post-treatment lesions (T2 lesion: p=5.4e-6; CE lesion: p=0.00022; Figure
1(B,E)). The percentage change in MTRasym was strongly correlated with the
percentage change in tumor volume (T2 lesion: r=0.67, p=0.028; CE lesion: r=0.82,
p=0.0037; Figure 1(C,F)). Change in MTRasym was negatively correlated with PFS,
both in the T2 lesion (r=-0.89, p=0.00026, Figure 2 (A)) and the CE lesion (r=-0.62,
p=0.044, Figure 2 (D)). Post-treatment MTRasym in the T2 lesion was also
negatively correlated with PFS (r=-0.79, p=0.0036, Figure 2 (B)), although the
correlation is was not significant when evaluating MTRasym in the CE lesion (r=-0.57,
p=0.060, Figure 2 (E)). No significant correlation was found between
pre-treatment MTRasym and PFS, nor between any MTRasym features and OS. We did
not find any correlation between volume responses and patient outcome (PFS and
OS) in this small cohort. In addition, we observed that in some patients, the
site of residue or new emergence of high MTRasym contrast was colocalized with
recurrence tumor location, about two months before the recurrent tumor was
first observed on conventional MR images (Figure 3).DISCUSSION AND CONCLUSION
Results
suggest a significantly lower MTRasym at 3.0ppm in recurrent GBM tumors after bevacizumab
treatment may be associated with better patient outcome (PFS), indicating that
pH-weighted amine CEST MRI could serve as a potential non-invasive imaging
biomarker for treatment response evaluation. The colocalization of recurrence
tumor site and high MTRasym contrast post-treatment further suggest pH-weighted
amine CEST may provide valuable information for early detection of tumor
progression.Acknowledgements
No acknowledgement found.References
1. Stupp R,
Mason WP, van den Bent MJ, Weller M, Fisher B, Taphoorn MJ, et al. Radiotherapy
plus concomitant and adjuvant Temozolomide for glioblastoma. N Engl J Med.
2005;352:987–96.
2. Chinot
OL, Wick W, Mason W, Henriksson R, Saran F, Nishikawa R, Carpentier AF,
Hoang-Xuan K, Kavan P, Cernea D, Brandes AA. Bevacizumab plus
radiotherapy–temozolomide for newly diagnosed glioblastoma. New England Journal
of Medicine. 2014 Feb 20;370(8):709-22.
3. Plate
KH, Mennel HD. Vascular morphology and angiogenesis in glial tumors.
Experimental and Toxicologic Pathology. 1995 Jan 1;47(2-3):89-94.
4. Rong Y,
Durden DL, Van Meir EG, Brat DJ. ‘Pseudopalisading’necrosis in glioblastoma: a
familiar morphologic feature that links vascular pathology, hypoxia, and
angiogenesis. Journal of Neuropathology & Experimental Neurology. 2006 Jun
1;65(6):529-39.
5. Kato Y,
Ozawa S, Miyamoto C, Maehata Y, Suzuki A, Maeda T, Baba Y. Acidic extracellular
microenvironment and cancer. Cancer cell international. 2013 Dec;13(1):89.
6. Harris
RJ, Cloughesy TF, Liau LM, Prins RM, Antonios JP, Li D, Yong WH, Pope WB, Lai
A, Nghiemphu PL, Ellingson BM. pH-weighted molecular imaging of gliomas using
amine chemical exchange saturation transfer MRI. Neuro-oncology. 2015 Jun
24;17(11):1514-24.
7. Harris
RJ, Yao J, Chakhoyan A, Raymond C, Leu K, Liau LM, Nghiemphu PL, Lai A, Salamon
N, Pope WB, Cloughesy TF. Simultaneous p H‐sensitive and oxygen‐sensitive MRI
of human gliomas at 3 T using multi‐echo amine proton chemical exchange
saturation transfer spin‐and‐gradient echo echo‐planar imaging (CEST‐SAGE‐EPI).
Magnetic resonance in medicine. 2018 Apr.
8. Ellingson
BM, Kim HJ, Woodworth DC, Pope WB, Cloughesy JN, Harris RJ, Lai A, Nghiemphu
PL, Cloughesy TF. Recurrent glioblastoma treated with bevacizumab:
contrast-enhanced T1-weighted subtraction maps improve tumor delineation and
aid prediction of survival in a multicenter clinical trial. Radiology. 2013 Nov
27;271(1):200-10.
9. Ellingson
BM, Cloughesy TF, Lai A, Nghiemphu PL, Mischel PS, Pope WB. Quantitative
volumetric analysis of conventional MRI response in recurrent glioblastoma
treated with bevacizumab. Neuro-oncology. 2011 Feb 15;13(4):401-9.