Marcus J. Couch1,2, Jonathan H. Rayment3, Robert Grimm4, Andreas Voskrebenzev5,6, Jens Vogel-Claussen5,6, Felix Ratjen1,7, and Giles Santyr1,2
1Translational Medicine Program, The Hospital for Sick Children, Toronto, ON, Canada, 2Department of Medical Biophysics, University of Toronto, Toronto, ON, Canada, 3Division of Respiratory Medicine, British Columbia Children’s Hospital, Vancouver, BC, Canada, 4MR Application Predevelopment, Siemens Healthcare, Erlangen, Germany, 5Diagnostic and Interventional Radiology, Hannover Medical School, Hannover, Germany, 6Biomedical Research in Endstage and Obstructive Lung Disease Hannover (BREATH), Member of the German Center for Lung Research (DZL), Hannover, Germany, 7Division of Respiratory Medicine, The Hospital for Sick Children, Toronto, ON, Canada
Synopsis
Hyperpolarized 129Xe MRI provides robust measurements of ventilatory function through the measurement of the ventilation defect percent (VDP). Recent progress in 1H-based free-breathing techniques (phase-resolved functional lung; PREFUL) allows for the calculation of fractional ventilation maps, which can be similarly processed to calculate VDP. While hyperpolarized 129Xe is an established research technique, PREFUL MRI is simple to implement on any MRI scanner and therefore has good potential for use in future clinical trials in cystic fibrosis (CF). In this study, VDP measurements performed using hyperpolarized 129Xe and PREFUL MRI were compared and correlated with pulmonary function tests in pediatric CF.
Introduction
Free-breathing 1H-based functional lung
imaging techniques, such as Fourier Decomposition (FD), provide maps related to
ventilation and perfusion.1 Additional post-processing steps can
be applied to calculate fractional ventilation (FV) from the free-breathing 1H
images using a modified FD reconstruction2 or Phase-Resolved
Functional Lung (PREFUL) MRI.3 Hyperpolarized (HP) 129Xe MRI is an
established lung imaging technique that is feasible in children with cystic
fibrosis (CF)4, and measurements of the ventilation
defect percent (VDP), defined as the fraction of unventilated lung, can provide
a more sensitive indicator of mild lung disease than spirometric indices, such
as the forced expiratory volume in one second (FEV1).5 HP 129Xe VDP is strongly
correlated with the lung clearance index (LCI), a measure of ventilation
heterogeneity derived from nitrogen multiple breath washout (MBW).6-8 Since HP 129Xe MRI is not
widely available, 1H-based functional lung imaging approaches are
desirable; however, the application of PREFUL MRI in pediatric CF has been
limited to date. The purpose of this study was to compare
PREFUL and HP 129Xe MRI and correlate both techniques to LCI and FEV1
in pediatric CF.Methods
24 pediatric participants were recruited (mean age 13±3
years), including 8 healthy controls, 5 with stable well-controlled CF, and 11
CF patients undergoing a pulmonary exacerbation (PEx) at the time of imaging. 9
of the PEx participants returned for a second imaging visit after 2 weeks of
treatment. Standard pulmonary function tests were performed, as well as N2
MBW (Exhalyzer D®, EcoMedics AG) to
measure LCI (2.5% threshold). Imaging was
performed at 3T (MAGNETOM Prisma, Siemens Healthcare) using a flexible 129Xe
vest coil (Clinical MR Solutions) and previously described methods.9 Table 1 summarizes
the GRE acquisition parameters for the HP 129Xe breath-hold and
accompanying breath-hold of N2 for 1H imaging at the same
lung volume. Functional 1H MRI was
performed by repeating a single central coronal slice TurboFLASH acquisition at
a sampling rate of ~3.6 frames per second (Table 1). PREFUL FV maps were
calculated using prototype software (MR Lung, Siemens Healthcare)3, and VDP was
calculated for both PREFUL and HP 129Xe MRI and using k-means
segmentation.9,10Results
Figure 1 shows a comparison of PREFUL FV maps and HP 129Xe
MRI acquired in a representative healthy participant and two CF patients. The HP 129Xe VDP represents a
whole lung measurement, and the slice most closely matching the location of the
FV map is shown. The healthy and stable CF
participants had a low VDP as measured by either PREFUL or HP 129Xe.
The CF participant undergoing a PEx had substantial ventilation defects in both
the PREFUL and HP 129Xe maps, and these defects improved following
treatment. Figure 2 shows that the VDP measurements from both techniques are
correlated with one another. Figure 3 shows moderate and significant
correlations for both VDP calculation methods compared to LCI. Figure 4 shows
similar moderate and significant correlations for both methods compared to FEV1.
For the PEx participants that returned for a second visit after treatment,
there was a statistically significant difference in HP 129Xe VDP and
FEV1, but not for PREFUL VDP and LCI (p = 0.020, 0.008, 0.098, and
0.074 from Wilcoxon matched-pairs tests, respectively).Discussion
This
study demonstrates a correlation between PREFUL and HP 129Xe VDP in
pediatric CF, which qualitatively agrees with similar VDP measurements
previously performed using HP 3He and FD MRI in adults with chronic
obstructive pulmonary disease.11 The differences in defect regions
captured in the segmented maps reflect the complementary nature of the two
imaging approaches. The good correlation between VDP and LCI for both
techniques suggests that imaging provides a sensitive indicator of ventilation
heterogeneity, which is especially important in early CF lung disease where FEV1
often appears normal. Previous work in stable CF has shown a stronger
correlation between VDP and LCI6; however, this
work includes a broader spectrum of CF lung disease (i.e. PEx). For the whole
PEx group, PREFUL VDP was unable to
detect significant functional changes following treatment for a PEx, which may
point to the need for further image quality optimization. On the other hand,
the single-slice nature of the PREFUL acquisition does not necessarily capture
regions of the lung that are most affected by the treatment.Conclusions
HP
129Xe and PREFUL MRI are able to provide measures of VDP that are
correlated with pulmonary function tests in pediatric CF. PREFUL MRI has a
potentially broader applicability in the clinic, since it can be performed on
any MRI scanner without inhaled contrast gases, which may be advantageous for
young CF patients.Acknowledgements
The authors would like to thank the
following individuals for their help with data collection: Yonni Friedlander, Raymond
Hu, Nikhil Kanhere, Krzysztof Kowalik, Andras Lindenmaier, Tammy Rayner, Laura
Seed, Ravi Seethamraju, Elaine Stirrat, Ruth Weiss, David Wilson, and Brandon
Zanette. We would also like to thank the following sources of funding: The
Hospital for Sick Children (Catalyst Grant from the Cystic Fibrosis Centre),
Natural Sciences and Engineering Research Council of Canada (NSERC) Discovery grant
(RGPIN 217015-2013), Canadian Institutes of
Health Research (CIHR) operating and project grants (MOP 123431, PJT 153099). MJC was
funded by a Research Training Competition (Restracomp) Fellowship from the
Hospital for Sick Children and a Mitacs Elevate Postdoctoral Fellowship.References
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