Min-Hee Lee1, Nolan Baird O'Hara2, Csaba Juhasz3, Eishi Asano4, and Jeong-Won Jeong3
1Pediatrics and Translational Imaging Laboratory, Wayne State University School of Medicine, Detroit, MI, United States, 2Translational Neuroscience Program, Wayne State University School of Medicine, Detroit, MI, United States, 3Pediatrics, Neurology and Translational Imaging Laboratory, Wayne State University School of Medicine, Detroit, MI, United States, 4Pediatrics and Neurology, Wayne State University School of Medicine, Detroit, MI, United States
Synopsis
The present study proposes a novel diffusion weighted imaging (DWI) tract classification methodology which integrates DWI-maximum a posteriori probability (DWI-MAP) analysis with Kalman filter in order to predict an optimal margin of cortical resection balancing postoperative benefit (seizure freedom) and risk (motor deficit in face, hand and leg) in pediatric epilepsy surgery. The predicted margins provided high Fisher’s exact test probability, 0.92 (0.94) of successful avoidance of motor deficits with (or without) seizure freedom. This finding demonstrates the translational value of a DWI tract classification approach in quantitative benefit-risk assessment to achieve ultimate goal of pediatric epilepsy surgery.
Introduction
Clinical management of children with drug-resistant
epilepsy includes surgical resection of the epileptogenic zone following invasive
electrocorticography (ECoG) recording.1,2 Thereby, clinicians intend
to maximize the chance of postoperative seizure freedom (benefit) while minimizing
postoperative neurological deficits such as motor function (risk). In the current
ECoG practice for young children, the benefit-risk prediction is inevitably limited
by poor spatial resolution and suboptimal sensitivity to localize eloquent areas
at an individual patient level.3 Thus, a more structured and
quantitative tool is required to provide an optimal resection margin taking
into account the balance between benefit and risk of epilepsy surgery. The
present study proposes a novel DWI tract classification model which integrates
DWI-maximum a posteriori probability (DWI-MAP)4 analysis with Kalman
filter5 in order to model “ECoG data-driven knowledge of benefit and
risk” as a hidden state function of DWI-MAP-defined tract loss determined by a
given surgical margin.Methods
We studied 40 children with drug-resistant epilepsy
(age: 8.7±4.8 years) who underwent resection of the presumed epileptogenic zone
following extraoperative ECoG recording. Newly developed postoperative motor
deļ¬cits were determined during a six-month follow-up. DWI scans were acquired using
a 3T scanner with 55 isotropic gradient directions and b = 1000 s/mm2.
Pre- and postoperative tractography evaluations were performed by our previously
described DWI-MAP analysis,4,5 where whole brain tractography of the
operated hemisphere was obtained by independent component analysis with ball
and stick model6 and then sorted into 3 eloquent white matter
pathways using stereotaxic white matter probability maps of age-gender matched
controls: "C1-3: face/hand/leg motor area-internal capsule
pathway". Also, we adopted an additional streamline clustering procedure to
Ci=1,2,3 where average direct-flip distance, β*i (i.e., mean distance of equally
sampled bidirectional fibers to their exemplar fiber)7 was optimized
to reclassify true streamlines in Ci so that their postoperative
volume change (ri = 100×(volume
of preoperative Ci ∩ volume
of resected tissue)/volume of preoperative Ci) should maximize the
prediction of postoperative deficit in binary logistic regression model. Resection
margin, di, was determined by minimal Euclidean distance between voxels
of Ci and resection boundary on co-registering the postoperative to
preoperative b0 images. In case Ci was resected, di was
assumed as -1 × maximum Euclidean distance between
every paired voxel inside the resected Ci. For Kalman filter
analysis to approximate the hidden relationship between the preoperatively measurable
di and unmeasurable ri, it was assumed that ri
is a dynamic variable to control the unknown state vector, x(ri),
affecting the surgical margin, di, where Kalman filter directly models
a stochastic system with dynamics: x(ri), and observation: di(ri).5 To obtain
a better estimate of di(ri) in a small sample size,
Rauch-Tung-Striebel algorithm7 was used to smooth the estimated di(ri)
at fixed interval. An optimal margin, d*i, balancing seizure
freedom with the occurrence of deficit after surgery, was found at di
satisfying P(deficit|di(ri)) = P(seizure freedom|di(ri)) where P(deficit|di(ri)) and P(seizure freedom|di(ri))
represent cumulative probability density functions of seizure freedom and
deficit at d ≤ di(ri),
respectively. Finally, Fisher’s exact probability test8 was applied
to investigate statistical significance of d*i for
prediction of successful avoidance of postoperative deficit with (or without)
seizure freedom.Results
Binary logistic regression analysis revealed
that postoperative fiber loss, r1,2,3 of DWI-MAP-determined C1,2,3
achieved clinically relevant accuracy of 0.93, 1.00 and 0.98 for prediction of postoperative
deficits in face (β*1
= 13 mm), hand (β*2
= 9 mm), and leg (β*3
= 8 mm), respectively. The
subsequent Kalman filter analysis also revealed hidden nonlinear state relationships
between r1,2,3 and d1,2,3 (Figure 1), yielding d*1,2,3 = -1.93, 2.29, -4.84 mm,
which ultimately balanced the values of P(deficit|di(ri)) and P(seizure freedom|d(ri)) as plotted in Figure 2. The surgical margin, d, greater than the estimated d*
achieved high accuracy for prediction of successful functional and seizure outcomes.
Namely, Fisher’s probability of successful avoidance of motor deficits with (or
without) seizure freedom was 0.83 (0.88), 0.96 (1.00), and 0.96 (0.94). Figure 3 presents safe boundaries of Ci
(i.e., outmost boundaries of Ci + d*i), which is
associated with preserved motor function and seizure freedom.Discussion
We have established a clinically effective DWI tractography
method to allow objective prediction of surgical outcomes including postoperative
functional deficits and seizure freedom. This method may help in achieving the ultimate
goal of epilepsy surgery. In contrast to other tractography approaches,9-12 the proposed method was systematically validated by empirical evidence including
eloquent areas, postoperative functional outcome and clinical outcome.Conclusion
Our findings demonstrate the translational
value of a DWI tract classification approach in quantitative benefit-risk assessment
in pediatric epilepsy surgery.Acknowledgements
This study was funded by
a grant from the National Institute of Health, (R01-NS089659 to J.J and R01
NS064033 to E.A.).References
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