Rui Vasco Simões1, Sergio Caja-Galán1, Rafael Neto Henriques1, Bruno Costa-Silva1, and Noam Shemesh1
1Champalimaud Research, Champalimaud Centre for the Unknown, Lisbon, Portugal
Synopsis
Cancer cells
can induce phenotypic modifications at future sites of dissemination
(pre-metastatic niches), which support tumor growth and metastasis. Here we evaluated whether diffusion-weighted imaging (DWI)
could detect mouse liver pre-metastatic niches (LPM) ex vivo using ultrahigh
magnetic field MRI. Our results
show that mean diffusivity (MD) and
mean kurtosis (MK) can
depict microstructural
changes associated with LPM formation, consistent with a more fibrotic and
cellular microenvironment revealed by histologic analysis of the same samples.
These results represent a solid step toward the development of a non-invasive
imaging tool for pre-metastatic niche diagnosis.
INTRODUCTION
Intercellular communication is critical for
metastatic progression – a multi-step process involving “premetastatic niche”
formation at target organs during early phase spreading. This is mediated by cancer cell-derived exosomes, which can induce
phenotypic modifications at future sites of dissemination and prime them for metastasis (1). Mapping premetastatic niches non-invasively could thus
provide a crucial diagnostic biomarker for early detection
of metastatic spread, and ultimately its prevention. It has recently been shown that pancreatic
ductal adenocarcinoma (PDAC)-derived exosomes can induce liver pre-metastatic
niches (LPM) in naive mice, characterized by upregulation
of fibronectin production by hepatic stellate cells and enhanced macrophage recruitment
(2).
Given the sensitivity of diffusion-weighted imaging (DWI)
metrics to tissue microstructure (3), we hypothesized their
suitability for depicting such LPM-associated changes.PURPOSE
To investigate the ability of DWI to detect
mouse LPMs ex vivo at ultrahigh-field.METHODS
All animal experiments were preapproved by the institutional
and national authorities, and carried out according to European Directive
2010/63.
Animal model. PDAC-derived
exosomes were isolated by ultracentrifugation from pancreatic adenocarcinoma bearing-mice
(Pan02 allografts on a C57Bl/6 background) and verified by nanoparticle
tracking analysis, and injected in the retro-orbital venous sinus of 5 naive C57Bl/6
mice (LPM group: 5μg of total protein in 100 µL PBS), 3 times a week for 2 weeks, as reported before (2); whereas
5 control C57Bl/6 mice (CTR group) received sham injections (100 µL PBS).
Sample preparation and immunofluorescence. After perfusing/fixating each liver in 4% PFA (Fig. 1), one lobule was separated for
histology and the rest kept for MRI. For histology, samples were further fixed overnight in 2% PFA + 20% sucrose, OCT-embedded
and frozen; tissue cryosections were immunostained for F4/80+, fibronectin, and αSMA, and analyzed by fluorescence microscopy.
For MRI, the remaining tissues were
kept in PBS for 24h at 4ºC, then loaded on a 15mm NMR tube filled with
Fluorinert and sodium azide, and kept at 4ºC for 1 week.
MRI. Each sample was scanned on a Bruker 16.4T Aeon
Ascend spectrometer equipped with an Avance IIIHD console and a Micro2.5 probe
(Gmax 1500 mT/m in
all directions). Diffusion was encoded using the remmiRARE
pulse sequence (kindly provided by Prof. Mark D Does from Vanderbilt
University, USA) using the following acquisition parameters: RARE
factor, 12; TE1, 43.9ms; Echo Spacing,
3.3ms; TR, 2s; averages,
2; FOV/matrix, 22.4x15.5mm/104x72 (0.215x0.215mm in plane
resolution); 0.8mm slice thickness (10 slices, total); total acquisition time,
67min. For the diffusion weighting, eight b-values were spaced between 20-2000s/mm2,
with 20 directions per b-value, Δ/δ= 40/1.8ms, and 8
non-diffusion weighted acquisitions (b0) for normalization.
Data analysis. Immunofluorescence data were analyzed for significance between CTR and
LPM groups with a two-tailed t-Test (Graph Pad Prism 5.0a,
La Jolla/CA, USA). MRI data
were analyzed in Matlab R2015a (Natick/MA, USA). Preprocessing included
Marchenko-Pastur
PCA denoising (4) and Gibbs unringing (5). Data were analyzed by pixel-wise
fitting to extract mean
diffusivity (MD), mean kurtosis (MK), and
fractional anisotropy (FA), based on the literature (6-10). After normality assessment by the Kolmogorov-Smirnov test, CTR
and LTR groups were compared for each metric according to the Mann Whitney test.RESULTS
Immunoflurescence studies confirmed a significantly
higher accumulation of LPM markers in the respective samples: αSMA,
fibronectin, and F4/80+ cells (Fig. 2). DWI analysis (Fig. 3) revealed significantly lower MD
(-6%, p=0.0006), higher MK (+11%, p=0.0074), and higher MK/MD (+22%, p=0.0002)
in LPM samples (Fig. 4). MD recalculated
without correction for kurtosis was also significantly lower in LPM samples
(-9%, p=0.0002), but FA did not significantly vary between the two groups (Table 1).DISCUSSION
MK/MD distributions reflect
microstructural changes occurring in the LPM group, which are consistent
with a more fibrotic and cellular microenvironment revealed by histologic
analysis of the same samples. Further studies shall involve enhanced microstructural specificity and independence
of orientation dispersion (11), as well as in
vivo translation concomitant with metastatic growth.CONCLUSION
Our first-of-its-kind finding represents
an important step
toward establishing a MRI-based marker for premetastatic niches.Acknowledgements
The authors thank Ms. Joana Maia and Dr. Ana Gregório for their help with the animal model, and Dr. Jelle Veraart for helpful discussions about DWI analysis. Funding Support: Champalimaud Foundation; H2020-MSCA-IF-2016 grant, ref. 751547; EMBO Installation Grant, ref. 3921; NIH, ref. EB019980.References
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