Justin P Yuan1, Melanie A Morrison1, Angela Jakary1, Sabine Mueller2, Olga Tymofiyeva1, Duan Xu1, and Janine M Lupo1
1Department of Radiology & Biomedical Imaging, University of California, San Francisco, San Francisco, CA, United States, 2Department of Neurology, University of California, San Francisco, San Francisco, CA, United States
Synopsis
Cranial radiation therapy (CRT) is an effective brain cancer treatment but many patients exhibit cognitive deficits over time. We studied these deficits in adolescent and young adult survivors of pediatric brain cancer with prior CRT using white matter graph network analysis. Executive function and working memory performance were correlated with structural connectivity metrics. Global integration and segregation metrics were associated with neurocognitive deficits, as well as connectivity at domain-specific regions. Our results support past findings of CRT’s negative cognitive effects and suggest that they are driven through structural changes in brain white matter
Introduction
The prognosis for pediatric brain cancers has improved such that there is a growing population of long-term cancer survivors. Many of these patients have undergone whole-brain cranial radiation therapy (CRT), a now-standard treatment that has significantly improved outcomes. However, CRT is linked to neurocognitive impairments1 that often affect attention, working memory, visual-motor processing, and spatial relations.2-4 Such declines have been observed in adult populations who received prior radiation as children5 and newly-diagnosed elderly patients receiving radiation therapy for the first time.6
Previous studies using magnetic resonance imaging (MRI) have found that CRT is associated with structural brain changes such as altered white matter morphology.7 Graph network analysis of white matter (WM) connectivity is a promising method to study CRT effects on cognitive deficits, as such functions engage multiple brain regions. The method models the brain as a network of connected edges and nodes, which are quantitatively described with graph theory.8 The goal of this study was to examine the long-term effects of whole-brain and whole-ventricular CRT in adolescent and young adult survivors of pediatric brain cancer using graph analysis of ultra-high-field (7T) MRI to study the associations between current neurocognitive deficits and WM structural connectivity.
Methods
Ten adolescent and young adult subjects (6F, mean age ± SD = 17.7 ± 5.0yrs.) with prior whole-brain CRT for pediatric brain cancers participated in this study (Table 1). Subjects were scanned using a GE 7T MRI scanner using a protocol that included a T1 IR-SPGR sequence (TR/TE=4s/1.75ms, TI=1350ms (T1), flip angle=8o, 1mm isotropic resolution, parallel imaging R=2.2, and Tacq=4:28min) and a multiband two-shell diffusion sequence with 90 directions (30 at b=1000s/mm2; 60 at b=2000s/mm2), 7 b0 images, and 1 additional b0 image with reversed PE gradient, TR/TE=4000/71.6ms, isotropic 2mm resolution, FOV=256x256 mm, 128x128 matrix, parallel imaging R=3, and Tacq=7:20min.
Diffusion image processing was performed using FSL,9 MATLAB, and Diffusion Toolkit,10 and included: multiband reconstruction, TOPUP and eddy current correction, and deterministic tractography (FACT).11 T1-weighted data was registered to the DTI b0-volume and the MNI template (FLIRT),12,13 allowing AAL atlas application to create 90 network ROIs. A weighted connectivity matrix was constructed, with average voxel fractional anisotropy (FA) along streamlines as the edge weight.
Global graph metrics included measures of segregation (clustering coefficient and transitivity), integration (characteristic path length and efficiency), and small-worldness. Local metrics included node strength at regions associated with executive function14 (middle frontal gyrus, [MFG]) and working memory15,16 (superior frontal gyrus [SFG] and superior parietal lobule [SPL]).Subjects completed a computerized battery of neurocognitive tests (CogState),17,18 which included the Groton Maze Learning (GML) task,19,20 an executive functioning and spatial working memory task, and the One-Back (ONB) working memory task21 (Table 2). Graph metric and cognitive task performance were associated using a Pearson correlation coefficient.
Results
Figure 1 illustrates a tractogram and connectivity matrix of a study participant. Subjects performed poorly for both tasks relative to age-matched peers: GML=-0.49±1.39 (mean±std. dev); ONB=-1.17±1.52. There were significant negative correlations between GML legal errors, a spatial working memory component of the task, and both global metrics (clustering coefficient, efficiency, and transitivity) and local node strength at all regions except the R-MFG (Figure 2). Table 3 details the full results.Discussion
Our results indicated an inverse relationship between WM structural connectivity properties and cognitive performance in survivors who received whole-brain CRT. The tumors’ infratentorial locations suggested that the changes were due to CRT rather than the tumor itself. These findings support previous reports of CRT-related cognitive deficits22 and WM structural changes.23 Our graph analysis of WM connectivity showed that global WM segregation and integration were negatively correlated with spatial working memory performance. Local node strength findings suggested that decreased WM connections from executive function brain regions (L-MFG) and working memory regions (bilateral SFG and SPL) were associated with increased error rates. These indicated that WM network changes, particularly at domain-specific regions, may underlie CRT-associated cognitive deficits. Ongoing analyses include longitudinal follow-up, differentiating between RT-type, and control analysis with healthy adolescents and cancer survivors without CRT treatment.Acknowledgements
NIH Natl Inst. Child Health & Human Dev. R01 HD079568 and R01 HD072074References
- Martin, A. M., Raabe, E., Eberhart, C., & Cohen, K. J. (2014). Management of Pediatric and Adult Patients with Medulloblastoma. Current Treatment Options in Oncology, 15(4), 581–594.
- Reeves, C. B., Palmer, S. L., Reddick, W. E., Merchant, T. E., Buchanan, G. M., Gajjar, A., & Mulhern, R. K. (2006). Attention and memory functioning among pediatric patients with medulloblastoma. Journal of Pediatric Psychology, 31(3), 272–280.
- Mabbott, D. J., Penkman, L., Witol, A., Strother, D., & Bouffet, E. (2008). Core neurocognitive functions in children treated for posterior fossa tumors. Neuropsychology, 22(2), 159–168.
- Jacola, L. M., Ashford, J. M., Reddick, W. E., Glass, J. O., Ogg, R. J., Merchant, T. E., & Conklin, H. M. (2014). The relationship between working memory and cerebral white matter volume in survivors of childhood brain tumors treated with conformal radiation therapy. Journal of Neuro-Oncology, 119(1), 197–205.
- Hudson, M. M., Ness, K. K., Gurney, J. G., Mulrooney, D. A., Chemaitilly, W., Krull, K. R., … Robison, L. L. (2013). Clinical Ascertainment of Health Outcomes Among Adults Treated for Childhood Cancer. JAMA, 309(22), 2371–2381.
- Loh, K. P., Janelsins, M. C., Mohile, S. G., Holmes, H. M., Hsu, T., Inouye, S. K., … Ahles, T. A. (2016). Chemotherapy-related cognitive impairment in older patients with cancer. Journal of Geriatric Oncology, 7(4), 270–280.
- Beera, K. G., Li, Y.-Q., Dazai, J., Stewart, J., Egan, S., Ahmed, M., … Nieman, B. J. (2018). Altered brain morphology after focal radiation reveals impact of off-target effects: implications for white matter development and neurogenesis. Neuro-Oncology, 20(6), 788–798.
- Rubinov, M., & Sporns, O. (2010). Complex network measures of brain connectivity: Uses and interpretations. NeuroImage, 52(3), 1059–1069.
- Smith, S. M., Jenkinson, M., Woolrich, M. W., Beckmann, C. F., Behrens, T. E. J., Johansen-Berg, H., … Matthews, P. M. (2004). Advances in functional and structural MR image analysis and implementation as FSL. NeuroImage, 23, Supplement 1, S208–S219.
- Wang, R., Benner, T., Sorensen, A. G., & Wedeen, V. J. (2007, May). Diffusion toolkit: a software package for diffusion imaging data processing and tractography. Proc. Intl. Soc. Mag. Reson. Med. (Vol. 15, No. 3720).
- Mori, S., Crain, B. J., Chacko, V. P., & Van Zijl, P. C. M. (1999). Three-dimensional tracking of axonal projections in the brain by magnetic resonance imaging. Annals of Neurology, 45(2), 265–269.
- Jenkinson, M., & Smith, S. (2001). A global optimisation method for robust affine registration of brain images. Medical Image Analysis, 5(2), 143–156.
- Jenkinson, Mark, Bannister, P., Brady, M., & Smith, S. (2002). Improved Optimization for the Robust and Accurate Linear Registration and Motion Correction of Brain Images. NeuroImage, 17(2), 825–841.
- Baum, G. L., Ciric, R., Roalf, D. R., Betzel, R. F., Moore, T. M., Shinohara, R. T., … Satterthwaite, T. D. (2017). Modular Segregation of Structural Brain Networks Supports the Development of Executive Function in Youth. Current Biology, 27(11), 1561-1572.e8.
- Wager, T. D., & Smith, E. E. (2003). Neuroimaging studies of working memory: a meta-analysis. Cognitive, Affective & Behavioral Neuroscience, 3(4), 255–274.
- Nee, D. E., Brown, J. W., Askren, M. K., Berman, M. G., Demiralp, E., Krawitz, A., & Jonides, J. (2013). A Meta-analysis of Executive Components of Working Memory. Cerebral Cortex, 23(2), 264–282.
- Maruff, P., Thomas, E., Cysique, L., Brew, B., Collie, A., Snyder, P., & Pietrzak, R. H. (2009). Validity of the CogState brief battery: relationship to standardized tests and sensitivity to cognitive impairment in mild traumatic brain injury, schizophrenia, and AIDS dementia complex. Archives of Clinical Neuropsychology: The Official Journal of the National Academy of Neuropsychologists, 24(2), 165–178.
- Mielke, M. M., Machulda, M. M., Hagen, C. E., Edwards, K. K., Roberts, R. O., Pankratz, V. S., … Petersen, R. C. (2015). Performance of the CogState computerized battery in the Mayo Clinic Study on Aging. Alzheimer’s & Dementia : The Journal of the Alzheimer’s Association, 11(11), 1367–1376.
- Snyder, P. J., Bednar, M. M., Cromer, J. R., & Maruff, P. (2005). Reversal of scopolamine-induced deficits with a single dose of donepezil, an acetylcholinesterase inhibitor. Alzheimer’s & Dementia, 1(2), 126–135.
- Pietrzak, R. H., Maruff, P., Mayes, L. C., Roman, S. A., Sosa, J. A., & Snyder, P. J. (2008). An examination of the construct validity and factor structure of the Groton Maze Learning Test, a new measure of spatial working memory, learning efficiency, and error monitoring. Archives of Clinical Neuropsychology, 23(4), 433–445.
- Kirchner, W. K. (1958). Age Differences in Short-Term Retention of Rapidly Changing Information. Journal of Experimental Psychology; Washington, Etc., 55(4), 352.
- Vannorsdall, T. D. (2017). Cognitive Changes Related to Cancer Therapy. Medical Clinics of North America, 101(6), 1115–1134.
- Connor, M., Karunamuni, R., McDonald, C., White, N., Pettersson, N., Moiseenko, V., … Hattangadi-Gluth, J. (2016). Dose-dependent white matter damage after brain radiotherapy. Radiotherapy and Oncology: Journal of the European Society for Therapeutic Radiology and Oncology, 121(2), 209–216.
-
Bastian,
M., Heymann, S., & Jacomy, M. (2009). Gephi: an open source software
for exploring and manipulating networks. ICWSM, 8, 361-362.