Agilo L Kern1,2, Filip Klimes1,2, Andreas Voskrebenzev1,2, Marcel Gutberlet1,2, Heike Biller2,3, Julius Renne1,2, Olaf Holz2,3, Frank Wacker1,2, Jens M Hohlfeld2,3,4, and Jens Vogel-Claussen1,2
1Institute of Diagnostic and Interventional Radiology, Hannover Medical School, Hannover, Germany, 2Biomedical Research in Endstage and Obstructive Lung Disease Hannover (BREATH), Member of the German Center for Lung Research (DZL), Hannover, Germany, 3Department of Clinical Airway Research, Fraunhofer Institute for Toxicology and Experimental Medicine, Hannover, Germany, 4Department of Respiratory Medicine, Hannover Medical School, Hannover, Germany
Synopsis
Low-dose
inhalation of lipopolysaccharide (LPS) provides a disease model in humans for
development of anti-inflammatory drugs but sensitive methods for assessment of
the inflammatory response to LPS are lacking. The feasibility of hyperpolarized
129Xe dissolved-phase imaging and chemical shift saturation recovery
(CSSR) was investigated in this setting. The ratio of 129Xe in red
blood cells and in tissue/plasma was found to decrease and the capillary transit
time derived from CSSR was found to increase after LPS inhalation. These
effects are attributed to pulmonary edema and vasodilation. In conclusion,
hyperpolarized 129Xe MR is sensitive even for low-dose LPS
challenges in humans.
Introduction
Chronic
obstructive pulmonary disease (COPD) poses a major burden to the world
population, being the 4th leading cause of death in 2015.1 Progression of COPD is associated with
neutrophilic airway inflammation and targeted anti-inflammatory drugs would be
a promising candidate to prevent disease worsening.2 Unfortunately, such drugs are still lacking.
Provocation
by lipopolysaccharide (LPS) elicits a neutrophilic inflammatory response in
human lungs and is thought to be a safe disease model for drug development of
anti-inflammatory drugs.
Previously,
dissolved-phase MRI/MR spectroscopy of 129Xe in tissue-plasma (TP)
and red blood cells (RBC) has been shown to be feasible for disease monitoring
after segmental provocation of human lungs by bronchoscopy.3 However, the invasiveness of repeated
bronchoscopies limits the use of this technique. Low-dose inhalation challenges
of the whole lung using LPS represent a less invasive alternative but the
detection of its functional effects remains challenging.4
Therefore,
the aim of this work was to test the feasibility of hyperpolarized 129Xe
dissolved-phase MRI and MR spectroscopy for monitoring the response of human
lungs after low-dose LPS inhalation.Methods
This study was approved by the institutional review board. 13 healthy
volunteers were included, out of which 10 completed the study
protocol. Hyperpolarized 129Xe MRI was performed at baseline and 6
hours after provocation. For provocation, the subjects inhaled 2µg LPS as
described previously.4
Imaging was
performed at 1.5T (Avanto, Siemens Healthineers, Erlangen, Germany) using a 129Xe
birdcage transmit coil and 16-channel receive array (Rapid Biomedical, Rimpar,
Germany). Hyperpolarization of 129Xe was achieved using a commercially
available polarizer (9810, Polarean, Durham, NC, USA).
The imaging
protocol consisted of a 129Xe dissolved-phase imaging (DPI) scan5 and chemical shift saturation recovery
spectroscopy (CSSR6) during separate breathholds. Starting from
residual volume, subjects inhaled 1L of hyperpolarized 129Xe for DPI
and a variable amount of air to achieve a lung inflation of 1/3 forced vital
capacity. For CSSR, after inhalation of a mixture of 0.5L 129Xe and
high-purity nitrogen, subjects further inhaled room air to fully inflate their
lungs.
DPI data
was separated into RBC and TP phase using hierarchical IDEAL7 and whole-lung mean values for the
ratios TP-GP (GP, gas phase), RBC-GP and RBC-TP were computed. 129Xe
gas uptake data to the TP phase from CSSR was fitted using the Patz model and
physiological parameters were extracted.8 High-resolution spectra of the dissolved phase
acquired directly after DPI were fitted with two complex Lorentzians for
lineshape analysis.Results
For DPI,
the whole-lung ratios RBC-TP (Wilcoxon’s signed rank test, p = 0.004) and RBC-GP (p = 0.020) were significantly reduced after provocation
compared to baseline. There also was a trend for elevated TP-GP ratio, which
was not significant (p = 0.074).
See Figure 1 for DPI results.
For CSSR,
the capillary transit time was significantly increased after provocation (p = 0.020), corresponding to
slower blood flow. There was a trend for elevated surface-to-volume ratio (p = 0.084). No significant
change was observed for septal wall thickness (p = 0.193). CSSR results are summarized in Figure 2.
Spectroscopic
lineshape analysis exhibited a significant increase in T2*
of the TP phase (p = 0.004)
and a significant reduction in RBC chemical shift (p = 0.023), Figure 3.Discussion
This study
demonstrates the sensitivity of hyperpolarized 129Xe dissolved-phase
MRI and MR spectroscopy for the response of human lungs to low-dose inhalation
challenges with LPS.
The
reduction of the ratios RBC-TP and RBC-GP in DPI is likely due to the presence
of increased fluid content of the lungs due to edema after LPS inhalation,
leading to diffusion restriction. This is consistent with the slight increase
in T2* of TP, which is expected to occur in lungs with
reduced air fraction.9
The
increase in capillary transit time from CSSR can be explained by vasodilation
due to LPS-induced inflammation, leading to reduced blood flow velocity.
An
increased fluid content of the lung would imply an increase of the alveolar
wall thickness parameter and of the surface-to-volume ratio obtained from the
TP phase. However, only a trend towards elevated surface-to-volume ratio was
observed, likely due to the relatively small sample size.
The
apparent reduction of chemical shift of the RBC phase could be a sign for a
reduced oxygenation of the RBCs due to a diffusion limitation of oxygen.10 However, given that the mean difference
observed in RBC Larmor frequency is only ~0.2ppm, further research is necessary
to validate this finding.Conclusion
Hyperpolarized
129Xe dissolved-phase MR is highly sensitive for the effects of inhaled
LPS challenge in humans and is therefore suitable as a research tool for drug
development.Acknowledgements
No acknowledgement found.References
- World Health Organization. WHO methods
and data sources for country ‐ level causes of death 2000-2015.
http://www.who.int/healthinfo/global_burden_disease/GlobalCOD_method_2000_2015.pdf.
Published 2016. Accessed July 12, 2017.
- Singh D, Siew L, Christensen J, et al.
Oral and inhaled p38 MAPK inhibitors: Effects on inhaled LPS challenge in
healthy subjects. Eur J Clin Pharmacol. 2015;71(10):1175-1184.
doi:10.1007/s00228-015-1920-1.
- Kern AL, Biller H, Klimes F, et al.
Hyperpolarized 129Xe MR functional imaging to monitor the response of the human
lungs after segmental lipopolysaccharide challenge. In: Proc Intl Soc Mag
Reson Med 26. ; 2018:2436.
- Janssen O, Schaumann F, Holz O, et al.
Low-dose endotoxin inhalation in healthy volunteers - a challenge model for
early clinical drug development. BMC Pulm Med. 2013;13(1):1.
doi:10.1186/1471-2466-13-19.
- Qing K, Mugler JP, Altes TA, et al.
Assessment of lung function in asthma and COPD using hyperpolarized 129 Xe
chemical shift saturation recovery spectroscopy and dissolved-phase MRI. NMR
Biomed. 2014;27(12):1490-1501. doi:10.1002/nbm.3179.
- Kern AL, Gutberlet M, Qing K, et al.
Regional investigation of lung function and microstructure parameters by
localized 129 Xe chemical shift saturation recovery and dissolved-phase
imaging: A reproducibility study. Magn Reson Med. September 2018.
doi:10.1002/mrm.27407.
- Tsao J, Jiang Y. Hierarchical IDEAL:
Fast, robust, and multiresolution separation of multiple chemical species from
multiple echo times. Magn Reson Med. 2013;70(1):155-159.
doi:10.1002/mrm.24441.
- Patz S, Muradyan I, Hrovat MI, et al.
Diffusion of hyperpolarized 129 Xe in the lung: a simplified model of 129 Xe
septal uptake and experimental results. New J Phys. 2011;13(1):015009.
doi:10.1088/1367-2630/13/1/015009.
- Christman RA, Ailion DC, Case TA, et al.
Comparison of calculated and experimental NMR spectral broadening for lung
tissue. Magn Reson Med. 1996;35(1):6-13. doi:10.1002/mrm.1910350103.
- Wolber J, Cherubini A, Leach MO, Bifone A.
Hyperpolarized 129Xe NMR as a probe for blood oxygenation. Magn Reson Med.
2000;43(4):491-496.
doi:10.1002/(SICI)1522-2594(200004)43:4<491::AID-MRM1>3.0.CO;2-6.